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Identification and Characterization of BTD Gene Mutations in Jordanian Children with Biotinidase Deficiency
Biotinidase deficiency is an autosomal recessive metabolic disorder whose diagnosis currently depends on clinical symptoms and a biotinidase enzyme assay. This study aimed to investigate the mutational status and enzymatic activity of biotinidase deficiency in seven unrelated Jordanian families incl...
Autores principales: | , , , , , , , , , |
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Formato: | Online Artículo Texto |
Lenguaje: | English |
Publicado: |
MDPI
2020
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Materias: | |
Acceso en línea: | https://www.ncbi.nlm.nih.gov/pmc/articles/PMC7151559/ https://www.ncbi.nlm.nih.gov/pubmed/31973013 http://dx.doi.org/10.3390/jpm10010004 |
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author | AL-Eitan, Laith N. Alqa’qa’, Kifah Amayreh, Wajdi Khasawneh, Rame Aljamal, Hanan Al-Abed, Mamoon Haddad, Yazan Rawashdeh, Tamara Jaradat, Zaher Haddad, Hazem |
author_facet | AL-Eitan, Laith N. Alqa’qa’, Kifah Amayreh, Wajdi Khasawneh, Rame Aljamal, Hanan Al-Abed, Mamoon Haddad, Yazan Rawashdeh, Tamara Jaradat, Zaher Haddad, Hazem |
author_sort | AL-Eitan, Laith N. |
collection | PubMed |
description | Biotinidase deficiency is an autosomal recessive metabolic disorder whose diagnosis currently depends on clinical symptoms and a biotinidase enzyme assay. This study aimed to investigate the mutational status and enzymatic activity of biotinidase deficiency in seven unrelated Jordanian families including 10 patients and 17 healthy family members. Amplified DNA was analyzed by the automated Sanger sequencing method, and the enzymatic assay was performed using a colorimetric assessment. Biotinidase level was significantly lower (p < 0.001) in BTD children compare to their non-affected family members. Genetic sequencing revealed six different mutations in Jordanian patients. One mutation was novel and located in exon 4, which could be a prevalent mutation for biotinidase deficiency in the Jordanian population. Identification of these common mutations and combing the enzymatic activity with genotypic data will help clinicians with regard to better genetic counseling and management through implementing prevention programs in the future. |
format | Online Article Text |
id | pubmed-7151559 |
institution | National Center for Biotechnology Information |
language | English |
publishDate | 2020 |
publisher | MDPI |
record_format | MEDLINE/PubMed |
spelling | pubmed-71515592020-04-20 Identification and Characterization of BTD Gene Mutations in Jordanian Children with Biotinidase Deficiency AL-Eitan, Laith N. Alqa’qa’, Kifah Amayreh, Wajdi Khasawneh, Rame Aljamal, Hanan Al-Abed, Mamoon Haddad, Yazan Rawashdeh, Tamara Jaradat, Zaher Haddad, Hazem J Pers Med Article Biotinidase deficiency is an autosomal recessive metabolic disorder whose diagnosis currently depends on clinical symptoms and a biotinidase enzyme assay. This study aimed to investigate the mutational status and enzymatic activity of biotinidase deficiency in seven unrelated Jordanian families including 10 patients and 17 healthy family members. Amplified DNA was analyzed by the automated Sanger sequencing method, and the enzymatic assay was performed using a colorimetric assessment. Biotinidase level was significantly lower (p < 0.001) in BTD children compare to their non-affected family members. Genetic sequencing revealed six different mutations in Jordanian patients. One mutation was novel and located in exon 4, which could be a prevalent mutation for biotinidase deficiency in the Jordanian population. Identification of these common mutations and combing the enzymatic activity with genotypic data will help clinicians with regard to better genetic counseling and management through implementing prevention programs in the future. MDPI 2020-01-21 /pmc/articles/PMC7151559/ /pubmed/31973013 http://dx.doi.org/10.3390/jpm10010004 Text en © 2020 by the authors. Licensee MDPI, Basel, Switzerland. This article is an open access article distributed under the terms and conditions of the Creative Commons Attribution (CC BY) license (http://creativecommons.org/licenses/by/4.0/). |
spellingShingle | Article AL-Eitan, Laith N. Alqa’qa’, Kifah Amayreh, Wajdi Khasawneh, Rame Aljamal, Hanan Al-Abed, Mamoon Haddad, Yazan Rawashdeh, Tamara Jaradat, Zaher Haddad, Hazem Identification and Characterization of BTD Gene Mutations in Jordanian Children with Biotinidase Deficiency |
title | Identification and Characterization of BTD Gene Mutations in Jordanian Children with Biotinidase Deficiency |
title_full | Identification and Characterization of BTD Gene Mutations in Jordanian Children with Biotinidase Deficiency |
title_fullStr | Identification and Characterization of BTD Gene Mutations in Jordanian Children with Biotinidase Deficiency |
title_full_unstemmed | Identification and Characterization of BTD Gene Mutations in Jordanian Children with Biotinidase Deficiency |
title_short | Identification and Characterization of BTD Gene Mutations in Jordanian Children with Biotinidase Deficiency |
title_sort | identification and characterization of btd gene mutations in jordanian children with biotinidase deficiency |
topic | Article |
url | https://www.ncbi.nlm.nih.gov/pmc/articles/PMC7151559/ https://www.ncbi.nlm.nih.gov/pubmed/31973013 http://dx.doi.org/10.3390/jpm10010004 |
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