Intraluminal Duplication of the Terminal Ileum with Ectopic Gastric Mucosa in an Infant: A Rare Cause of Intussusception
Enteric duplication cysts are rare malformations mostly diagnosed before the age of two, with varied clinical presentations. Ectopic gastrointestinal epithelium can be present, and management involves surgical resection. A three-month-old girl presented with rectal bleeding due to an ileocolic intus...
Autores principales: | , , , , , |
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Formato: | Online Artículo Texto |
Lenguaje: | English |
Publicado: |
Hindawi
2020
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Materias: | |
Acceso en línea: | https://www.ncbi.nlm.nih.gov/pmc/articles/PMC7007750/ https://www.ncbi.nlm.nih.gov/pubmed/32047690 http://dx.doi.org/10.1155/2020/6898795 |
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author | Paradiso, Filomena Valentina Merli, Laura Silvaroli, Sara Fiorentino, Vincenzo Ricci, Riccardo Nanni, Lorenzo |
author_facet | Paradiso, Filomena Valentina Merli, Laura Silvaroli, Sara Fiorentino, Vincenzo Ricci, Riccardo Nanni, Lorenzo |
author_sort | Paradiso, Filomena Valentina |
collection | PubMed |
description | Enteric duplication cysts are rare malformations mostly diagnosed before the age of two, with varied clinical presentations. Ectopic gastrointestinal epithelium can be present, and management involves surgical resection. A three-month-old girl presented with rectal bleeding due to an ileocolic intussusception. Abdominal ultrasound revealed a target sign in the right upper part of the abdomen. At hydrostatic contrast enema, an incomplete reduction of the intussusception was obtained: only a trickle of contrast material entered the terminal ileum. An exploratory laparotomy ensued with manual reduction of the intussusception. At the end of the maneuver, a soft intraluminal mass was palpated within the ileocecal valve. Thus, an ileocecal resection was performed. At histology, an intraluminal enteric duplication cyst was documented, containing ectopic gastric mucosa. Secondary intussusception should be suspected even in infants in case of abnormal findings at hydrostatic contrast enema. Intraluminal enteric duplication cysts may be a rare cause of intussusception. |
format | Online Article Text |
id | pubmed-7007750 |
institution | National Center for Biotechnology Information |
language | English |
publishDate | 2020 |
publisher | Hindawi |
record_format | MEDLINE/PubMed |
spelling | pubmed-70077502020-02-11 Intraluminal Duplication of the Terminal Ileum with Ectopic Gastric Mucosa in an Infant: A Rare Cause of Intussusception Paradiso, Filomena Valentina Merli, Laura Silvaroli, Sara Fiorentino, Vincenzo Ricci, Riccardo Nanni, Lorenzo Case Rep Pediatr Case Report Enteric duplication cysts are rare malformations mostly diagnosed before the age of two, with varied clinical presentations. Ectopic gastrointestinal epithelium can be present, and management involves surgical resection. A three-month-old girl presented with rectal bleeding due to an ileocolic intussusception. Abdominal ultrasound revealed a target sign in the right upper part of the abdomen. At hydrostatic contrast enema, an incomplete reduction of the intussusception was obtained: only a trickle of contrast material entered the terminal ileum. An exploratory laparotomy ensued with manual reduction of the intussusception. At the end of the maneuver, a soft intraluminal mass was palpated within the ileocecal valve. Thus, an ileocecal resection was performed. At histology, an intraluminal enteric duplication cyst was documented, containing ectopic gastric mucosa. Secondary intussusception should be suspected even in infants in case of abnormal findings at hydrostatic contrast enema. Intraluminal enteric duplication cysts may be a rare cause of intussusception. Hindawi 2020-01-27 /pmc/articles/PMC7007750/ /pubmed/32047690 http://dx.doi.org/10.1155/2020/6898795 Text en Copyright © 2020 Filomena Valentina Paradiso et al. http://creativecommons.org/licenses/by/4.0/ This is an open access article distributed under the Creative Commons Attribution License, which permits unrestricted use, distribution, and reproduction in any medium, provided the original work is properly cited. |
spellingShingle | Case Report Paradiso, Filomena Valentina Merli, Laura Silvaroli, Sara Fiorentino, Vincenzo Ricci, Riccardo Nanni, Lorenzo Intraluminal Duplication of the Terminal Ileum with Ectopic Gastric Mucosa in an Infant: A Rare Cause of Intussusception |
title | Intraluminal Duplication of the Terminal Ileum with Ectopic Gastric Mucosa in an Infant: A Rare Cause of Intussusception |
title_full | Intraluminal Duplication of the Terminal Ileum with Ectopic Gastric Mucosa in an Infant: A Rare Cause of Intussusception |
title_fullStr | Intraluminal Duplication of the Terminal Ileum with Ectopic Gastric Mucosa in an Infant: A Rare Cause of Intussusception |
title_full_unstemmed | Intraluminal Duplication of the Terminal Ileum with Ectopic Gastric Mucosa in an Infant: A Rare Cause of Intussusception |
title_short | Intraluminal Duplication of the Terminal Ileum with Ectopic Gastric Mucosa in an Infant: A Rare Cause of Intussusception |
title_sort | intraluminal duplication of the terminal ileum with ectopic gastric mucosa in an infant: a rare cause of intussusception |
topic | Case Report |
url | https://www.ncbi.nlm.nih.gov/pmc/articles/PMC7007750/ https://www.ncbi.nlm.nih.gov/pubmed/32047690 http://dx.doi.org/10.1155/2020/6898795 |
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