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Congenital Lobar Overinflation Presenting with Recurrent Pneumothoraces

Congenital lobar overinflation (CLO) is a rare neonatal developmental anomaly. We present the case of a newborn boy who was born as a first twin at the 26th gestation week, and transferred to the department of pediatric intensive care due to respiratory distress and prematurity. Recurrent pneumothor...

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Detalles Bibliográficos
Autores principales: Hanžič, Nina, Čizmarević, Urban, Žerdin, Matija
Formato: Online Artículo Texto
Lenguaje:English
Publicado: Cureus 2019
Materias:
Acceso en línea:https://www.ncbi.nlm.nih.gov/pmc/articles/PMC6827704/
https://www.ncbi.nlm.nih.gov/pubmed/31754565
http://dx.doi.org/10.7759/cureus.5830
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author Hanžič, Nina
Čizmarević, Urban
Žerdin, Matija
author_facet Hanžič, Nina
Čizmarević, Urban
Žerdin, Matija
author_sort Hanžič, Nina
collection PubMed
description Congenital lobar overinflation (CLO) is a rare neonatal developmental anomaly. We present the case of a newborn boy who was born as a first twin at the 26th gestation week, and transferred to the department of pediatric intensive care due to respiratory distress and prematurity. Recurrent pneumothoraces were observed, and the chest drain was inserted. However, saturation was unsatisfactory although he was intubated and ventilated by synchronized intermittent-mandatory ventilation (SIMV). The chest radiographs showed hyperinflation of the right middle lobe, with mediastinal shift to the left, and atelectasis of the remaining lobes. That caused ventilation and perfusion mismatch and hypoxia, due to a decrease in ventilated lung tissue. When high-frequency ventilation was instituted, he stabilized. Computed tomography (CT) of the chest revealed the cause and the diagnosis of CLO was made. A high index of suspicion is needed when clinical and radiological findings are present in a newborn with respiratory distress and recurrent pneumothoraces to ensure prompt diagnosis and optimal, timely treatment.
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spelling pubmed-68277042019-11-21 Congenital Lobar Overinflation Presenting with Recurrent Pneumothoraces Hanžič, Nina Čizmarević, Urban Žerdin, Matija Cureus Radiology Congenital lobar overinflation (CLO) is a rare neonatal developmental anomaly. We present the case of a newborn boy who was born as a first twin at the 26th gestation week, and transferred to the department of pediatric intensive care due to respiratory distress and prematurity. Recurrent pneumothoraces were observed, and the chest drain was inserted. However, saturation was unsatisfactory although he was intubated and ventilated by synchronized intermittent-mandatory ventilation (SIMV). The chest radiographs showed hyperinflation of the right middle lobe, with mediastinal shift to the left, and atelectasis of the remaining lobes. That caused ventilation and perfusion mismatch and hypoxia, due to a decrease in ventilated lung tissue. When high-frequency ventilation was instituted, he stabilized. Computed tomography (CT) of the chest revealed the cause and the diagnosis of CLO was made. A high index of suspicion is needed when clinical and radiological findings are present in a newborn with respiratory distress and recurrent pneumothoraces to ensure prompt diagnosis and optimal, timely treatment. Cureus 2019-10-03 /pmc/articles/PMC6827704/ /pubmed/31754565 http://dx.doi.org/10.7759/cureus.5830 Text en Copyright © 2019, Hanžič et al. http://creativecommons.org/licenses/by/3.0/ This is an open access article distributed under the terms of the Creative Commons Attribution License, which permits unrestricted use, distribution, and reproduction in any medium, provided the original author and source are credited.
spellingShingle Radiology
Hanžič, Nina
Čizmarević, Urban
Žerdin, Matija
Congenital Lobar Overinflation Presenting with Recurrent Pneumothoraces
title Congenital Lobar Overinflation Presenting with Recurrent Pneumothoraces
title_full Congenital Lobar Overinflation Presenting with Recurrent Pneumothoraces
title_fullStr Congenital Lobar Overinflation Presenting with Recurrent Pneumothoraces
title_full_unstemmed Congenital Lobar Overinflation Presenting with Recurrent Pneumothoraces
title_short Congenital Lobar Overinflation Presenting with Recurrent Pneumothoraces
title_sort congenital lobar overinflation presenting with recurrent pneumothoraces
topic Radiology
url https://www.ncbi.nlm.nih.gov/pmc/articles/PMC6827704/
https://www.ncbi.nlm.nih.gov/pubmed/31754565
http://dx.doi.org/10.7759/cureus.5830
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