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Congenital Bladder and Urethral Agenesis: Two Case Reports and Management

BACKGROUND: Agenesis of the bladder and urethra is a rare congenital anomaly, with a very few living cases reported in the literature so far. Case Presentation. We are reporting two female patients (3 and 6 years old) with bladder and urethral agenesis who presented with urinary incontinence. In bot...

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Autores principales: Delshad, Salahaddin, Rastad, Hadith, Mardi, Parham
Formato: Online Artículo Texto
Lenguaje:English
Publicado: Hindawi 2020
Materias:
Acceso en línea:https://www.ncbi.nlm.nih.gov/pmc/articles/PMC7532414/
https://www.ncbi.nlm.nih.gov/pubmed/33029134
http://dx.doi.org/10.1155/2020/2782783
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author Delshad, Salahaddin
Rastad, Hadith
Mardi, Parham
author_facet Delshad, Salahaddin
Rastad, Hadith
Mardi, Parham
author_sort Delshad, Salahaddin
collection PubMed
description BACKGROUND: Agenesis of the bladder and urethra is a rare congenital anomaly, with a very few living cases reported in the literature so far. Case Presentation. We are reporting two female patients (3 and 6 years old) with bladder and urethral agenesis who presented with urinary incontinence. In both patients, magnetic resonant imaging (MRI) revealed a case of bladder and urethral agenesis with normal ureters draining into the vagina. Patients underwent a neobladder and conduit creation surgery. The neobladder was constructed from the whole cecum and a part of the ascending colon, followed by an anastomose of the ureters into the neobladder in a nonrefluxing fashion; the appendix was used simultaneously as a continent catheterizable conduit. The two patients attained urinary continence postoperatively. CONCLUSION: We reported two cases of bladder agenesis, and for the first time, we have performed neobladder creation surgery using the cecum and ascending colon. One-year follow-up did not reveal any complications.
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spelling pubmed-75324142020-10-06 Congenital Bladder and Urethral Agenesis: Two Case Reports and Management Delshad, Salahaddin Rastad, Hadith Mardi, Parham Adv Urol Research Article BACKGROUND: Agenesis of the bladder and urethra is a rare congenital anomaly, with a very few living cases reported in the literature so far. Case Presentation. We are reporting two female patients (3 and 6 years old) with bladder and urethral agenesis who presented with urinary incontinence. In both patients, magnetic resonant imaging (MRI) revealed a case of bladder and urethral agenesis with normal ureters draining into the vagina. Patients underwent a neobladder and conduit creation surgery. The neobladder was constructed from the whole cecum and a part of the ascending colon, followed by an anastomose of the ureters into the neobladder in a nonrefluxing fashion; the appendix was used simultaneously as a continent catheterizable conduit. The two patients attained urinary continence postoperatively. CONCLUSION: We reported two cases of bladder agenesis, and for the first time, we have performed neobladder creation surgery using the cecum and ascending colon. One-year follow-up did not reveal any complications. Hindawi 2020-09-24 /pmc/articles/PMC7532414/ /pubmed/33029134 http://dx.doi.org/10.1155/2020/2782783 Text en Copyright © 2020 Salahaddin Delshad et al. https://creativecommons.org/licenses/by/4.0/ This is an open access article distributed under the Creative Commons Attribution License, which permits unrestricted use, distribution, and reproduction in any medium, provided the original work is properly cited.
spellingShingle Research Article
Delshad, Salahaddin
Rastad, Hadith
Mardi, Parham
Congenital Bladder and Urethral Agenesis: Two Case Reports and Management
title Congenital Bladder and Urethral Agenesis: Two Case Reports and Management
title_full Congenital Bladder and Urethral Agenesis: Two Case Reports and Management
title_fullStr Congenital Bladder and Urethral Agenesis: Two Case Reports and Management
title_full_unstemmed Congenital Bladder and Urethral Agenesis: Two Case Reports and Management
title_short Congenital Bladder and Urethral Agenesis: Two Case Reports and Management
title_sort congenital bladder and urethral agenesis: two case reports and management
topic Research Article
url https://www.ncbi.nlm.nih.gov/pmc/articles/PMC7532414/
https://www.ncbi.nlm.nih.gov/pubmed/33029134
http://dx.doi.org/10.1155/2020/2782783
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