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Functional characterization of SMARCA4 variants identified by targeted exome-sequencing of 131,668 cancer patients

Genomic studies performed in cancer patients and tumor-derived cell lines have identified a high frequency of alterations in components of the mammalian switch/sucrose non-fermentable (mSWI/SNF or BAF) chromatin remodeling complex, including its core catalytic subunit, SMARCA4. Cells exhibiting loss...

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Autores principales: Fernando, Tharu M., Piskol, Robert, Bainer, Russell, Sokol, Ethan S., Trabucco, Sally E., Zhang, Qing, Trinh, Huong, Maund, Sophia, Kschonsak, Marc, Chaudhuri, Subhra, Modrusan, Zora, Januario, Thomas, Yauch, Robert L.
Formato: Online Artículo Texto
Lenguaje:English
Publicado: Nature Publishing Group UK 2020
Materias:
Acceso en línea:https://www.ncbi.nlm.nih.gov/pmc/articles/PMC7609548/
https://www.ncbi.nlm.nih.gov/pubmed/33144586
http://dx.doi.org/10.1038/s41467-020-19402-8
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author Fernando, Tharu M.
Piskol, Robert
Bainer, Russell
Sokol, Ethan S.
Trabucco, Sally E.
Zhang, Qing
Trinh, Huong
Maund, Sophia
Kschonsak, Marc
Chaudhuri, Subhra
Modrusan, Zora
Januario, Thomas
Yauch, Robert L.
author_facet Fernando, Tharu M.
Piskol, Robert
Bainer, Russell
Sokol, Ethan S.
Trabucco, Sally E.
Zhang, Qing
Trinh, Huong
Maund, Sophia
Kschonsak, Marc
Chaudhuri, Subhra
Modrusan, Zora
Januario, Thomas
Yauch, Robert L.
author_sort Fernando, Tharu M.
collection PubMed
description Genomic studies performed in cancer patients and tumor-derived cell lines have identified a high frequency of alterations in components of the mammalian switch/sucrose non-fermentable (mSWI/SNF or BAF) chromatin remodeling complex, including its core catalytic subunit, SMARCA4. Cells exhibiting loss of SMARCA4 rely on its paralog, SMARCA2, making SMARCA2 an attractive therapeutic target. Here we report the genomic profiling of solid tumors from 131,668 cancer patients, identifying 9434 patients with one or more SMARCA4 gene alterations. Homozygous SMARCA4 mutations were highly prevalent in certain tumor types, notably non-small cell lung cancer (NSCLC), and associated with reduced survival. The large sample size revealed previously uncharacterized hotspot missense mutations within the SMARCA4 helicase domain. Functional characterization of these mutations demonstrated markedly reduced remodeling activity. Surprisingly, a few SMARCA4 missense variants partially or fully rescued paralog dependency, underscoring that careful selection criteria must be employed to identify patients with inactivating, homozygous SMARCA4 missense mutations who may benefit from SMARCA2-targeted therapy.
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spelling pubmed-76095482020-11-10 Functional characterization of SMARCA4 variants identified by targeted exome-sequencing of 131,668 cancer patients Fernando, Tharu M. Piskol, Robert Bainer, Russell Sokol, Ethan S. Trabucco, Sally E. Zhang, Qing Trinh, Huong Maund, Sophia Kschonsak, Marc Chaudhuri, Subhra Modrusan, Zora Januario, Thomas Yauch, Robert L. Nat Commun Article Genomic studies performed in cancer patients and tumor-derived cell lines have identified a high frequency of alterations in components of the mammalian switch/sucrose non-fermentable (mSWI/SNF or BAF) chromatin remodeling complex, including its core catalytic subunit, SMARCA4. Cells exhibiting loss of SMARCA4 rely on its paralog, SMARCA2, making SMARCA2 an attractive therapeutic target. Here we report the genomic profiling of solid tumors from 131,668 cancer patients, identifying 9434 patients with one or more SMARCA4 gene alterations. Homozygous SMARCA4 mutations were highly prevalent in certain tumor types, notably non-small cell lung cancer (NSCLC), and associated with reduced survival. The large sample size revealed previously uncharacterized hotspot missense mutations within the SMARCA4 helicase domain. Functional characterization of these mutations demonstrated markedly reduced remodeling activity. Surprisingly, a few SMARCA4 missense variants partially or fully rescued paralog dependency, underscoring that careful selection criteria must be employed to identify patients with inactivating, homozygous SMARCA4 missense mutations who may benefit from SMARCA2-targeted therapy. Nature Publishing Group UK 2020-11-03 /pmc/articles/PMC7609548/ /pubmed/33144586 http://dx.doi.org/10.1038/s41467-020-19402-8 Text en © The Author(s) 2020 Open Access This article is licensed under a Creative Commons Attribution 4.0 International License, which permits use, sharing, adaptation, distribution and reproduction in any medium or format, as long as you give appropriate credit to the original author(s) and the source, provide a link to the Creative Commons license, and indicate if changes were made. The images or other third party material in this article are included in the article’s Creative Commons license, unless indicated otherwise in a credit line to the material. If material is not included in the article’s Creative Commons license and your intended use is not permitted by statutory regulation or exceeds the permitted use, you will need to obtain permission directly from the copyright holder. To view a copy of this license, visit http://creativecommons.org/licenses/by/4.0/.
spellingShingle Article
Fernando, Tharu M.
Piskol, Robert
Bainer, Russell
Sokol, Ethan S.
Trabucco, Sally E.
Zhang, Qing
Trinh, Huong
Maund, Sophia
Kschonsak, Marc
Chaudhuri, Subhra
Modrusan, Zora
Januario, Thomas
Yauch, Robert L.
Functional characterization of SMARCA4 variants identified by targeted exome-sequencing of 131,668 cancer patients
title Functional characterization of SMARCA4 variants identified by targeted exome-sequencing of 131,668 cancer patients
title_full Functional characterization of SMARCA4 variants identified by targeted exome-sequencing of 131,668 cancer patients
title_fullStr Functional characterization of SMARCA4 variants identified by targeted exome-sequencing of 131,668 cancer patients
title_full_unstemmed Functional characterization of SMARCA4 variants identified by targeted exome-sequencing of 131,668 cancer patients
title_short Functional characterization of SMARCA4 variants identified by targeted exome-sequencing of 131,668 cancer patients
title_sort functional characterization of smarca4 variants identified by targeted exome-sequencing of 131,668 cancer patients
topic Article
url https://www.ncbi.nlm.nih.gov/pmc/articles/PMC7609548/
https://www.ncbi.nlm.nih.gov/pubmed/33144586
http://dx.doi.org/10.1038/s41467-020-19402-8
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