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Incidental Hamartoma in an elderly patient: a case report

BACKGROUND: Neuromuscular hamartoma is a very rare tumor; with only five cases reported in the orbit. It often occurs in infants and young children and involves large peripheral nerves, but there has been only few reports of occurrence in the orbit and adults. CASE PRESENTATION: This paper describes...

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Autores principales: Joo, Tae-Sung, Kim, Hyejee, Park, In-Ki, Shin, Jae-Ho
Formato: Online Artículo Texto
Lenguaje:English
Publicado: BioMed Central 2020
Materias:
Acceso en línea:https://www.ncbi.nlm.nih.gov/pmc/articles/PMC7433136/
https://www.ncbi.nlm.nih.gov/pubmed/32807115
http://dx.doi.org/10.1186/s12886-020-01604-9
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author Joo, Tae-Sung
Kim, Hyejee
Park, In-Ki
Shin, Jae-Ho
author_facet Joo, Tae-Sung
Kim, Hyejee
Park, In-Ki
Shin, Jae-Ho
author_sort Joo, Tae-Sung
collection PubMed
description BACKGROUND: Neuromuscular hamartoma is a very rare tumor; with only five cases reported in the orbit. It often occurs in infants and young children and involves large peripheral nerves, but there has been only few reports of occurrence in the orbit and adults. CASE PRESENTATION: This paper describes a 70-year-old man with an incidental orbital mass detected by an imaging test and who later developed associated symptoms. The mass was diagnosed as neuromuscular hamartoma. Superior rectus muscle recession and inferior rectus muscle resection were performed in the right eye for hypertropia secondary to postoperative inferior rectus muscle palsy. Hypertropia in the right eye and diplopia improved after surgery, and regular follow-up is underway. CONCLUSION: This is the first case of an incidentally detected orbital mass diagnosed by histologic examination as a neuromuscular hamartoma in an older patient whose proptosis progressed after a long period of inactivity.
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spelling pubmed-74331362020-08-19 Incidental Hamartoma in an elderly patient: a case report Joo, Tae-Sung Kim, Hyejee Park, In-Ki Shin, Jae-Ho BMC Ophthalmol Case Report BACKGROUND: Neuromuscular hamartoma is a very rare tumor; with only five cases reported in the orbit. It often occurs in infants and young children and involves large peripheral nerves, but there has been only few reports of occurrence in the orbit and adults. CASE PRESENTATION: This paper describes a 70-year-old man with an incidental orbital mass detected by an imaging test and who later developed associated symptoms. The mass was diagnosed as neuromuscular hamartoma. Superior rectus muscle recession and inferior rectus muscle resection were performed in the right eye for hypertropia secondary to postoperative inferior rectus muscle palsy. Hypertropia in the right eye and diplopia improved after surgery, and regular follow-up is underway. CONCLUSION: This is the first case of an incidentally detected orbital mass diagnosed by histologic examination as a neuromuscular hamartoma in an older patient whose proptosis progressed after a long period of inactivity. BioMed Central 2020-08-17 /pmc/articles/PMC7433136/ /pubmed/32807115 http://dx.doi.org/10.1186/s12886-020-01604-9 Text en © The Author(s) 2020 Open AccessThis article is licensed under a Creative Commons Attribution 4.0 International License, which permits use, sharing, adaptation, distribution and reproduction in any medium or format, as long as you give appropriate credit to the original author(s) and the source, provide a link to the Creative Commons licence, and indicate if changes were made. The images or other third party material in this article are included in the article's Creative Commons licence, unless indicated otherwise in a credit line to the material. If material is not included in the article's Creative Commons licence and your intended use is not permitted by statutory regulation or exceeds the permitted use, you will need to obtain permission directly from the copyright holder. To view a copy of this licence, visit http://creativecommons.org/licenses/by/4.0/. The Creative Commons Public Domain Dedication waiver (http://creativecommons.org/publicdomain/zero/1.0/) applies to the data made available in this article, unless otherwise stated in a credit line to the data.
spellingShingle Case Report
Joo, Tae-Sung
Kim, Hyejee
Park, In-Ki
Shin, Jae-Ho
Incidental Hamartoma in an elderly patient: a case report
title Incidental Hamartoma in an elderly patient: a case report
title_full Incidental Hamartoma in an elderly patient: a case report
title_fullStr Incidental Hamartoma in an elderly patient: a case report
title_full_unstemmed Incidental Hamartoma in an elderly patient: a case report
title_short Incidental Hamartoma in an elderly patient: a case report
title_sort incidental hamartoma in an elderly patient: a case report
topic Case Report
url https://www.ncbi.nlm.nih.gov/pmc/articles/PMC7433136/
https://www.ncbi.nlm.nih.gov/pubmed/32807115
http://dx.doi.org/10.1186/s12886-020-01604-9
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