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Genetic analyses of human fetal retinal pigment epithelium gene expression suggest ocular disease mechanisms

The retinal pigment epithelium (RPE) serves vital roles in ocular development and retinal homeostasis but has limited representation in large-scale functional genomics datasets. Understanding how common human genetic variants affect RPE gene expression could elucidate the sources of phenotypic varia...

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Autores principales: Liu, Boxiang, Calton, Melissa A., Abell, Nathan S., Benchorin, Gillie, Gloudemans, Michael J., Chen, Ming, Hu, Jane, Li, Xin, Balliu, Brunilda, Bok, Dean, Montgomery, Stephen B., Vollrath, Douglas
Formato: Online Artículo Texto
Lenguaje:English
Publicado: Nature Publishing Group UK 2019
Materias:
Acceso en línea:https://www.ncbi.nlm.nih.gov/pmc/articles/PMC6527609/
https://www.ncbi.nlm.nih.gov/pubmed/31123710
http://dx.doi.org/10.1038/s42003-019-0430-6
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author Liu, Boxiang
Calton, Melissa A.
Abell, Nathan S.
Benchorin, Gillie
Gloudemans, Michael J.
Chen, Ming
Hu, Jane
Li, Xin
Balliu, Brunilda
Bok, Dean
Montgomery, Stephen B.
Vollrath, Douglas
author_facet Liu, Boxiang
Calton, Melissa A.
Abell, Nathan S.
Benchorin, Gillie
Gloudemans, Michael J.
Chen, Ming
Hu, Jane
Li, Xin
Balliu, Brunilda
Bok, Dean
Montgomery, Stephen B.
Vollrath, Douglas
author_sort Liu, Boxiang
collection PubMed
description The retinal pigment epithelium (RPE) serves vital roles in ocular development and retinal homeostasis but has limited representation in large-scale functional genomics datasets. Understanding how common human genetic variants affect RPE gene expression could elucidate the sources of phenotypic variability in selected monogenic ocular diseases and pinpoint causal genes at genome-wide association study (GWAS) loci. We interrogated the genetics of gene expression of cultured human fetal RPE (fRPE) cells under two metabolic conditions and discovered hundreds of shared or condition-specific expression or splice quantitative trait loci (e/sQTLs). Co-localizations of fRPE e/sQTLs with age-related macular degeneration (AMD) and myopia GWAS data suggest new candidate genes, and mechanisms by which a common RDH5 allele contributes to both increased AMD risk and decreased myopia risk. Our study highlights the unique transcriptomic characteristics of fRPE and provides a resource to connect e/sQTLs in a critical ocular cell type to monogenic and complex eye disorders.
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spelling pubmed-65276092019-05-23 Genetic analyses of human fetal retinal pigment epithelium gene expression suggest ocular disease mechanisms Liu, Boxiang Calton, Melissa A. Abell, Nathan S. Benchorin, Gillie Gloudemans, Michael J. Chen, Ming Hu, Jane Li, Xin Balliu, Brunilda Bok, Dean Montgomery, Stephen B. Vollrath, Douglas Commun Biol Article The retinal pigment epithelium (RPE) serves vital roles in ocular development and retinal homeostasis but has limited representation in large-scale functional genomics datasets. Understanding how common human genetic variants affect RPE gene expression could elucidate the sources of phenotypic variability in selected monogenic ocular diseases and pinpoint causal genes at genome-wide association study (GWAS) loci. We interrogated the genetics of gene expression of cultured human fetal RPE (fRPE) cells under two metabolic conditions and discovered hundreds of shared or condition-specific expression or splice quantitative trait loci (e/sQTLs). Co-localizations of fRPE e/sQTLs with age-related macular degeneration (AMD) and myopia GWAS data suggest new candidate genes, and mechanisms by which a common RDH5 allele contributes to both increased AMD risk and decreased myopia risk. Our study highlights the unique transcriptomic characteristics of fRPE and provides a resource to connect e/sQTLs in a critical ocular cell type to monogenic and complex eye disorders. Nature Publishing Group UK 2019-05-20 /pmc/articles/PMC6527609/ /pubmed/31123710 http://dx.doi.org/10.1038/s42003-019-0430-6 Text en © The Author(s) 2019 Open Access This article is licensed under a Creative Commons Attribution 4.0 International License, which permits use, sharing, adaptation, distribution and reproduction in any medium or format, as long as you give appropriate credit to the original author(s) and the source, provide a link to the Creative Commons license, and indicate if changes were made. The images or other third party material in this article are included in the article’s Creative Commons license, unless indicated otherwise in a credit line to the material. If material is not included in the article’s Creative Commons license and your intended use is not permitted by statutory regulation or exceeds the permitted use, you will need to obtain permission directly from the copyright holder. To view a copy of this license, visit http://creativecommons.org/licenses/by/4.0/.
spellingShingle Article
Liu, Boxiang
Calton, Melissa A.
Abell, Nathan S.
Benchorin, Gillie
Gloudemans, Michael J.
Chen, Ming
Hu, Jane
Li, Xin
Balliu, Brunilda
Bok, Dean
Montgomery, Stephen B.
Vollrath, Douglas
Genetic analyses of human fetal retinal pigment epithelium gene expression suggest ocular disease mechanisms
title Genetic analyses of human fetal retinal pigment epithelium gene expression suggest ocular disease mechanisms
title_full Genetic analyses of human fetal retinal pigment epithelium gene expression suggest ocular disease mechanisms
title_fullStr Genetic analyses of human fetal retinal pigment epithelium gene expression suggest ocular disease mechanisms
title_full_unstemmed Genetic analyses of human fetal retinal pigment epithelium gene expression suggest ocular disease mechanisms
title_short Genetic analyses of human fetal retinal pigment epithelium gene expression suggest ocular disease mechanisms
title_sort genetic analyses of human fetal retinal pigment epithelium gene expression suggest ocular disease mechanisms
topic Article
url https://www.ncbi.nlm.nih.gov/pmc/articles/PMC6527609/
https://www.ncbi.nlm.nih.gov/pubmed/31123710
http://dx.doi.org/10.1038/s42003-019-0430-6
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