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Updated birth prevalence and relative frequency of mucopolysaccharidoses across Brazilian regions

The mucopolysaccharidoses (MPS) are a group of lysosomal storage disorders caused by 11 enzyme deficiencies, classified into seven types. Data on the birth prevalence of each MPS type are available for only a few countries, and the totality of cases may be underestimated. To determine the epidemiolo...

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Autores principales: Josahkian, Juliana Alves, Trapp, Franciele Barbosa, Burin, Maira Graeff, Michelin-Tirelli, Kristiane, de Magalhães, Ana Paula Pereira Scholz, Sebastião, Fernanda Medeiros, Bender, Fernanda, Mari, Jurema Fátima De, Brusius-Facchin, Ana Carolina, Leistner-Segal, Sandra, Málaga, Diana Rojas, Giugliani, Roberto
Formato: Online Artículo Texto
Lenguaje:English
Publicado: Sociedade Brasileira de Genética 2021
Materias:
Acceso en línea:https://www.ncbi.nlm.nih.gov/pmc/articles/PMC7839630/
https://www.ncbi.nlm.nih.gov/pubmed/33503199
http://dx.doi.org/10.1590/1678-4685-GMB-2020-0138
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author Josahkian, Juliana Alves
Trapp, Franciele Barbosa
Burin, Maira Graeff
Michelin-Tirelli, Kristiane
de Magalhães, Ana Paula Pereira Scholz
Sebastião, Fernanda Medeiros
Bender, Fernanda
Mari, Jurema Fátima De
Brusius-Facchin, Ana Carolina
Leistner-Segal, Sandra
Málaga, Diana Rojas
Giugliani, Roberto
author_facet Josahkian, Juliana Alves
Trapp, Franciele Barbosa
Burin, Maira Graeff
Michelin-Tirelli, Kristiane
de Magalhães, Ana Paula Pereira Scholz
Sebastião, Fernanda Medeiros
Bender, Fernanda
Mari, Jurema Fátima De
Brusius-Facchin, Ana Carolina
Leistner-Segal, Sandra
Málaga, Diana Rojas
Giugliani, Roberto
author_sort Josahkian, Juliana Alves
collection PubMed
description The mucopolysaccharidoses (MPS) are a group of lysosomal storage disorders caused by 11 enzyme deficiencies, classified into seven types. Data on the birth prevalence of each MPS type are available for only a few countries, and the totality of cases may be underestimated. To determine the epidemiological profile of MPS in each Brazilian region, we analyzed data collected between 1982 and 2019 by a national reference laboratory and identified 1,652 patients. Using data between 1994 and 2018, the birth prevalence (by 100,000 live births) for MPS was 1.57. MPS II was the most common type of MPS in Brazil, and its birth prevalence was 0.48 (0.94 considering only male births). Regarding the number of cases per region, MPS II was the most frequent in the North and Center-West (followed by MPS VI), and also in the Southeast (followed by MPS I); MPS I and MPS II were the most common types in the South; and MPS VI was the most common in the Northeast (followed by MPS II). The differences observed in the relative frequencies of MPS types across Brazilian regions are likely linked to founder effect, endogamy, and consanguinity, but other factors may be present and need further investigation.
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spelling pubmed-78396302021-02-03 Updated birth prevalence and relative frequency of mucopolysaccharidoses across Brazilian regions Josahkian, Juliana Alves Trapp, Franciele Barbosa Burin, Maira Graeff Michelin-Tirelli, Kristiane de Magalhães, Ana Paula Pereira Scholz Sebastião, Fernanda Medeiros Bender, Fernanda Mari, Jurema Fátima De Brusius-Facchin, Ana Carolina Leistner-Segal, Sandra Málaga, Diana Rojas Giugliani, Roberto Genet Mol Biol Human and Medical Genetics The mucopolysaccharidoses (MPS) are a group of lysosomal storage disorders caused by 11 enzyme deficiencies, classified into seven types. Data on the birth prevalence of each MPS type are available for only a few countries, and the totality of cases may be underestimated. To determine the epidemiological profile of MPS in each Brazilian region, we analyzed data collected between 1982 and 2019 by a national reference laboratory and identified 1,652 patients. Using data between 1994 and 2018, the birth prevalence (by 100,000 live births) for MPS was 1.57. MPS II was the most common type of MPS in Brazil, and its birth prevalence was 0.48 (0.94 considering only male births). Regarding the number of cases per region, MPS II was the most frequent in the North and Center-West (followed by MPS VI), and also in the Southeast (followed by MPS I); MPS I and MPS II were the most common types in the South; and MPS VI was the most common in the Northeast (followed by MPS II). The differences observed in the relative frequencies of MPS types across Brazilian regions are likely linked to founder effect, endogamy, and consanguinity, but other factors may be present and need further investigation. Sociedade Brasileira de Genética 2021-01-27 /pmc/articles/PMC7839630/ /pubmed/33503199 http://dx.doi.org/10.1590/1678-4685-GMB-2020-0138 Text en https://creativecommons.org/licenses/by/4.0/ This is an open-access article distributed under the terms of the Creative Commons Attribution License
spellingShingle Human and Medical Genetics
Josahkian, Juliana Alves
Trapp, Franciele Barbosa
Burin, Maira Graeff
Michelin-Tirelli, Kristiane
de Magalhães, Ana Paula Pereira Scholz
Sebastião, Fernanda Medeiros
Bender, Fernanda
Mari, Jurema Fátima De
Brusius-Facchin, Ana Carolina
Leistner-Segal, Sandra
Málaga, Diana Rojas
Giugliani, Roberto
Updated birth prevalence and relative frequency of mucopolysaccharidoses across Brazilian regions
title Updated birth prevalence and relative frequency of mucopolysaccharidoses across Brazilian regions
title_full Updated birth prevalence and relative frequency of mucopolysaccharidoses across Brazilian regions
title_fullStr Updated birth prevalence and relative frequency of mucopolysaccharidoses across Brazilian regions
title_full_unstemmed Updated birth prevalence and relative frequency of mucopolysaccharidoses across Brazilian regions
title_short Updated birth prevalence and relative frequency of mucopolysaccharidoses across Brazilian regions
title_sort updated birth prevalence and relative frequency of mucopolysaccharidoses across brazilian regions
topic Human and Medical Genetics
url https://www.ncbi.nlm.nih.gov/pmc/articles/PMC7839630/
https://www.ncbi.nlm.nih.gov/pubmed/33503199
http://dx.doi.org/10.1590/1678-4685-GMB-2020-0138
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