IgG4-related small-sized occlusive vasculitis in Mikulicz's disease

Mikulicz's disease is one of the IgG4-related diseases (IgG4-RDs) that involves the cardiovascular system; however, small-sized vasculitis is rare in IgG4-related diseases. A 64-year-old man presented with distal occlusive disease and developed left cerebrovascular infarction with occlusion of...

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Autores principales: Ikeoka, Kuniyasu, Watanabe, Tetsuya, Ohkawa, Toshika, Tsuzuki, Takashi, Ikeda, Yoshihiko, Takeda, Masashi, Hoshida, Shiro
Formato: Online Artículo Texto
Lenguaje:English
Publicado: Elsevier 2019
Materias:
Case report
Acceso en línea:https://www.ncbi.nlm.nih.gov/pmc/articles/PMC6614702/
https://www.ncbi.nlm.nih.gov/pubmed/31334401
http://dx.doi.org/10.1016/j.jvscit.2019.03.019
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author Ikeoka, Kuniyasu
Watanabe, Tetsuya
Ohkawa, Toshika
Tsuzuki, Takashi
Ikeda, Yoshihiko
Takeda, Masashi
Hoshida, Shiro
author_facet Ikeoka, Kuniyasu
Watanabe, Tetsuya
Ohkawa, Toshika
Tsuzuki, Takashi
Ikeda, Yoshihiko
Takeda, Masashi
Hoshida, Shiro
author_sort Ikeoka, Kuniyasu
collection PubMed
description Mikulicz's disease is one of the IgG4-related diseases (IgG4-RDs) that involves the cardiovascular system; however, small-sized vasculitis is rare in IgG4-related diseases. A 64-year-old man presented with distal occlusive disease and developed left cerebrovascular infarction with occlusion of the middle cerebral artery and diseased temporal artery branches. He underwent superficial temporal artery-middle cerebral artery anastomosis surgery. Histology of the temporal artery biopsy showed smooth muscle cell proliferation with many IgG4-positive plasma cells. He then developed salivary gland inflammation, and Mikulicz's disease was diagnosed. Small-sized occlusive vasculitis was observed in this IgG4-RD. Low-dose corticosteroid therapy is effective in preventing progressive occlusive disease.
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spelling pubmed-66147022019-07-22 IgG4-related small-sized occlusive vasculitis in Mikulicz's disease Ikeoka, Kuniyasu Watanabe, Tetsuya Ohkawa, Toshika Tsuzuki, Takashi Ikeda, Yoshihiko Takeda, Masashi Hoshida, Shiro J Vasc Surg Cases Innov Tech Case report Mikulicz's disease is one of the IgG4-related diseases (IgG4-RDs) that involves the cardiovascular system; however, small-sized vasculitis is rare in IgG4-related diseases. A 64-year-old man presented with distal occlusive disease and developed left cerebrovascular infarction with occlusion of the middle cerebral artery and diseased temporal artery branches. He underwent superficial temporal artery-middle cerebral artery anastomosis surgery. Histology of the temporal artery biopsy showed smooth muscle cell proliferation with many IgG4-positive plasma cells. He then developed salivary gland inflammation, and Mikulicz's disease was diagnosed. Small-sized occlusive vasculitis was observed in this IgG4-RD. Low-dose corticosteroid therapy is effective in preventing progressive occlusive disease. Elsevier 2019-06-29 /pmc/articles/PMC6614702/ /pubmed/31334401 http://dx.doi.org/10.1016/j.jvscit.2019.03.019 Text en © 2019 The Authors http://creativecommons.org/licenses/by-nc-nd/4.0/ This is an open access article under the CC BY-NC-ND license (http://creativecommons.org/licenses/by-nc-nd/4.0/).
spellingShingle Case report
Ikeoka, Kuniyasu
Watanabe, Tetsuya
Ohkawa, Toshika
Tsuzuki, Takashi
Ikeda, Yoshihiko
Takeda, Masashi
Hoshida, Shiro
IgG4-related small-sized occlusive vasculitis in Mikulicz's disease
title IgG4-related small-sized occlusive vasculitis in Mikulicz's disease
title_full IgG4-related small-sized occlusive vasculitis in Mikulicz's disease
title_fullStr IgG4-related small-sized occlusive vasculitis in Mikulicz's disease
title_full_unstemmed IgG4-related small-sized occlusive vasculitis in Mikulicz's disease
title_short IgG4-related small-sized occlusive vasculitis in Mikulicz's disease
title_sort igg4-related small-sized occlusive vasculitis in mikulicz's disease
topic Case report
url https://www.ncbi.nlm.nih.gov/pmc/articles/PMC6614702/
https://www.ncbi.nlm.nih.gov/pubmed/31334401
http://dx.doi.org/10.1016/j.jvscit.2019.03.019
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