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Inducible transgene expression in PDX models in vivo identifies KLF4 as a therapeutic target for B-ALL

BACKGROUND: Clinically relevant methods are not available that prioritize and validate potential therapeutic targets for individual tumors, from the vast amount of tumor descriptive expression data. METHODS: We established inducible transgene expression in clinically relevant patient-derived xenogra...

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Autores principales: Liu, Wen-Hsin, Mrozek-Gorska, Paulina, Wirth, Anna-Katharina, Herold, Tobias, Schwarzkopf, Larissa, Pich, Dagmar, Völse, Kerstin, Melo-Narváez, M. Camila, Carlet, Michela, Hammerschmidt, Wolfgang, Jeremias, Irmela
Formato: Online Artículo Texto
Lenguaje:English
Publicado: BioMed Central 2020
Materias:
Acceso en línea:https://www.ncbi.nlm.nih.gov/pmc/articles/PMC7493381/
https://www.ncbi.nlm.nih.gov/pubmed/32944247
http://dx.doi.org/10.1186/s40364-020-00226-z
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author Liu, Wen-Hsin
Mrozek-Gorska, Paulina
Wirth, Anna-Katharina
Herold, Tobias
Schwarzkopf, Larissa
Pich, Dagmar
Völse, Kerstin
Melo-Narváez, M. Camila
Carlet, Michela
Hammerschmidt, Wolfgang
Jeremias, Irmela
author_facet Liu, Wen-Hsin
Mrozek-Gorska, Paulina
Wirth, Anna-Katharina
Herold, Tobias
Schwarzkopf, Larissa
Pich, Dagmar
Völse, Kerstin
Melo-Narváez, M. Camila
Carlet, Michela
Hammerschmidt, Wolfgang
Jeremias, Irmela
author_sort Liu, Wen-Hsin
collection PubMed
description BACKGROUND: Clinically relevant methods are not available that prioritize and validate potential therapeutic targets for individual tumors, from the vast amount of tumor descriptive expression data. METHODS: We established inducible transgene expression in clinically relevant patient-derived xenograft (PDX) models in vivo to fill this gap. RESULTS: With this technique at hand, we analyzed the role of the transcription factor Krüppel-like factor 4 (KLF4) in B-cell acute lymphoblastic leukemia (B-ALL) PDX models at different disease stages. In competitive preclinical in vivo trials, we found that re-expression of wild type KLF4 reduced the leukemia load in PDX models of B-ALL, with the strongest effects being observed after conventional chemotherapy in minimal residual disease (MRD). A nonfunctional KLF4 mutant had no effect on this model. The re-expression of KLF4 sensitized tumor cells in the PDX model towards systemic chemotherapy in vivo. It is of major translational relevance that azacitidine upregulated KLF4 levels in the PDX model and a KLF4 knockout reduced azacitidine-induced cell death, suggesting that azacitidine can regulate KLF4 re-expression. These results support the application of azacitidine in patients with B-ALL as a therapeutic option to regulate KLF4. CONCLUSION: Genetic engineering of PDX models allows the examination of the function of dysregulated genes like KLF4 in a highly clinically relevant translational context, and it also enables the selection of therapeutic targets in individual tumors and links their functions to clinically available drugs, which will facilitate personalized treatment in the future.
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spelling pubmed-74933812020-09-16 Inducible transgene expression in PDX models in vivo identifies KLF4 as a therapeutic target for B-ALL Liu, Wen-Hsin Mrozek-Gorska, Paulina Wirth, Anna-Katharina Herold, Tobias Schwarzkopf, Larissa Pich, Dagmar Völse, Kerstin Melo-Narváez, M. Camila Carlet, Michela Hammerschmidt, Wolfgang Jeremias, Irmela Biomark Res Research BACKGROUND: Clinically relevant methods are not available that prioritize and validate potential therapeutic targets for individual tumors, from the vast amount of tumor descriptive expression data. METHODS: We established inducible transgene expression in clinically relevant patient-derived xenograft (PDX) models in vivo to fill this gap. RESULTS: With this technique at hand, we analyzed the role of the transcription factor Krüppel-like factor 4 (KLF4) in B-cell acute lymphoblastic leukemia (B-ALL) PDX models at different disease stages. In competitive preclinical in vivo trials, we found that re-expression of wild type KLF4 reduced the leukemia load in PDX models of B-ALL, with the strongest effects being observed after conventional chemotherapy in minimal residual disease (MRD). A nonfunctional KLF4 mutant had no effect on this model. The re-expression of KLF4 sensitized tumor cells in the PDX model towards systemic chemotherapy in vivo. It is of major translational relevance that azacitidine upregulated KLF4 levels in the PDX model and a KLF4 knockout reduced azacitidine-induced cell death, suggesting that azacitidine can regulate KLF4 re-expression. These results support the application of azacitidine in patients with B-ALL as a therapeutic option to regulate KLF4. CONCLUSION: Genetic engineering of PDX models allows the examination of the function of dysregulated genes like KLF4 in a highly clinically relevant translational context, and it also enables the selection of therapeutic targets in individual tumors and links their functions to clinically available drugs, which will facilitate personalized treatment in the future. BioMed Central 2020-09-16 /pmc/articles/PMC7493381/ /pubmed/32944247 http://dx.doi.org/10.1186/s40364-020-00226-z Text en © The Author(s) 2020 Open AccessThis article is licensed under a Creative Commons Attribution 4.0 International License, which permits use, sharing, adaptation, distribution and reproduction in any medium or format, as long as you give appropriate credit to the original author(s) and the source, provide a link to the Creative Commons licence, and indicate if changes were made. The images or other third party material in this article are included in the article's Creative Commons licence, unless indicated otherwise in a credit line to the material. If material is not included in the article's Creative Commons licence and your intended use is not permitted by statutory regulation or exceeds the permitted use, you will need to obtain permission directly from the copyright holder. To view a copy of this licence, visit http://creativecommons.org/licenses/by/4.0/. The Creative Commons Public Domain Dedication waiver (http://creativecommons.org/publicdomain/zero/1.0/) applies to the data made available in this article, unless otherwise stated in a credit line to the data.
spellingShingle Research
Liu, Wen-Hsin
Mrozek-Gorska, Paulina
Wirth, Anna-Katharina
Herold, Tobias
Schwarzkopf, Larissa
Pich, Dagmar
Völse, Kerstin
Melo-Narváez, M. Camila
Carlet, Michela
Hammerschmidt, Wolfgang
Jeremias, Irmela
Inducible transgene expression in PDX models in vivo identifies KLF4 as a therapeutic target for B-ALL
title Inducible transgene expression in PDX models in vivo identifies KLF4 as a therapeutic target for B-ALL
title_full Inducible transgene expression in PDX models in vivo identifies KLF4 as a therapeutic target for B-ALL
title_fullStr Inducible transgene expression in PDX models in vivo identifies KLF4 as a therapeutic target for B-ALL
title_full_unstemmed Inducible transgene expression in PDX models in vivo identifies KLF4 as a therapeutic target for B-ALL
title_short Inducible transgene expression in PDX models in vivo identifies KLF4 as a therapeutic target for B-ALL
title_sort inducible transgene expression in pdx models in vivo identifies klf4 as a therapeutic target for b-all
topic Research
url https://www.ncbi.nlm.nih.gov/pmc/articles/PMC7493381/
https://www.ncbi.nlm.nih.gov/pubmed/32944247
http://dx.doi.org/10.1186/s40364-020-00226-z
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