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Giant aortic aneurysm due to fibulin- 4 deficiency: case series
Cutis laxa tip1b is a rare autosomal recessive disorder caused by FBLN 4 mutation and primarily characterized by vascular anomalies. Herein, we present five patients who are the members of the same family. The primary cardiac findings of these patients were giant aortic aneurysms. One 2.5-year-old p...
Autores principales: | , , |
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Formato: | Online Artículo Texto |
Lenguaje: | English |
Publicado: |
Kare Publishing
2019
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Materias: | |
Acceso en línea: | https://www.ncbi.nlm.nih.gov/pmc/articles/PMC6666362/ https://www.ncbi.nlm.nih.gov/pubmed/31384147 http://dx.doi.org/10.5152/TurkPediatriArs.2018.4658 |
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author | Sülü, Ayşe Başpınar, Osman Şahin, Derya Aydın |
author_facet | Sülü, Ayşe Başpınar, Osman Şahin, Derya Aydın |
author_sort | Sülü, Ayşe |
collection | PubMed |
description | Cutis laxa tip1b is a rare autosomal recessive disorder caused by FBLN 4 mutation and primarily characterized by vascular anomalies. Herein, we present five patients who are the members of the same family. The primary cardiac findings of these patients were giant aortic aneurysms. One 2.5-year-old patient with a massive aneurysm of the ascending aorta died as a result of compression to the heart chambers, trachea, and bronchi. The bentall procedure was performed in three of our patients who are under follow-up. One patient is still under clinical follow-up without surgery. After the diagnosis of the first patient, a genetic study was performed in which FBLN 4 mutations were investigated. Four new patients were detected during genetic screening of the family. Other 29 family members were screened bur were negative in physical examinations and echocardiography. Pedigree is important for early diagnosis of genetic diseases in asymptomatic individuals. |
format | Online Article Text |
id | pubmed-6666362 |
institution | National Center for Biotechnology Information |
language | English |
publishDate | 2019 |
publisher | Kare Publishing |
record_format | MEDLINE/PubMed |
spelling | pubmed-66663622019-08-05 Giant aortic aneurysm due to fibulin- 4 deficiency: case series Sülü, Ayşe Başpınar, Osman Şahin, Derya Aydın Turk Pediatri Ars Case Report Cutis laxa tip1b is a rare autosomal recessive disorder caused by FBLN 4 mutation and primarily characterized by vascular anomalies. Herein, we present five patients who are the members of the same family. The primary cardiac findings of these patients were giant aortic aneurysms. One 2.5-year-old patient with a massive aneurysm of the ascending aorta died as a result of compression to the heart chambers, trachea, and bronchi. The bentall procedure was performed in three of our patients who are under follow-up. One patient is still under clinical follow-up without surgery. After the diagnosis of the first patient, a genetic study was performed in which FBLN 4 mutations were investigated. Four new patients were detected during genetic screening of the family. Other 29 family members were screened bur were negative in physical examinations and echocardiography. Pedigree is important for early diagnosis of genetic diseases in asymptomatic individuals. Kare Publishing 2019-07-11 /pmc/articles/PMC6666362/ /pubmed/31384147 http://dx.doi.org/10.5152/TurkPediatriArs.2018.4658 Text en Copyright: © 2019 Turkish Archives of Pediatrics http://creativecommons.org/licenses/by-nc-sa/4.0 This work is licensed under a Creative Commons Attribution-NonCommercial 4.0 International License |
spellingShingle | Case Report Sülü, Ayşe Başpınar, Osman Şahin, Derya Aydın Giant aortic aneurysm due to fibulin- 4 deficiency: case series |
title | Giant aortic aneurysm due to fibulin- 4 deficiency: case series |
title_full | Giant aortic aneurysm due to fibulin- 4 deficiency: case series |
title_fullStr | Giant aortic aneurysm due to fibulin- 4 deficiency: case series |
title_full_unstemmed | Giant aortic aneurysm due to fibulin- 4 deficiency: case series |
title_short | Giant aortic aneurysm due to fibulin- 4 deficiency: case series |
title_sort | giant aortic aneurysm due to fibulin- 4 deficiency: case series |
topic | Case Report |
url | https://www.ncbi.nlm.nih.gov/pmc/articles/PMC6666362/ https://www.ncbi.nlm.nih.gov/pubmed/31384147 http://dx.doi.org/10.5152/TurkPediatriArs.2018.4658 |
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