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Immunohistochemistry and Mutation Analysis of SDHx Genes in Carotid Paragangliomas

Carotid paragangliomas (CPGLs) are rare neuroendocrine tumors often associated with mutations in SDHx genes. The immunohistochemistry of succinate dehydrogenase (SDH) subunits has been considered a useful instrument for the prediction of SDHx mutations in paragangliomas/pheochromocytomas. We compare...

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Autores principales: Snezhkina, Anastasiya V., Kalinin, Dmitry V., Pavlov, Vladislav S., Lukyanova, Elena N., Golovyuk, Alexander L., Fedorova, Maria S., Pudova, Elena A., Savvateeva, Maria V., Stepanov, Oleg A., Poloznikov, Andrey A., Demidova, Tatiana B., Melnikova, Nataliya V., Dmitriev, Alexey A., Krasnov, George S., Kudryavtseva, Anna V.
Formato: Online Artículo Texto
Lenguaje:English
Publicado: MDPI 2020
Materias:
Acceso en línea:https://www.ncbi.nlm.nih.gov/pmc/articles/PMC7576476/
https://www.ncbi.nlm.nih.gov/pubmed/32971818
http://dx.doi.org/10.3390/ijms21186950
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author Snezhkina, Anastasiya V.
Kalinin, Dmitry V.
Pavlov, Vladislav S.
Lukyanova, Elena N.
Golovyuk, Alexander L.
Fedorova, Maria S.
Pudova, Elena A.
Savvateeva, Maria V.
Stepanov, Oleg A.
Poloznikov, Andrey A.
Demidova, Tatiana B.
Melnikova, Nataliya V.
Dmitriev, Alexey A.
Krasnov, George S.
Kudryavtseva, Anna V.
author_facet Snezhkina, Anastasiya V.
Kalinin, Dmitry V.
Pavlov, Vladislav S.
Lukyanova, Elena N.
Golovyuk, Alexander L.
Fedorova, Maria S.
Pudova, Elena A.
Savvateeva, Maria V.
Stepanov, Oleg A.
Poloznikov, Andrey A.
Demidova, Tatiana B.
Melnikova, Nataliya V.
Dmitriev, Alexey A.
Krasnov, George S.
Kudryavtseva, Anna V.
author_sort Snezhkina, Anastasiya V.
collection PubMed
description Carotid paragangliomas (CPGLs) are rare neuroendocrine tumors often associated with mutations in SDHx genes. The immunohistochemistry of succinate dehydrogenase (SDH) subunits has been considered a useful instrument for the prediction of SDHx mutations in paragangliomas/pheochromocytomas. We compared the mutation status of SDHx genes with the immunohistochemical (IHC) staining of SDH subunits in CPGLs. To identify pathogenic/likely pathogenic variants in SDHx genes, exome sequencing data analysis among 42 CPGL patients was performed. IHC staining of SDH subunits was carried out for all CPGLs studied. We encountered SDHx variants in 38% (16/42) of the cases in SDHx genes. IHC showed negative (5/15) or weak diffuse (10/15) SDHB staining in most tumors with variants in any of SDHx (94%, 15/16). In SDHA-mutated CPGL, SDHA expression was completely absent and weak diffuse SDHB staining was detected. Positive immunoreactivity for all SDH subunits was found in one case with a variant in SDHD. Notably, CPGL samples without variants in SDHx also demonstrated negative (2/11) or weak diffuse (9/11) SDHB staining (42%, 11/26). Obtained results indicate that SDH immunohistochemistry does not fully reflect the presence of mutations in the genes; diagnostic effectiveness of this method was 71%. However, given the high sensitivity of SDHB immunohistochemistry, it could be used for initial identifications of patients potentially carrying SDHx mutations for recommendation of genetic testing.
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spelling pubmed-75764762020-10-28 Immunohistochemistry and Mutation Analysis of SDHx Genes in Carotid Paragangliomas Snezhkina, Anastasiya V. Kalinin, Dmitry V. Pavlov, Vladislav S. Lukyanova, Elena N. Golovyuk, Alexander L. Fedorova, Maria S. Pudova, Elena A. Savvateeva, Maria V. Stepanov, Oleg A. Poloznikov, Andrey A. Demidova, Tatiana B. Melnikova, Nataliya V. Dmitriev, Alexey A. Krasnov, George S. Kudryavtseva, Anna V. Int J Mol Sci Article Carotid paragangliomas (CPGLs) are rare neuroendocrine tumors often associated with mutations in SDHx genes. The immunohistochemistry of succinate dehydrogenase (SDH) subunits has been considered a useful instrument for the prediction of SDHx mutations in paragangliomas/pheochromocytomas. We compared the mutation status of SDHx genes with the immunohistochemical (IHC) staining of SDH subunits in CPGLs. To identify pathogenic/likely pathogenic variants in SDHx genes, exome sequencing data analysis among 42 CPGL patients was performed. IHC staining of SDH subunits was carried out for all CPGLs studied. We encountered SDHx variants in 38% (16/42) of the cases in SDHx genes. IHC showed negative (5/15) or weak diffuse (10/15) SDHB staining in most tumors with variants in any of SDHx (94%, 15/16). In SDHA-mutated CPGL, SDHA expression was completely absent and weak diffuse SDHB staining was detected. Positive immunoreactivity for all SDH subunits was found in one case with a variant in SDHD. Notably, CPGL samples without variants in SDHx also demonstrated negative (2/11) or weak diffuse (9/11) SDHB staining (42%, 11/26). Obtained results indicate that SDH immunohistochemistry does not fully reflect the presence of mutations in the genes; diagnostic effectiveness of this method was 71%. However, given the high sensitivity of SDHB immunohistochemistry, it could be used for initial identifications of patients potentially carrying SDHx mutations for recommendation of genetic testing. MDPI 2020-09-22 /pmc/articles/PMC7576476/ /pubmed/32971818 http://dx.doi.org/10.3390/ijms21186950 Text en © 2020 by the authors. Licensee MDPI, Basel, Switzerland. This article is an open access article distributed under the terms and conditions of the Creative Commons Attribution (CC BY) license (http://creativecommons.org/licenses/by/4.0/).
spellingShingle Article
Snezhkina, Anastasiya V.
Kalinin, Dmitry V.
Pavlov, Vladislav S.
Lukyanova, Elena N.
Golovyuk, Alexander L.
Fedorova, Maria S.
Pudova, Elena A.
Savvateeva, Maria V.
Stepanov, Oleg A.
Poloznikov, Andrey A.
Demidova, Tatiana B.
Melnikova, Nataliya V.
Dmitriev, Alexey A.
Krasnov, George S.
Kudryavtseva, Anna V.
Immunohistochemistry and Mutation Analysis of SDHx Genes in Carotid Paragangliomas
title Immunohistochemistry and Mutation Analysis of SDHx Genes in Carotid Paragangliomas
title_full Immunohistochemistry and Mutation Analysis of SDHx Genes in Carotid Paragangliomas
title_fullStr Immunohistochemistry and Mutation Analysis of SDHx Genes in Carotid Paragangliomas
title_full_unstemmed Immunohistochemistry and Mutation Analysis of SDHx Genes in Carotid Paragangliomas
title_short Immunohistochemistry and Mutation Analysis of SDHx Genes in Carotid Paragangliomas
title_sort immunohistochemistry and mutation analysis of sdhx genes in carotid paragangliomas
topic Article
url https://www.ncbi.nlm.nih.gov/pmc/articles/PMC7576476/
https://www.ncbi.nlm.nih.gov/pubmed/32971818
http://dx.doi.org/10.3390/ijms21186950
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