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Non surgical management of unilateral lacrimal gland swelling in a paediatric patient of Rosai-Dorfman disease: A case report

A 10-year-old girl presented to us with inferonasally displaced, non-axial proptosis of oculus dexter (OD), with ipsilateral, painless massive cervical lymphadenopathy of ten weeks duration. After a detailed hematological work-up and imaging, the histological evidence obtained on cervical lymph node...

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Autores principales: Shirodkar, Sailie, Patil, Prachi, Shah, Nagendra
Formato: Online Artículo Texto
Lenguaje:English
Publicado: Wolters Kluwer - Medknow 2019
Materias:
Acceso en línea:https://www.ncbi.nlm.nih.gov/pmc/articles/PMC6611273/
https://www.ncbi.nlm.nih.gov/pubmed/31238480
http://dx.doi.org/10.4103/ijo.IJO_1596_18
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author Shirodkar, Sailie
Patil, Prachi
Shah, Nagendra
author_facet Shirodkar, Sailie
Patil, Prachi
Shah, Nagendra
author_sort Shirodkar, Sailie
collection PubMed
description A 10-year-old girl presented to us with inferonasally displaced, non-axial proptosis of oculus dexter (OD), with ipsilateral, painless massive cervical lymphadenopathy of ten weeks duration. After a detailed hematological work-up and imaging, the histological evidence obtained on cervical lymph node biopsy established the diagnosis of Rosai-Dorfman disease. Although, Rosai-Dorfman disease of unilateral lacrimal gland is extremely infrequent, a high degree of suspicion is warranted in a case of young patient presenting with unilateral isolated lacrimal gland swelling and associated lymphadenopathy, wherein no other cause is found. Treatment protocol should be individualized as per the extent of systemic involvement and functional disability.
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spelling pubmed-66112732019-07-22 Non surgical management of unilateral lacrimal gland swelling in a paediatric patient of Rosai-Dorfman disease: A case report Shirodkar, Sailie Patil, Prachi Shah, Nagendra Indian J Ophthalmol Case Reports A 10-year-old girl presented to us with inferonasally displaced, non-axial proptosis of oculus dexter (OD), with ipsilateral, painless massive cervical lymphadenopathy of ten weeks duration. After a detailed hematological work-up and imaging, the histological evidence obtained on cervical lymph node biopsy established the diagnosis of Rosai-Dorfman disease. Although, Rosai-Dorfman disease of unilateral lacrimal gland is extremely infrequent, a high degree of suspicion is warranted in a case of young patient presenting with unilateral isolated lacrimal gland swelling and associated lymphadenopathy, wherein no other cause is found. Treatment protocol should be individualized as per the extent of systemic involvement and functional disability. Wolters Kluwer - Medknow 2019-07 /pmc/articles/PMC6611273/ /pubmed/31238480 http://dx.doi.org/10.4103/ijo.IJO_1596_18 Text en Copyright: © 2019 Indian Journal of Ophthalmology http://creativecommons.org/licenses/by-nc-sa/4.0 This is an open access journal, and articles are distributed under the terms of the Creative Commons Attribution-NonCommercial-ShareAlike 4.0 License, which allows others to remix, tweak, and build upon the work non-commercially, as long as appropriate credit is given and the new creations are licensed under the identical terms.
spellingShingle Case Reports
Shirodkar, Sailie
Patil, Prachi
Shah, Nagendra
Non surgical management of unilateral lacrimal gland swelling in a paediatric patient of Rosai-Dorfman disease: A case report
title Non surgical management of unilateral lacrimal gland swelling in a paediatric patient of Rosai-Dorfman disease: A case report
title_full Non surgical management of unilateral lacrimal gland swelling in a paediatric patient of Rosai-Dorfman disease: A case report
title_fullStr Non surgical management of unilateral lacrimal gland swelling in a paediatric patient of Rosai-Dorfman disease: A case report
title_full_unstemmed Non surgical management of unilateral lacrimal gland swelling in a paediatric patient of Rosai-Dorfman disease: A case report
title_short Non surgical management of unilateral lacrimal gland swelling in a paediatric patient of Rosai-Dorfman disease: A case report
title_sort non surgical management of unilateral lacrimal gland swelling in a paediatric patient of rosai-dorfman disease: a case report
topic Case Reports
url https://www.ncbi.nlm.nih.gov/pmc/articles/PMC6611273/
https://www.ncbi.nlm.nih.gov/pubmed/31238480
http://dx.doi.org/10.4103/ijo.IJO_1596_18
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