Intraluminal Duplication of the Terminal Ileum with Ectopic Gastric Mucosa in an Infant: A Rare Cause of Intussusception

Enteric duplication cysts are rare malformations mostly diagnosed before the age of two, with varied clinical presentations. Ectopic gastrointestinal epithelium can be present, and management involves surgical resection. A three-month-old girl presented with rectal bleeding due to an ileocolic intus...

Descripción completa

Detalles Bibliográficos
Autores principales: Paradiso, Filomena Valentina, Merli, Laura, Silvaroli, Sara, Fiorentino, Vincenzo, Ricci, Riccardo, Nanni, Lorenzo
Formato: Online Artículo Texto
Lenguaje:English
Publicado: Hindawi 2020
Materias:
Acceso en línea:https://www.ncbi.nlm.nih.gov/pmc/articles/PMC7007750/
https://www.ncbi.nlm.nih.gov/pubmed/32047690
http://dx.doi.org/10.1155/2020/6898795
_version_ 1783495364255416320
author Paradiso, Filomena Valentina
Merli, Laura
Silvaroli, Sara
Fiorentino, Vincenzo
Ricci, Riccardo
Nanni, Lorenzo
author_facet Paradiso, Filomena Valentina
Merli, Laura
Silvaroli, Sara
Fiorentino, Vincenzo
Ricci, Riccardo
Nanni, Lorenzo
author_sort Paradiso, Filomena Valentina
collection PubMed
description Enteric duplication cysts are rare malformations mostly diagnosed before the age of two, with varied clinical presentations. Ectopic gastrointestinal epithelium can be present, and management involves surgical resection. A three-month-old girl presented with rectal bleeding due to an ileocolic intussusception. Abdominal ultrasound revealed a target sign in the right upper part of the abdomen. At hydrostatic contrast enema, an incomplete reduction of the intussusception was obtained: only a trickle of contrast material entered the terminal ileum. An exploratory laparotomy ensued with manual reduction of the intussusception. At the end of the maneuver, a soft intraluminal mass was palpated within the ileocecal valve. Thus, an ileocecal resection was performed. At histology, an intraluminal enteric duplication cyst was documented, containing ectopic gastric mucosa. Secondary intussusception should be suspected even in infants in case of abnormal findings at hydrostatic contrast enema. Intraluminal enteric duplication cysts may be a rare cause of intussusception.
format Online
Article
Text
id pubmed-7007750
institution National Center for Biotechnology Information
language English
publishDate 2020
publisher Hindawi
record_format MEDLINE/PubMed
spelling pubmed-70077502020-02-11 Intraluminal Duplication of the Terminal Ileum with Ectopic Gastric Mucosa in an Infant: A Rare Cause of Intussusception Paradiso, Filomena Valentina Merli, Laura Silvaroli, Sara Fiorentino, Vincenzo Ricci, Riccardo Nanni, Lorenzo Case Rep Pediatr Case Report Enteric duplication cysts are rare malformations mostly diagnosed before the age of two, with varied clinical presentations. Ectopic gastrointestinal epithelium can be present, and management involves surgical resection. A three-month-old girl presented with rectal bleeding due to an ileocolic intussusception. Abdominal ultrasound revealed a target sign in the right upper part of the abdomen. At hydrostatic contrast enema, an incomplete reduction of the intussusception was obtained: only a trickle of contrast material entered the terminal ileum. An exploratory laparotomy ensued with manual reduction of the intussusception. At the end of the maneuver, a soft intraluminal mass was palpated within the ileocecal valve. Thus, an ileocecal resection was performed. At histology, an intraluminal enteric duplication cyst was documented, containing ectopic gastric mucosa. Secondary intussusception should be suspected even in infants in case of abnormal findings at hydrostatic contrast enema. Intraluminal enteric duplication cysts may be a rare cause of intussusception. Hindawi 2020-01-27 /pmc/articles/PMC7007750/ /pubmed/32047690 http://dx.doi.org/10.1155/2020/6898795 Text en Copyright © 2020 Filomena Valentina Paradiso et al. http://creativecommons.org/licenses/by/4.0/ This is an open access article distributed under the Creative Commons Attribution License, which permits unrestricted use, distribution, and reproduction in any medium, provided the original work is properly cited.
spellingShingle Case Report
Paradiso, Filomena Valentina
Merli, Laura
Silvaroli, Sara
Fiorentino, Vincenzo
Ricci, Riccardo
Nanni, Lorenzo
Intraluminal Duplication of the Terminal Ileum with Ectopic Gastric Mucosa in an Infant: A Rare Cause of Intussusception
title Intraluminal Duplication of the Terminal Ileum with Ectopic Gastric Mucosa in an Infant: A Rare Cause of Intussusception
title_full Intraluminal Duplication of the Terminal Ileum with Ectopic Gastric Mucosa in an Infant: A Rare Cause of Intussusception
title_fullStr Intraluminal Duplication of the Terminal Ileum with Ectopic Gastric Mucosa in an Infant: A Rare Cause of Intussusception
title_full_unstemmed Intraluminal Duplication of the Terminal Ileum with Ectopic Gastric Mucosa in an Infant: A Rare Cause of Intussusception
title_short Intraluminal Duplication of the Terminal Ileum with Ectopic Gastric Mucosa in an Infant: A Rare Cause of Intussusception
title_sort intraluminal duplication of the terminal ileum with ectopic gastric mucosa in an infant: a rare cause of intussusception
topic Case Report
url https://www.ncbi.nlm.nih.gov/pmc/articles/PMC7007750/
https://www.ncbi.nlm.nih.gov/pubmed/32047690
http://dx.doi.org/10.1155/2020/6898795
work_keys_str_mv AT paradisofilomenavalentina intraluminalduplicationoftheterminalileumwithectopicgastricmucosainaninfantararecauseofintussusception
AT merlilaura intraluminalduplicationoftheterminalileumwithectopicgastricmucosainaninfantararecauseofintussusception
AT silvarolisara intraluminalduplicationoftheterminalileumwithectopicgastricmucosainaninfantararecauseofintussusception
AT fiorentinovincenzo intraluminalduplicationoftheterminalileumwithectopicgastricmucosainaninfantararecauseofintussusception
AT ricciriccardo intraluminalduplicationoftheterminalileumwithectopicgastricmucosainaninfantararecauseofintussusception
AT nannilorenzo intraluminalduplicationoftheterminalileumwithectopicgastricmucosainaninfantararecauseofintussusception