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Primary Immunodeficiency with Severe Multi-Organ Immune Dysregulation

Polyglandular autoimmune syndrome type 1, also known as autoimmune polyendocrinopathy-candidiasis-ectodermal dystrophy (APECED), is a rare primary immunodeficiency disorder with multi-organ involvement. Besides for being predisposed to severe life-threatening infections, patients with APECED are als...

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Detalles Bibliográficos
Autor principal: Gavrilova, Tatyana
Formato: Online Artículo Texto
Lenguaje:English
Publicado: Hindawi 2019
Materias:
Acceso en línea:https://www.ncbi.nlm.nih.gov/pmc/articles/PMC6949663/
https://www.ncbi.nlm.nih.gov/pubmed/31956453
http://dx.doi.org/10.1155/2019/8746249
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author Gavrilova, Tatyana
author_facet Gavrilova, Tatyana
author_sort Gavrilova, Tatyana
collection PubMed
description Polyglandular autoimmune syndrome type 1, also known as autoimmune polyendocrinopathy-candidiasis-ectodermal dystrophy (APECED), is a rare primary immunodeficiency disorder with multi-organ involvement. Besides for being predisposed to severe life-threatening infections, patients with APECED are also prone to organ impairment secondary to severe autoimmunity. As this is an autosomal recessive disorder, a biallelic mutation in the AIRE gene is responsible for APECED. The author presents a case of APECED with a single AIRE mutation. Whole exome sequencing identified a mutation in the BTNL2 gene that the author suggests may have contributed to the patient's presentation.
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spelling pubmed-69496632020-01-17 Primary Immunodeficiency with Severe Multi-Organ Immune Dysregulation Gavrilova, Tatyana Case Reports Immunol Case Report Polyglandular autoimmune syndrome type 1, also known as autoimmune polyendocrinopathy-candidiasis-ectodermal dystrophy (APECED), is a rare primary immunodeficiency disorder with multi-organ involvement. Besides for being predisposed to severe life-threatening infections, patients with APECED are also prone to organ impairment secondary to severe autoimmunity. As this is an autosomal recessive disorder, a biallelic mutation in the AIRE gene is responsible for APECED. The author presents a case of APECED with a single AIRE mutation. Whole exome sequencing identified a mutation in the BTNL2 gene that the author suggests may have contributed to the patient's presentation. Hindawi 2019-12-28 /pmc/articles/PMC6949663/ /pubmed/31956453 http://dx.doi.org/10.1155/2019/8746249 Text en Copyright © 2019 Tatyana Gavrilova. http://creativecommons.org/licenses/by/4.0/ This is an open access article distributed under the Creative Commons Attribution License, which permits unrestricted use, distribution, and reproduction in any medium, provided the original work is properly cited.
spellingShingle Case Report
Gavrilova, Tatyana
Primary Immunodeficiency with Severe Multi-Organ Immune Dysregulation
title Primary Immunodeficiency with Severe Multi-Organ Immune Dysregulation
title_full Primary Immunodeficiency with Severe Multi-Organ Immune Dysregulation
title_fullStr Primary Immunodeficiency with Severe Multi-Organ Immune Dysregulation
title_full_unstemmed Primary Immunodeficiency with Severe Multi-Organ Immune Dysregulation
title_short Primary Immunodeficiency with Severe Multi-Organ Immune Dysregulation
title_sort primary immunodeficiency with severe multi-organ immune dysregulation
topic Case Report
url https://www.ncbi.nlm.nih.gov/pmc/articles/PMC6949663/
https://www.ncbi.nlm.nih.gov/pubmed/31956453
http://dx.doi.org/10.1155/2019/8746249
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