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Mild myopathic phenotype in a patient with homozygous c.416C > T mutation in TK2 gene
The mitochondrial DNA depletion syndrome (MDDS) is characterized by extensive phenotypic variability and is due to nuclear gene mutations resulting in reduced mtDNA copy number. Thymidine kinase 2 (TK2) mutations are well known to be associated with MDDS. Few severely affected cases carrying the c.4...
Autores principales: | , , , , , , , , |
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Formato: | Online Artículo Texto |
Lenguaje: | English |
Publicado: |
Pacini Editore Srl
2020
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Materias: | |
Acceso en línea: | https://www.ncbi.nlm.nih.gov/pmc/articles/PMC7460728/ https://www.ncbi.nlm.nih.gov/pubmed/32904881 http://dx.doi.org/10.36185/2532-1900-012 |
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author | Papadimas, George K. Vargiami, Efthimia Dragoumi, Pinelopi Van Coster, Rudy Smet, Joel Seneca, Sara Papadopoulos, Constantinos Kararizou, Evangelia Zafeiriou, Dimitrios |
author_facet | Papadimas, George K. Vargiami, Efthimia Dragoumi, Pinelopi Van Coster, Rudy Smet, Joel Seneca, Sara Papadopoulos, Constantinos Kararizou, Evangelia Zafeiriou, Dimitrios |
author_sort | Papadimas, George K. |
collection | PubMed |
description | The mitochondrial DNA depletion syndrome (MDDS) is characterized by extensive phenotypic variability and is due to nuclear gene mutations resulting in reduced mtDNA copy number. Thymidine kinase 2 (TK2) mutations are well known to be associated with MDDS. Few severely affected cases carrying the c.416C > T mutation in TK2 gene have been described so far. We describe the case of a 14months boy with the aforementioned TK2 gene pathogenic mutation at a homozygous state, presenting with a mild clinical phenotype. In addition to severe mitochondrial pathology on muscle biopsy, there was also histochemical evidence of adenylate deaminase deficiency. Overall, this report serves to further expand the clinical spectrum of TK2 mutations associated with MDDS. |
format | Online Article Text |
id | pubmed-7460728 |
institution | National Center for Biotechnology Information |
language | English |
publishDate | 2020 |
publisher | Pacini Editore Srl |
record_format | MEDLINE/PubMed |
spelling | pubmed-74607282020-09-04 Mild myopathic phenotype in a patient with homozygous c.416C > T mutation in TK2 gene Papadimas, George K. Vargiami, Efthimia Dragoumi, Pinelopi Van Coster, Rudy Smet, Joel Seneca, Sara Papadopoulos, Constantinos Kararizou, Evangelia Zafeiriou, Dimitrios Acta Myol Case Report The mitochondrial DNA depletion syndrome (MDDS) is characterized by extensive phenotypic variability and is due to nuclear gene mutations resulting in reduced mtDNA copy number. Thymidine kinase 2 (TK2) mutations are well known to be associated with MDDS. Few severely affected cases carrying the c.416C > T mutation in TK2 gene have been described so far. We describe the case of a 14months boy with the aforementioned TK2 gene pathogenic mutation at a homozygous state, presenting with a mild clinical phenotype. In addition to severe mitochondrial pathology on muscle biopsy, there was also histochemical evidence of adenylate deaminase deficiency. Overall, this report serves to further expand the clinical spectrum of TK2 mutations associated with MDDS. Pacini Editore Srl 2020-06-01 /pmc/articles/PMC7460728/ /pubmed/32904881 http://dx.doi.org/10.36185/2532-1900-012 Text en ©2020 Gaetano Conte Academy - Mediterranean Society of Myology, Naples, Italy https://creativecommons.org/licenses/by-nc-nd/4.0/deed.en This is an open access article distributed in accordance with the CC-BY-NC-ND (Creative Commons Attribution-NonCommercial-NoDerivatives 4.0 International) license. The article can be used by giving appropriate credit and mentioning the license, but only for non-commercial purposes and only in the original version. For further information: https://creativecommons.org/licenses/by-nc-nd/4.0/deed.en |
spellingShingle | Case Report Papadimas, George K. Vargiami, Efthimia Dragoumi, Pinelopi Van Coster, Rudy Smet, Joel Seneca, Sara Papadopoulos, Constantinos Kararizou, Evangelia Zafeiriou, Dimitrios Mild myopathic phenotype in a patient with homozygous c.416C > T mutation in TK2 gene |
title | Mild myopathic phenotype in a patient with homozygous c.416C > T mutation in TK2 gene |
title_full | Mild myopathic phenotype in a patient with homozygous c.416C > T mutation in TK2 gene |
title_fullStr | Mild myopathic phenotype in a patient with homozygous c.416C > T mutation in TK2 gene |
title_full_unstemmed | Mild myopathic phenotype in a patient with homozygous c.416C > T mutation in TK2 gene |
title_short | Mild myopathic phenotype in a patient with homozygous c.416C > T mutation in TK2 gene |
title_sort | mild myopathic phenotype in a patient with homozygous c.416c > t mutation in tk2 gene |
topic | Case Report |
url | https://www.ncbi.nlm.nih.gov/pmc/articles/PMC7460728/ https://www.ncbi.nlm.nih.gov/pubmed/32904881 http://dx.doi.org/10.36185/2532-1900-012 |
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