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Difficult airway associated with bifid glottis and coexistent subglottic stenosis in a patient with Pallister–Hall syndrome: a case report
BACKGROUND: Pallister–Hall syndrome is a rare disorder characterized by hypothalamic hamartoma, hypopituitarism, bifid epiglottis, and micrognathia. CASE PRESENTATION: We describe the airway management under general anesthesia of a 15-year-old female with Pallister–Hall syndrome whose airway was com...
Autores principales: | , , , |
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Formato: | Online Artículo Texto |
Lenguaje: | English |
Publicado: |
Springer Berlin Heidelberg
2018
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Materias: | |
Acceso en línea: | https://www.ncbi.nlm.nih.gov/pmc/articles/PMC6966929/ https://www.ncbi.nlm.nih.gov/pubmed/32025855 http://dx.doi.org/10.1186/s40981-018-0158-1 |
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author | Oe, Yukimura Godai, Kohei Masuda, Mina Kanmura, Yuichi |
author_facet | Oe, Yukimura Godai, Kohei Masuda, Mina Kanmura, Yuichi |
author_sort | Oe, Yukimura |
collection | PubMed |
description | BACKGROUND: Pallister–Hall syndrome is a rare disorder characterized by hypothalamic hamartoma, hypopituitarism, bifid epiglottis, and micrognathia. CASE PRESENTATION: We describe the airway management under general anesthesia of a 15-year-old female with Pallister–Hall syndrome whose airway was compromised with bifid epiglottis and acquired subglottic stenosis. The three options considered for airway management were tracheal intubation, a supraglottic device, and surgical tracheotomy. Tracheal intubation provides a secured airway, but extubation can be difficult. A supraglottic device minimizes airway injury, but it does not completely protect the airway from aspiration. CONCLUSIONS: The patient’s airway was successfully managed using a supraglottic device with aspiration prophylaxis. Airway management devices should be selected according to each patients’ individual circumstances. ELECTRONIC SUPPLEMENTARY MATERIAL: The online version of this article (10.1186/s40981-018-0158-1) contains supplementary material, which is available to authorized users. |
format | Online Article Text |
id | pubmed-6966929 |
institution | National Center for Biotechnology Information |
language | English |
publishDate | 2018 |
publisher | Springer Berlin Heidelberg |
record_format | MEDLINE/PubMed |
spelling | pubmed-69669292020-02-04 Difficult airway associated with bifid glottis and coexistent subglottic stenosis in a patient with Pallister–Hall syndrome: a case report Oe, Yukimura Godai, Kohei Masuda, Mina Kanmura, Yuichi JA Clin Rep Case Report BACKGROUND: Pallister–Hall syndrome is a rare disorder characterized by hypothalamic hamartoma, hypopituitarism, bifid epiglottis, and micrognathia. CASE PRESENTATION: We describe the airway management under general anesthesia of a 15-year-old female with Pallister–Hall syndrome whose airway was compromised with bifid epiglottis and acquired subglottic stenosis. The three options considered for airway management were tracheal intubation, a supraglottic device, and surgical tracheotomy. Tracheal intubation provides a secured airway, but extubation can be difficult. A supraglottic device minimizes airway injury, but it does not completely protect the airway from aspiration. CONCLUSIONS: The patient’s airway was successfully managed using a supraglottic device with aspiration prophylaxis. Airway management devices should be selected according to each patients’ individual circumstances. ELECTRONIC SUPPLEMENTARY MATERIAL: The online version of this article (10.1186/s40981-018-0158-1) contains supplementary material, which is available to authorized users. Springer Berlin Heidelberg 2018-02-23 /pmc/articles/PMC6966929/ /pubmed/32025855 http://dx.doi.org/10.1186/s40981-018-0158-1 Text en © The Author(s) 2018 Open Access This article is distributed under the terms of the Creative Commons Attribution 4.0 International License (http://creativecommons.org/licenses/by/4.0/), which permits unrestricted use, distribution, and reproduction in any medium, provided you give appropriate credit to the original author(s) and the source, provide a link to the Creative Commons license, and indicate if changes were made. |
spellingShingle | Case Report Oe, Yukimura Godai, Kohei Masuda, Mina Kanmura, Yuichi Difficult airway associated with bifid glottis and coexistent subglottic stenosis in a patient with Pallister–Hall syndrome: a case report |
title | Difficult airway associated with bifid glottis and coexistent subglottic stenosis in a patient with Pallister–Hall syndrome: a case report |
title_full | Difficult airway associated with bifid glottis and coexistent subglottic stenosis in a patient with Pallister–Hall syndrome: a case report |
title_fullStr | Difficult airway associated with bifid glottis and coexistent subglottic stenosis in a patient with Pallister–Hall syndrome: a case report |
title_full_unstemmed | Difficult airway associated with bifid glottis and coexistent subglottic stenosis in a patient with Pallister–Hall syndrome: a case report |
title_short | Difficult airway associated with bifid glottis and coexistent subglottic stenosis in a patient with Pallister–Hall syndrome: a case report |
title_sort | difficult airway associated with bifid glottis and coexistent subglottic stenosis in a patient with pallister–hall syndrome: a case report |
topic | Case Report |
url | https://www.ncbi.nlm.nih.gov/pmc/articles/PMC6966929/ https://www.ncbi.nlm.nih.gov/pubmed/32025855 http://dx.doi.org/10.1186/s40981-018-0158-1 |
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