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Successful Treatment of Anti-Factor H Antibody-Associated Atypical Hemolytic Uremic Syndrome

Anti-complement factor H (CFH) autoantibody (Ab)-associated atypical hemolytic uremic syndrome (aHUS) has a poor prognosis in terms of frequent relapses. Although eculizumab is an effective treatment for this type of aHUS, the method of eculizumab discontinuation is not yet established. Herein, we r...

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Autores principales: Kise, Tomoo, Fukuyama, Shigeru, Uehara, Masatsugu
Formato: Online Artículo Texto
Lenguaje:English
Publicado: Wolters Kluwer - Medknow 2020
Materias:
Acceso en línea:https://www.ncbi.nlm.nih.gov/pmc/articles/PMC6977382/
https://www.ncbi.nlm.nih.gov/pubmed/32015599
http://dx.doi.org/10.4103/ijn.IJN_336_18
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author Kise, Tomoo
Fukuyama, Shigeru
Uehara, Masatsugu
author_facet Kise, Tomoo
Fukuyama, Shigeru
Uehara, Masatsugu
author_sort Kise, Tomoo
collection PubMed
description Anti-complement factor H (CFH) autoantibody (Ab)-associated atypical hemolytic uremic syndrome (aHUS) has a poor prognosis in terms of frequent relapses. Although eculizumab is an effective treatment for this type of aHUS, the method of eculizumab discontinuation is not yet established. Herein, we report a case of anti-CFH Ab-associated aHUS in a 6-year-old boy. Eculizumab induction therapy following plasma exchange improved his condition. After 14 months, eculizumab was discontinued because of meningococcal bacteremia. After 6 months of eculizumab cessation, prednisolone (20 mg/alternate days) and mycophenolate mofetil (500 mg/day) were initiated. There were no relapses or increases in anti-CFH Ab titers for 26 months after treatment initiation. We believe that eculizumab induction therapy, following plasma exchange and maintenance therapy with immunosuppressants after eculizumab discontinuation are effective treatments for anti-CFH Ab-related aHUS.
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spelling pubmed-69773822020-02-03 Successful Treatment of Anti-Factor H Antibody-Associated Atypical Hemolytic Uremic Syndrome Kise, Tomoo Fukuyama, Shigeru Uehara, Masatsugu Indian J Nephrol Case Report Anti-complement factor H (CFH) autoantibody (Ab)-associated atypical hemolytic uremic syndrome (aHUS) has a poor prognosis in terms of frequent relapses. Although eculizumab is an effective treatment for this type of aHUS, the method of eculizumab discontinuation is not yet established. Herein, we report a case of anti-CFH Ab-associated aHUS in a 6-year-old boy. Eculizumab induction therapy following plasma exchange improved his condition. After 14 months, eculizumab was discontinued because of meningococcal bacteremia. After 6 months of eculizumab cessation, prednisolone (20 mg/alternate days) and mycophenolate mofetil (500 mg/day) were initiated. There were no relapses or increases in anti-CFH Ab titers for 26 months after treatment initiation. We believe that eculizumab induction therapy, following plasma exchange and maintenance therapy with immunosuppressants after eculizumab discontinuation are effective treatments for anti-CFH Ab-related aHUS. Wolters Kluwer - Medknow 2020 2019-09-06 /pmc/articles/PMC6977382/ /pubmed/32015599 http://dx.doi.org/10.4103/ijn.IJN_336_18 Text en Copyright: © 2020 Indian Journal of Nephrology http://creativecommons.org/licenses/by-nc-sa/4.0 This is an open access journal, and articles are distributed under the terms of the Creative Commons Attribution-NonCommercial-ShareAlike 4.0 License, which allows others to remix, tweak, and build upon the work non-commercially, as long as appropriate credit is given and the new creations are licensed under the identical terms.
spellingShingle Case Report
Kise, Tomoo
Fukuyama, Shigeru
Uehara, Masatsugu
Successful Treatment of Anti-Factor H Antibody-Associated Atypical Hemolytic Uremic Syndrome
title Successful Treatment of Anti-Factor H Antibody-Associated Atypical Hemolytic Uremic Syndrome
title_full Successful Treatment of Anti-Factor H Antibody-Associated Atypical Hemolytic Uremic Syndrome
title_fullStr Successful Treatment of Anti-Factor H Antibody-Associated Atypical Hemolytic Uremic Syndrome
title_full_unstemmed Successful Treatment of Anti-Factor H Antibody-Associated Atypical Hemolytic Uremic Syndrome
title_short Successful Treatment of Anti-Factor H Antibody-Associated Atypical Hemolytic Uremic Syndrome
title_sort successful treatment of anti-factor h antibody-associated atypical hemolytic uremic syndrome
topic Case Report
url https://www.ncbi.nlm.nih.gov/pmc/articles/PMC6977382/
https://www.ncbi.nlm.nih.gov/pubmed/32015599
http://dx.doi.org/10.4103/ijn.IJN_336_18
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