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Contributions of de novo variants to systemic lupus erythematosus

By performing whole-genome sequencing in a Swedish cohort of 71 parent-offspring trios, in which the child in each family is affected by systemic lupus erythematosus (SLE, OMIM 152700), we investigated the contribution of de novo variants to risk of SLE. We found de novo single nucleotide variants (...

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Autores principales: Almlöf, Jonas Carlsson, Nystedt, Sara, Mechtidou, Aikaterini, Leonard, Dag, Eloranta, Maija-Leena, Grosso, Giorgia, Sjöwall, Christopher, Bengtsson, Anders A., Jönsen, Andreas, Gunnarsson, Iva, Svenungsson, Elisabet, Rönnblom, Lars, Sandling, Johanna K., Syvänen, Ann-Christine
Formato: Online Artículo Texto
Lenguaje:English
Publicado: Springer International Publishing 2020
Materias:
Acceso en línea:https://www.ncbi.nlm.nih.gov/pmc/articles/PMC7852530/
https://www.ncbi.nlm.nih.gov/pubmed/32724065
http://dx.doi.org/10.1038/s41431-020-0698-5
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author Almlöf, Jonas Carlsson
Nystedt, Sara
Mechtidou, Aikaterini
Leonard, Dag
Eloranta, Maija-Leena
Grosso, Giorgia
Sjöwall, Christopher
Bengtsson, Anders A.
Jönsen, Andreas
Gunnarsson, Iva
Svenungsson, Elisabet
Rönnblom, Lars
Sandling, Johanna K.
Syvänen, Ann-Christine
author_facet Almlöf, Jonas Carlsson
Nystedt, Sara
Mechtidou, Aikaterini
Leonard, Dag
Eloranta, Maija-Leena
Grosso, Giorgia
Sjöwall, Christopher
Bengtsson, Anders A.
Jönsen, Andreas
Gunnarsson, Iva
Svenungsson, Elisabet
Rönnblom, Lars
Sandling, Johanna K.
Syvänen, Ann-Christine
author_sort Almlöf, Jonas Carlsson
collection PubMed
description By performing whole-genome sequencing in a Swedish cohort of 71 parent-offspring trios, in which the child in each family is affected by systemic lupus erythematosus (SLE, OMIM 152700), we investigated the contribution of de novo variants to risk of SLE. We found de novo single nucleotide variants (SNVs) to be significantly enriched in gene promoters in SLE patients compared with healthy controls at a level corresponding to 26 de novo promoter SNVs more in each patient than expected. We identified 12 de novo SNVs in promoter regions of genes that have been previously implicated in SLE, or that have functions that could be of relevance to SLE. Furthermore, we detected three missense de novo SNVs, five de novo insertion-deletions, and three de novo structural variants with potential to affect the expression of genes that are relevant for SLE. Based on enrichment analysis, disease-affecting de novo SNVs are expected to occur in one-third of SLE patients. This study shows that de novo variants in promoters commonly contribute to the genetic risk of SLE. The fact that de novo SNVs in SLE were enriched to promoter regions highlights the importance of using whole-genome sequencing for identification of de novo variants.
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spelling pubmed-78525302021-02-08 Contributions of de novo variants to systemic lupus erythematosus Almlöf, Jonas Carlsson Nystedt, Sara Mechtidou, Aikaterini Leonard, Dag Eloranta, Maija-Leena Grosso, Giorgia Sjöwall, Christopher Bengtsson, Anders A. Jönsen, Andreas Gunnarsson, Iva Svenungsson, Elisabet Rönnblom, Lars Sandling, Johanna K. Syvänen, Ann-Christine Eur J Hum Genet Article By performing whole-genome sequencing in a Swedish cohort of 71 parent-offspring trios, in which the child in each family is affected by systemic lupus erythematosus (SLE, OMIM 152700), we investigated the contribution of de novo variants to risk of SLE. We found de novo single nucleotide variants (SNVs) to be significantly enriched in gene promoters in SLE patients compared with healthy controls at a level corresponding to 26 de novo promoter SNVs more in each patient than expected. We identified 12 de novo SNVs in promoter regions of genes that have been previously implicated in SLE, or that have functions that could be of relevance to SLE. Furthermore, we detected three missense de novo SNVs, five de novo insertion-deletions, and three de novo structural variants with potential to affect the expression of genes that are relevant for SLE. Based on enrichment analysis, disease-affecting de novo SNVs are expected to occur in one-third of SLE patients. This study shows that de novo variants in promoters commonly contribute to the genetic risk of SLE. The fact that de novo SNVs in SLE were enriched to promoter regions highlights the importance of using whole-genome sequencing for identification of de novo variants. Springer International Publishing 2020-07-28 2021-01 /pmc/articles/PMC7852530/ /pubmed/32724065 http://dx.doi.org/10.1038/s41431-020-0698-5 Text en © The Author(s) 2020 Open Access This article is licensed under a Creative Commons Attribution 4.0 International License, which permits use, sharing, adaptation, distribution and reproduction in any medium or format, as long as you give appropriate credit to the original author(s) and the source, provide a link to the Creative Commons license, and indicate if changes were made. The images or other third party material in this article are included in the article’s Creative Commons license, unless indicated otherwise in a credit line to the material. If material is not included in the article’s Creative Commons license and your intended use is not permitted by statutory regulation or exceeds the permitted use, you will need to obtain permission directly from the copyright holder. To view a copy of this license, visit http://creativecommons.org/licenses/by/4.0/.
spellingShingle Article
Almlöf, Jonas Carlsson
Nystedt, Sara
Mechtidou, Aikaterini
Leonard, Dag
Eloranta, Maija-Leena
Grosso, Giorgia
Sjöwall, Christopher
Bengtsson, Anders A.
Jönsen, Andreas
Gunnarsson, Iva
Svenungsson, Elisabet
Rönnblom, Lars
Sandling, Johanna K.
Syvänen, Ann-Christine
Contributions of de novo variants to systemic lupus erythematosus
title Contributions of de novo variants to systemic lupus erythematosus
title_full Contributions of de novo variants to systemic lupus erythematosus
title_fullStr Contributions of de novo variants to systemic lupus erythematosus
title_full_unstemmed Contributions of de novo variants to systemic lupus erythematosus
title_short Contributions of de novo variants to systemic lupus erythematosus
title_sort contributions of de novo variants to systemic lupus erythematosus
topic Article
url https://www.ncbi.nlm.nih.gov/pmc/articles/PMC7852530/
https://www.ncbi.nlm.nih.gov/pubmed/32724065
http://dx.doi.org/10.1038/s41431-020-0698-5
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