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Anomalous origin of left coronary arteries from the pulmonary artery in an asymptomatic adult: An autopsy case report

RATIONALE: Anomalous Origin of Left Coronary Arteries from the Pulmonary Artery (ALCAPA), also known as Bland-White-Garland (BWG), is a rare form of coronary artery anomaly that is usually discovered in the first few months of life. Only rarely can patients with this anomaly reach adulthood without...

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Autores principales: Al Shaarani, Majd, Alzubaidi, Yasir, Jin, Long
Formato: Online Artículo Texto
Lenguaje:English
Publicado: Wolters Kluwer Health 2019
Materias:
Acceso en línea:https://www.ncbi.nlm.nih.gov/pmc/articles/PMC6756624/
https://www.ncbi.nlm.nih.gov/pubmed/31567975
http://dx.doi.org/10.1097/MD.0000000000017212
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author Al Shaarani, Majd
Alzubaidi, Yasir
Jin, Long
author_facet Al Shaarani, Majd
Alzubaidi, Yasir
Jin, Long
author_sort Al Shaarani, Majd
collection PubMed
description RATIONALE: Anomalous Origin of Left Coronary Arteries from the Pulmonary Artery (ALCAPA), also known as Bland-White-Garland (BWG), is a rare form of coronary artery anomaly that is usually discovered in the first few months of life. Only rarely can patients with this anomaly reach adulthood without symptoms. PATIENT CONCERNS: A 28-year-old female was witnessed suddenly collapse with a seizure-like episode by her colleagues at work. DIAGNOSIS AND INTERVENTION: Routine cardiopulmonary resuscitation was performed by emergency medical service technologists. The patient was unable to be revived. Postmortem examination revealed the patient had ALCAPA with a focal chronic ischemic injury of the left ventricle. Moreover, a high take-off of the right coronary artery was also discovered. OUTCOMES: The patient passed away due to ALCAPA. The mechanism of death was cardiac arrhythmia being triggered by myocardial ischemic changes. LESSONS: In the rare cases where ALCAPA manifests in an asymptomatic adult, the mortality rate is very high. This case demonstrates the importance of awareness of such patients living under the tremendous risk of sudden cardiac death.
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spelling pubmed-67566242019-10-07 Anomalous origin of left coronary arteries from the pulmonary artery in an asymptomatic adult: An autopsy case report Al Shaarani, Majd Alzubaidi, Yasir Jin, Long Medicine (Baltimore) 3400 RATIONALE: Anomalous Origin of Left Coronary Arteries from the Pulmonary Artery (ALCAPA), also known as Bland-White-Garland (BWG), is a rare form of coronary artery anomaly that is usually discovered in the first few months of life. Only rarely can patients with this anomaly reach adulthood without symptoms. PATIENT CONCERNS: A 28-year-old female was witnessed suddenly collapse with a seizure-like episode by her colleagues at work. DIAGNOSIS AND INTERVENTION: Routine cardiopulmonary resuscitation was performed by emergency medical service technologists. The patient was unable to be revived. Postmortem examination revealed the patient had ALCAPA with a focal chronic ischemic injury of the left ventricle. Moreover, a high take-off of the right coronary artery was also discovered. OUTCOMES: The patient passed away due to ALCAPA. The mechanism of death was cardiac arrhythmia being triggered by myocardial ischemic changes. LESSONS: In the rare cases where ALCAPA manifests in an asymptomatic adult, the mortality rate is very high. This case demonstrates the importance of awareness of such patients living under the tremendous risk of sudden cardiac death. Wolters Kluwer Health 2019-09-20 /pmc/articles/PMC6756624/ /pubmed/31567975 http://dx.doi.org/10.1097/MD.0000000000017212 Text en Copyright © 2019 the Author(s). Published by Wolters Kluwer Health, Inc. http://creativecommons.org/licenses/by/4.0 This is an open access article distributed under the Creative Commons Attribution License 4.0 (CCBY), which permits unrestricted use, distribution, and reproduction in any medium, provided the original work is properly cited. http://creativecommons.org/licenses/by/4.0
spellingShingle 3400
Al Shaarani, Majd
Alzubaidi, Yasir
Jin, Long
Anomalous origin of left coronary arteries from the pulmonary artery in an asymptomatic adult: An autopsy case report
title Anomalous origin of left coronary arteries from the pulmonary artery in an asymptomatic adult: An autopsy case report
title_full Anomalous origin of left coronary arteries from the pulmonary artery in an asymptomatic adult: An autopsy case report
title_fullStr Anomalous origin of left coronary arteries from the pulmonary artery in an asymptomatic adult: An autopsy case report
title_full_unstemmed Anomalous origin of left coronary arteries from the pulmonary artery in an asymptomatic adult: An autopsy case report
title_short Anomalous origin of left coronary arteries from the pulmonary artery in an asymptomatic adult: An autopsy case report
title_sort anomalous origin of left coronary arteries from the pulmonary artery in an asymptomatic adult: an autopsy case report
topic 3400
url https://www.ncbi.nlm.nih.gov/pmc/articles/PMC6756624/
https://www.ncbi.nlm.nih.gov/pubmed/31567975
http://dx.doi.org/10.1097/MD.0000000000017212
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