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Brain metabolism and neurological symptoms in combined malonic and methylmalonic aciduria
Combined malonic and methylmalonic aciduria (CMAMMA) is an inborn error of metabolism which has been proposed being a benign condition. However, older patients may present with neurological manifestations such as seizures, memory problems, psychiatric problems and/ or cognitive decline. In fibroblas...
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Formato: | Online Artículo Texto |
Lenguaje: | English |
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BioMed Central
2020
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Acceso en línea: | https://www.ncbi.nlm.nih.gov/pmc/articles/PMC6977288/ https://www.ncbi.nlm.nih.gov/pubmed/31969167 http://dx.doi.org/10.1186/s13023-020-1299-7 |
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author | Tucci, Sara |
author_facet | Tucci, Sara |
author_sort | Tucci, Sara |
collection | PubMed |
description | Combined malonic and methylmalonic aciduria (CMAMMA) is an inborn error of metabolism which has been proposed being a benign condition. However, older patients may present with neurological manifestations such as seizures, memory problems, psychiatric problems and/ or cognitive decline. In fibroblasts from CMAMMA patients we have recently demonstrated a dysregulation of energy metabolism with increased dependency on β-oxidation for energy production. Because of the inability of the brain to rely efficiently on this pathway to retrieve the required energy to a great extent, we hypothesize an alternative disease-causing mechanism that does not only include the accumulation of the metabolites malonic and methylmalonic acids. Here, we suggest a novel hypothesis on the possible pathophysiological mechanism responsible for the development of neurological symptoms in the long-run. |
format | Online Article Text |
id | pubmed-6977288 |
institution | National Center for Biotechnology Information |
language | English |
publishDate | 2020 |
publisher | BioMed Central |
record_format | MEDLINE/PubMed |
spelling | pubmed-69772882020-01-28 Brain metabolism and neurological symptoms in combined malonic and methylmalonic aciduria Tucci, Sara Orphanet J Rare Dis Letter to the Editor Combined malonic and methylmalonic aciduria (CMAMMA) is an inborn error of metabolism which has been proposed being a benign condition. However, older patients may present with neurological manifestations such as seizures, memory problems, psychiatric problems and/ or cognitive decline. In fibroblasts from CMAMMA patients we have recently demonstrated a dysregulation of energy metabolism with increased dependency on β-oxidation for energy production. Because of the inability of the brain to rely efficiently on this pathway to retrieve the required energy to a great extent, we hypothesize an alternative disease-causing mechanism that does not only include the accumulation of the metabolites malonic and methylmalonic acids. Here, we suggest a novel hypothesis on the possible pathophysiological mechanism responsible for the development of neurological symptoms in the long-run. BioMed Central 2020-01-22 /pmc/articles/PMC6977288/ /pubmed/31969167 http://dx.doi.org/10.1186/s13023-020-1299-7 Text en © The Author(s). 2020 Open AccessThis article is distributed under the terms of the Creative Commons Attribution 4.0 International License (http://creativecommons.org/licenses/by/4.0/), which permits unrestricted use, distribution, and reproduction in any medium, provided you give appropriate credit to the original author(s) and the source, provide a link to the Creative Commons license, and indicate if changes were made. The Creative Commons Public Domain Dedication waiver (http://creativecommons.org/publicdomain/zero/1.0/) applies to the data made available in this article, unless otherwise stated. |
spellingShingle | Letter to the Editor Tucci, Sara Brain metabolism and neurological symptoms in combined malonic and methylmalonic aciduria |
title | Brain metabolism and neurological symptoms in combined malonic and methylmalonic aciduria |
title_full | Brain metabolism and neurological symptoms in combined malonic and methylmalonic aciduria |
title_fullStr | Brain metabolism and neurological symptoms in combined malonic and methylmalonic aciduria |
title_full_unstemmed | Brain metabolism and neurological symptoms in combined malonic and methylmalonic aciduria |
title_short | Brain metabolism and neurological symptoms in combined malonic and methylmalonic aciduria |
title_sort | brain metabolism and neurological symptoms in combined malonic and methylmalonic aciduria |
topic | Letter to the Editor |
url | https://www.ncbi.nlm.nih.gov/pmc/articles/PMC6977288/ https://www.ncbi.nlm.nih.gov/pubmed/31969167 http://dx.doi.org/10.1186/s13023-020-1299-7 |
work_keys_str_mv | AT tuccisara brainmetabolismandneurologicalsymptomsincombinedmalonicandmethylmalonicaciduria |