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Identification and Characterization of BTD Gene Mutations in Jordanian Children with Biotinidase Deficiency

Biotinidase deficiency is an autosomal recessive metabolic disorder whose diagnosis currently depends on clinical symptoms and a biotinidase enzyme assay. This study aimed to investigate the mutational status and enzymatic activity of biotinidase deficiency in seven unrelated Jordanian families incl...

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Autores principales: AL-Eitan, Laith N., Alqa’qa’, Kifah, Amayreh, Wajdi, Khasawneh, Rame, Aljamal, Hanan, Al-Abed, Mamoon, Haddad, Yazan, Rawashdeh, Tamara, Jaradat, Zaher, Haddad, Hazem
Formato: Online Artículo Texto
Lenguaje:English
Publicado: MDPI 2020
Materias:
Acceso en línea:https://www.ncbi.nlm.nih.gov/pmc/articles/PMC7151559/
https://www.ncbi.nlm.nih.gov/pubmed/31973013
http://dx.doi.org/10.3390/jpm10010004
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author AL-Eitan, Laith N.
Alqa’qa’, Kifah
Amayreh, Wajdi
Khasawneh, Rame
Aljamal, Hanan
Al-Abed, Mamoon
Haddad, Yazan
Rawashdeh, Tamara
Jaradat, Zaher
Haddad, Hazem
author_facet AL-Eitan, Laith N.
Alqa’qa’, Kifah
Amayreh, Wajdi
Khasawneh, Rame
Aljamal, Hanan
Al-Abed, Mamoon
Haddad, Yazan
Rawashdeh, Tamara
Jaradat, Zaher
Haddad, Hazem
author_sort AL-Eitan, Laith N.
collection PubMed
description Biotinidase deficiency is an autosomal recessive metabolic disorder whose diagnosis currently depends on clinical symptoms and a biotinidase enzyme assay. This study aimed to investigate the mutational status and enzymatic activity of biotinidase deficiency in seven unrelated Jordanian families including 10 patients and 17 healthy family members. Amplified DNA was analyzed by the automated Sanger sequencing method, and the enzymatic assay was performed using a colorimetric assessment. Biotinidase level was significantly lower (p < 0.001) in BTD children compare to their non-affected family members. Genetic sequencing revealed six different mutations in Jordanian patients. One mutation was novel and located in exon 4, which could be a prevalent mutation for biotinidase deficiency in the Jordanian population. Identification of these common mutations and combing the enzymatic activity with genotypic data will help clinicians with regard to better genetic counseling and management through implementing prevention programs in the future.
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spelling pubmed-71515592020-04-20 Identification and Characterization of BTD Gene Mutations in Jordanian Children with Biotinidase Deficiency AL-Eitan, Laith N. Alqa’qa’, Kifah Amayreh, Wajdi Khasawneh, Rame Aljamal, Hanan Al-Abed, Mamoon Haddad, Yazan Rawashdeh, Tamara Jaradat, Zaher Haddad, Hazem J Pers Med Article Biotinidase deficiency is an autosomal recessive metabolic disorder whose diagnosis currently depends on clinical symptoms and a biotinidase enzyme assay. This study aimed to investigate the mutational status and enzymatic activity of biotinidase deficiency in seven unrelated Jordanian families including 10 patients and 17 healthy family members. Amplified DNA was analyzed by the automated Sanger sequencing method, and the enzymatic assay was performed using a colorimetric assessment. Biotinidase level was significantly lower (p < 0.001) in BTD children compare to their non-affected family members. Genetic sequencing revealed six different mutations in Jordanian patients. One mutation was novel and located in exon 4, which could be a prevalent mutation for biotinidase deficiency in the Jordanian population. Identification of these common mutations and combing the enzymatic activity with genotypic data will help clinicians with regard to better genetic counseling and management through implementing prevention programs in the future. MDPI 2020-01-21 /pmc/articles/PMC7151559/ /pubmed/31973013 http://dx.doi.org/10.3390/jpm10010004 Text en © 2020 by the authors. Licensee MDPI, Basel, Switzerland. This article is an open access article distributed under the terms and conditions of the Creative Commons Attribution (CC BY) license (http://creativecommons.org/licenses/by/4.0/).
spellingShingle Article
AL-Eitan, Laith N.
Alqa’qa’, Kifah
Amayreh, Wajdi
Khasawneh, Rame
Aljamal, Hanan
Al-Abed, Mamoon
Haddad, Yazan
Rawashdeh, Tamara
Jaradat, Zaher
Haddad, Hazem
Identification and Characterization of BTD Gene Mutations in Jordanian Children with Biotinidase Deficiency
title Identification and Characterization of BTD Gene Mutations in Jordanian Children with Biotinidase Deficiency
title_full Identification and Characterization of BTD Gene Mutations in Jordanian Children with Biotinidase Deficiency
title_fullStr Identification and Characterization of BTD Gene Mutations in Jordanian Children with Biotinidase Deficiency
title_full_unstemmed Identification and Characterization of BTD Gene Mutations in Jordanian Children with Biotinidase Deficiency
title_short Identification and Characterization of BTD Gene Mutations in Jordanian Children with Biotinidase Deficiency
title_sort identification and characterization of btd gene mutations in jordanian children with biotinidase deficiency
topic Article
url https://www.ncbi.nlm.nih.gov/pmc/articles/PMC7151559/
https://www.ncbi.nlm.nih.gov/pubmed/31973013
http://dx.doi.org/10.3390/jpm10010004
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