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A rare case of lupus-related gastrointestinal vasculitis presenting as rectal gangrene

Systemic lupus erythematosus (SLE) related gastrointestinal vasculitis is a rare condition limited to case studies within the literature however, no cases of rectal gangrene and perforation have been previously described. A 32-year-old male presented with abdominal pain, vomiting and fevers. CT demo...

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Detalles Bibliográficos
Autores principales: Liang, Yi, Di Re, Angelina, El Khoury, Toufic
Formato: Online Artículo Texto
Lenguaje:English
Publicado: Oxford University Press 2019
Materias:
Acceso en línea:https://www.ncbi.nlm.nih.gov/pmc/articles/PMC6486653/
https://www.ncbi.nlm.nih.gov/pubmed/31044066
http://dx.doi.org/10.1093/jscr/rjz128
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author Liang, Yi
Di Re, Angelina
El Khoury, Toufic
author_facet Liang, Yi
Di Re, Angelina
El Khoury, Toufic
author_sort Liang, Yi
collection PubMed
description Systemic lupus erythematosus (SLE) related gastrointestinal vasculitis is a rare condition limited to case studies within the literature however, no cases of rectal gangrene and perforation have been previously described. A 32-year-old male presented with abdominal pain, vomiting and fevers. CT demonstrated free gas and free fluid around the rectum indicative of a perforation. He proceeded to urgent laparotomy, confirming a diagnosis of rectal infarction and perforation. Uniquely, the involved segment of gangrene extended from the rectosigmoid to the anorectal junction. A Hartmanns procedure was performed. Histopathology confirmed underlying stenosis of the rectal arteries secondary to chronic vasculitis related to the affected areas. The current case is a unique presentation of SLE-related vasculitis. It highlights the need to judiciously investigate SLE patients presenting with surgical acute abdomen.
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spelling pubmed-64866532019-05-01 A rare case of lupus-related gastrointestinal vasculitis presenting as rectal gangrene Liang, Yi Di Re, Angelina El Khoury, Toufic J Surg Case Rep Case Report Systemic lupus erythematosus (SLE) related gastrointestinal vasculitis is a rare condition limited to case studies within the literature however, no cases of rectal gangrene and perforation have been previously described. A 32-year-old male presented with abdominal pain, vomiting and fevers. CT demonstrated free gas and free fluid around the rectum indicative of a perforation. He proceeded to urgent laparotomy, confirming a diagnosis of rectal infarction and perforation. Uniquely, the involved segment of gangrene extended from the rectosigmoid to the anorectal junction. A Hartmanns procedure was performed. Histopathology confirmed underlying stenosis of the rectal arteries secondary to chronic vasculitis related to the affected areas. The current case is a unique presentation of SLE-related vasculitis. It highlights the need to judiciously investigate SLE patients presenting with surgical acute abdomen. Oxford University Press 2019-04-27 /pmc/articles/PMC6486653/ /pubmed/31044066 http://dx.doi.org/10.1093/jscr/rjz128 Text en Published by Oxford University Press and JSCR Publishing Ltd. All rights reserved. © The Author(s) 2019. http://creativecommons.org/licenses/by-nc/4.0/ This is an Open Access article distributed under the terms of the Creative Commons Attribution Non-Commercial License (http://creativecommons.org/licenses/by-nc/4.0/), which permits non-commercial re-use, distribution, and reproduction in any medium, provided the original work is properly cited. For commercial re-use, please contact journals.permissions@oup.com
spellingShingle Case Report
Liang, Yi
Di Re, Angelina
El Khoury, Toufic
A rare case of lupus-related gastrointestinal vasculitis presenting as rectal gangrene
title A rare case of lupus-related gastrointestinal vasculitis presenting as rectal gangrene
title_full A rare case of lupus-related gastrointestinal vasculitis presenting as rectal gangrene
title_fullStr A rare case of lupus-related gastrointestinal vasculitis presenting as rectal gangrene
title_full_unstemmed A rare case of lupus-related gastrointestinal vasculitis presenting as rectal gangrene
title_short A rare case of lupus-related gastrointestinal vasculitis presenting as rectal gangrene
title_sort rare case of lupus-related gastrointestinal vasculitis presenting as rectal gangrene
topic Case Report
url https://www.ncbi.nlm.nih.gov/pmc/articles/PMC6486653/
https://www.ncbi.nlm.nih.gov/pubmed/31044066
http://dx.doi.org/10.1093/jscr/rjz128
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