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A De Novo Mutation in DYRK1A Causes Syndromic Intellectual Disability: A Chinese Case Report

Autosomal dominant mental retardation-7 (MRD7) is a rare anomaly, characterized by severe intellectual disability, feeding difficulties, behavior abnormalities, and distinctive facial features, including microcephaly, deep-set eyes, large simple ears, and a pointed or bulbous nasal tip. Some studies...

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Detalles Bibliográficos
Autores principales: Qiao, Fengchang, Shao, Binbin, Wang, Chen, Wang, Yan, Zhou, Ran, Liu, Gang, Meng, Lulu, Hu, Ping, Xu, Zhengfeng
Formato: Online Artículo Texto
Lenguaje:English
Publicado: Frontiers Media S.A. 2019
Materias:
Acceso en línea:https://www.ncbi.nlm.nih.gov/pmc/articles/PMC6877748/
https://www.ncbi.nlm.nih.gov/pubmed/31803247
http://dx.doi.org/10.3389/fgene.2019.01194
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author Qiao, Fengchang
Shao, Binbin
Wang, Chen
Wang, Yan
Zhou, Ran
Liu, Gang
Meng, Lulu
Hu, Ping
Xu, Zhengfeng
author_facet Qiao, Fengchang
Shao, Binbin
Wang, Chen
Wang, Yan
Zhou, Ran
Liu, Gang
Meng, Lulu
Hu, Ping
Xu, Zhengfeng
author_sort Qiao, Fengchang
collection PubMed
description Autosomal dominant mental retardation-7 (MRD7) is a rare anomaly, characterized by severe intellectual disability, feeding difficulties, behavior abnormalities, and distinctive facial features, including microcephaly, deep-set eyes, large simple ears, and a pointed or bulbous nasal tip. Some studies show that the disorder has a close correlation with variants in DYRK1A. Herein we described a Chinese girl presenting typical clinical features diagnosed at 4 years old. Whole-exome sequencing of the familial genomic DNA identified a novel mutation c.930C > A (p.Tyr310*) in exon 7 of DYRK1A in the proband. The nonsense mutation was predicted to render the truncation of the protein. Our results suggested that the de novo heterozygous mutation in DYRK1A was responsible for the MRD7 in this Chinese family, which both extended the knowledge of mutation spectrum in MRD7 patients and highlighted the clinical application of exome sequencing.
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spelling pubmed-68777482019-12-04 A De Novo Mutation in DYRK1A Causes Syndromic Intellectual Disability: A Chinese Case Report Qiao, Fengchang Shao, Binbin Wang, Chen Wang, Yan Zhou, Ran Liu, Gang Meng, Lulu Hu, Ping Xu, Zhengfeng Front Genet Genetics Autosomal dominant mental retardation-7 (MRD7) is a rare anomaly, characterized by severe intellectual disability, feeding difficulties, behavior abnormalities, and distinctive facial features, including microcephaly, deep-set eyes, large simple ears, and a pointed or bulbous nasal tip. Some studies show that the disorder has a close correlation with variants in DYRK1A. Herein we described a Chinese girl presenting typical clinical features diagnosed at 4 years old. Whole-exome sequencing of the familial genomic DNA identified a novel mutation c.930C > A (p.Tyr310*) in exon 7 of DYRK1A in the proband. The nonsense mutation was predicted to render the truncation of the protein. Our results suggested that the de novo heterozygous mutation in DYRK1A was responsible for the MRD7 in this Chinese family, which both extended the knowledge of mutation spectrum in MRD7 patients and highlighted the clinical application of exome sequencing. Frontiers Media S.A. 2019-11-19 /pmc/articles/PMC6877748/ /pubmed/31803247 http://dx.doi.org/10.3389/fgene.2019.01194 Text en Copyright © 2019 Qiao, Shao, Wang, Wang, Zhou, Liu, Meng, Hu and Xu http://creativecommons.org/licenses/by/4.0/ This is an open-access article distributed under the terms of the Creative Commons Attribution License (CC BY). The use, distribution or reproduction in other forums is permitted, provided the original author(s) and the copyright owner(s) are credited and that the original publication in this journal is cited, in accordance with accepted academic practice. No use, distribution or reproduction is permitted which does not comply with these terms.
spellingShingle Genetics
Qiao, Fengchang
Shao, Binbin
Wang, Chen
Wang, Yan
Zhou, Ran
Liu, Gang
Meng, Lulu
Hu, Ping
Xu, Zhengfeng
A De Novo Mutation in DYRK1A Causes Syndromic Intellectual Disability: A Chinese Case Report
title A De Novo Mutation in DYRK1A Causes Syndromic Intellectual Disability: A Chinese Case Report
title_full A De Novo Mutation in DYRK1A Causes Syndromic Intellectual Disability: A Chinese Case Report
title_fullStr A De Novo Mutation in DYRK1A Causes Syndromic Intellectual Disability: A Chinese Case Report
title_full_unstemmed A De Novo Mutation in DYRK1A Causes Syndromic Intellectual Disability: A Chinese Case Report
title_short A De Novo Mutation in DYRK1A Causes Syndromic Intellectual Disability: A Chinese Case Report
title_sort de novo mutation in dyrk1a causes syndromic intellectual disability: a chinese case report
topic Genetics
url https://www.ncbi.nlm.nih.gov/pmc/articles/PMC6877748/
https://www.ncbi.nlm.nih.gov/pubmed/31803247
http://dx.doi.org/10.3389/fgene.2019.01194
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