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Mild myopathic phenotype in a patient with homozygous c.416C > T mutation in TK2 gene

The mitochondrial DNA depletion syndrome (MDDS) is characterized by extensive phenotypic variability and is due to nuclear gene mutations resulting in reduced mtDNA copy number. Thymidine kinase 2 (TK2) mutations are well known to be associated with MDDS. Few severely affected cases carrying the c.4...

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Autores principales: Papadimas, George K., Vargiami, Efthimia, Dragoumi, Pinelopi, Van Coster, Rudy, Smet, Joel, Seneca, Sara, Papadopoulos, Constantinos, Kararizou, Evangelia, Zafeiriou, Dimitrios
Formato: Online Artículo Texto
Lenguaje:English
Publicado: Pacini Editore Srl 2020
Materias:
Acceso en línea:https://www.ncbi.nlm.nih.gov/pmc/articles/PMC7460728/
https://www.ncbi.nlm.nih.gov/pubmed/32904881
http://dx.doi.org/10.36185/2532-1900-012
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author Papadimas, George K.
Vargiami, Efthimia
Dragoumi, Pinelopi
Van Coster, Rudy
Smet, Joel
Seneca, Sara
Papadopoulos, Constantinos
Kararizou, Evangelia
Zafeiriou, Dimitrios
author_facet Papadimas, George K.
Vargiami, Efthimia
Dragoumi, Pinelopi
Van Coster, Rudy
Smet, Joel
Seneca, Sara
Papadopoulos, Constantinos
Kararizou, Evangelia
Zafeiriou, Dimitrios
author_sort Papadimas, George K.
collection PubMed
description The mitochondrial DNA depletion syndrome (MDDS) is characterized by extensive phenotypic variability and is due to nuclear gene mutations resulting in reduced mtDNA copy number. Thymidine kinase 2 (TK2) mutations are well known to be associated with MDDS. Few severely affected cases carrying the c.416C > T mutation in TK2 gene have been described so far. We describe the case of a 14months boy with the aforementioned TK2 gene pathogenic mutation at a homozygous state, presenting with a mild clinical phenotype. In addition to severe mitochondrial pathology on muscle biopsy, there was also histochemical evidence of adenylate deaminase deficiency. Overall, this report serves to further expand the clinical spectrum of TK2 mutations associated with MDDS.
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spelling pubmed-74607282020-09-04 Mild myopathic phenotype in a patient with homozygous c.416C > T mutation in TK2 gene Papadimas, George K. Vargiami, Efthimia Dragoumi, Pinelopi Van Coster, Rudy Smet, Joel Seneca, Sara Papadopoulos, Constantinos Kararizou, Evangelia Zafeiriou, Dimitrios Acta Myol Case Report The mitochondrial DNA depletion syndrome (MDDS) is characterized by extensive phenotypic variability and is due to nuclear gene mutations resulting in reduced mtDNA copy number. Thymidine kinase 2 (TK2) mutations are well known to be associated with MDDS. Few severely affected cases carrying the c.416C > T mutation in TK2 gene have been described so far. We describe the case of a 14months boy with the aforementioned TK2 gene pathogenic mutation at a homozygous state, presenting with a mild clinical phenotype. In addition to severe mitochondrial pathology on muscle biopsy, there was also histochemical evidence of adenylate deaminase deficiency. Overall, this report serves to further expand the clinical spectrum of TK2 mutations associated with MDDS. Pacini Editore Srl 2020-06-01 /pmc/articles/PMC7460728/ /pubmed/32904881 http://dx.doi.org/10.36185/2532-1900-012 Text en ©2020 Gaetano Conte Academy - Mediterranean Society of Myology, Naples, Italy https://creativecommons.org/licenses/by-nc-nd/4.0/deed.en This is an open access article distributed in accordance with the CC-BY-NC-ND (Creative Commons Attribution-NonCommercial-NoDerivatives 4.0 International) license. The article can be used by giving appropriate credit and mentioning the license, but only for non-commercial purposes and only in the original version. For further information: https://creativecommons.org/licenses/by-nc-nd/4.0/deed.en
spellingShingle Case Report
Papadimas, George K.
Vargiami, Efthimia
Dragoumi, Pinelopi
Van Coster, Rudy
Smet, Joel
Seneca, Sara
Papadopoulos, Constantinos
Kararizou, Evangelia
Zafeiriou, Dimitrios
Mild myopathic phenotype in a patient with homozygous c.416C > T mutation in TK2 gene
title Mild myopathic phenotype in a patient with homozygous c.416C > T mutation in TK2 gene
title_full Mild myopathic phenotype in a patient with homozygous c.416C > T mutation in TK2 gene
title_fullStr Mild myopathic phenotype in a patient with homozygous c.416C > T mutation in TK2 gene
title_full_unstemmed Mild myopathic phenotype in a patient with homozygous c.416C > T mutation in TK2 gene
title_short Mild myopathic phenotype in a patient with homozygous c.416C > T mutation in TK2 gene
title_sort mild myopathic phenotype in a patient with homozygous c.416c > t mutation in tk2 gene
topic Case Report
url https://www.ncbi.nlm.nih.gov/pmc/articles/PMC7460728/
https://www.ncbi.nlm.nih.gov/pubmed/32904881
http://dx.doi.org/10.36185/2532-1900-012
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