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A rare case of lupus-related gastrointestinal vasculitis presenting as rectal gangrene
Systemic lupus erythematosus (SLE) related gastrointestinal vasculitis is a rare condition limited to case studies within the literature however, no cases of rectal gangrene and perforation have been previously described. A 32-year-old male presented with abdominal pain, vomiting and fevers. CT demo...
Autores principales: | , , |
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Formato: | Online Artículo Texto |
Lenguaje: | English |
Publicado: |
Oxford University Press
2019
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Materias: | |
Acceso en línea: | https://www.ncbi.nlm.nih.gov/pmc/articles/PMC6486653/ https://www.ncbi.nlm.nih.gov/pubmed/31044066 http://dx.doi.org/10.1093/jscr/rjz128 |
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author | Liang, Yi Di Re, Angelina El Khoury, Toufic |
author_facet | Liang, Yi Di Re, Angelina El Khoury, Toufic |
author_sort | Liang, Yi |
collection | PubMed |
description | Systemic lupus erythematosus (SLE) related gastrointestinal vasculitis is a rare condition limited to case studies within the literature however, no cases of rectal gangrene and perforation have been previously described. A 32-year-old male presented with abdominal pain, vomiting and fevers. CT demonstrated free gas and free fluid around the rectum indicative of a perforation. He proceeded to urgent laparotomy, confirming a diagnosis of rectal infarction and perforation. Uniquely, the involved segment of gangrene extended from the rectosigmoid to the anorectal junction. A Hartmanns procedure was performed. Histopathology confirmed underlying stenosis of the rectal arteries secondary to chronic vasculitis related to the affected areas. The current case is a unique presentation of SLE-related vasculitis. It highlights the need to judiciously investigate SLE patients presenting with surgical acute abdomen. |
format | Online Article Text |
id | pubmed-6486653 |
institution | National Center for Biotechnology Information |
language | English |
publishDate | 2019 |
publisher | Oxford University Press |
record_format | MEDLINE/PubMed |
spelling | pubmed-64866532019-05-01 A rare case of lupus-related gastrointestinal vasculitis presenting as rectal gangrene Liang, Yi Di Re, Angelina El Khoury, Toufic J Surg Case Rep Case Report Systemic lupus erythematosus (SLE) related gastrointestinal vasculitis is a rare condition limited to case studies within the literature however, no cases of rectal gangrene and perforation have been previously described. A 32-year-old male presented with abdominal pain, vomiting and fevers. CT demonstrated free gas and free fluid around the rectum indicative of a perforation. He proceeded to urgent laparotomy, confirming a diagnosis of rectal infarction and perforation. Uniquely, the involved segment of gangrene extended from the rectosigmoid to the anorectal junction. A Hartmanns procedure was performed. Histopathology confirmed underlying stenosis of the rectal arteries secondary to chronic vasculitis related to the affected areas. The current case is a unique presentation of SLE-related vasculitis. It highlights the need to judiciously investigate SLE patients presenting with surgical acute abdomen. Oxford University Press 2019-04-27 /pmc/articles/PMC6486653/ /pubmed/31044066 http://dx.doi.org/10.1093/jscr/rjz128 Text en Published by Oxford University Press and JSCR Publishing Ltd. All rights reserved. © The Author(s) 2019. http://creativecommons.org/licenses/by-nc/4.0/ This is an Open Access article distributed under the terms of the Creative Commons Attribution Non-Commercial License (http://creativecommons.org/licenses/by-nc/4.0/), which permits non-commercial re-use, distribution, and reproduction in any medium, provided the original work is properly cited. For commercial re-use, please contact journals.permissions@oup.com |
spellingShingle | Case Report Liang, Yi Di Re, Angelina El Khoury, Toufic A rare case of lupus-related gastrointestinal vasculitis presenting as rectal gangrene |
title | A rare case of lupus-related gastrointestinal vasculitis presenting as rectal gangrene |
title_full | A rare case of lupus-related gastrointestinal vasculitis presenting as rectal gangrene |
title_fullStr | A rare case of lupus-related gastrointestinal vasculitis presenting as rectal gangrene |
title_full_unstemmed | A rare case of lupus-related gastrointestinal vasculitis presenting as rectal gangrene |
title_short | A rare case of lupus-related gastrointestinal vasculitis presenting as rectal gangrene |
title_sort | rare case of lupus-related gastrointestinal vasculitis presenting as rectal gangrene |
topic | Case Report |
url | https://www.ncbi.nlm.nih.gov/pmc/articles/PMC6486653/ https://www.ncbi.nlm.nih.gov/pubmed/31044066 http://dx.doi.org/10.1093/jscr/rjz128 |
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