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Renal Damage in Recurrent Atypical Hemolytic Uremic Syndrome Associated with C3 p.Ile1157Thr Gene Mutation

Patients with atypical hemolytic uremic syndrome (aHUS) associated with a C3 p.Ile1157Thr mutation show a relatively high renal survival and low mortality rates, but renal histopathological findings after recurrence have been rarely reported. A 30-year-old man with a C3 p.Ile1157Thr mutation experie...

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Autores principales: Okabe, Masahiro, Kobayashi, Arisa, Marumoto, Hirokazu, Koike, Kentaro, Yamamoto, Izumi, Kawamura, Tetsuya, Tsuboi, Nobuo, Yokoo, Takashi
Formato: Online Artículo Texto
Lenguaje:English
Publicado: The Japanese Society of Internal Medicine 2020
Materias:
Acceso en línea:https://www.ncbi.nlm.nih.gov/pmc/articles/PMC8024950/
https://www.ncbi.nlm.nih.gov/pubmed/33087669
http://dx.doi.org/10.2169/internalmedicine.5716-20
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author Okabe, Masahiro
Kobayashi, Arisa
Marumoto, Hirokazu
Koike, Kentaro
Yamamoto, Izumi
Kawamura, Tetsuya
Tsuboi, Nobuo
Yokoo, Takashi
author_facet Okabe, Masahiro
Kobayashi, Arisa
Marumoto, Hirokazu
Koike, Kentaro
Yamamoto, Izumi
Kawamura, Tetsuya
Tsuboi, Nobuo
Yokoo, Takashi
author_sort Okabe, Masahiro
collection PubMed
description Patients with atypical hemolytic uremic syndrome (aHUS) associated with a C3 p.Ile1157Thr mutation show a relatively high renal survival and low mortality rates, but renal histopathological findings after recurrence have been rarely reported. A 30-year-old man with a C3 p.Ile1157Thr mutation experienced a third recurrence of thrombotic microangiopathies with neurological and gastrointestinal disorders. A renal biopsy performed during the recovery phase of acute kidney injury revealed collapsed glomeruli and arteriolar vacuolization. Approximately 10% of glomeruli were globally sclerotic, despite the absence of arterio-/arteriolo-sclerosis. These findings suggest substantial progression of irreversible injuries in multiple organs, including kidneys, which occurs in aHUS patients with repeated thrombotic microangiopathies.
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spelling pubmed-80249502021-04-15 Renal Damage in Recurrent Atypical Hemolytic Uremic Syndrome Associated with C3 p.Ile1157Thr Gene Mutation Okabe, Masahiro Kobayashi, Arisa Marumoto, Hirokazu Koike, Kentaro Yamamoto, Izumi Kawamura, Tetsuya Tsuboi, Nobuo Yokoo, Takashi Intern Med Case Report Patients with atypical hemolytic uremic syndrome (aHUS) associated with a C3 p.Ile1157Thr mutation show a relatively high renal survival and low mortality rates, but renal histopathological findings after recurrence have been rarely reported. A 30-year-old man with a C3 p.Ile1157Thr mutation experienced a third recurrence of thrombotic microangiopathies with neurological and gastrointestinal disorders. A renal biopsy performed during the recovery phase of acute kidney injury revealed collapsed glomeruli and arteriolar vacuolization. Approximately 10% of glomeruli were globally sclerotic, despite the absence of arterio-/arteriolo-sclerosis. These findings suggest substantial progression of irreversible injuries in multiple organs, including kidneys, which occurs in aHUS patients with repeated thrombotic microangiopathies. The Japanese Society of Internal Medicine 2020-10-21 2021-03-15 /pmc/articles/PMC8024950/ /pubmed/33087669 http://dx.doi.org/10.2169/internalmedicine.5716-20 Text en Copyright © 2021 by The Japanese Society of Internal Medicine https://creativecommons.org/licenses/by-nc-nd/4.0/ The Internal Medicine is an Open Access journal distributed under the Creative Commons Attribution-NonCommercial-NoDerivatives 4.0 International License. To view the details of this license, please visit (https://creativecommons.org/licenses/by-nc-nd/4.0/).
spellingShingle Case Report
Okabe, Masahiro
Kobayashi, Arisa
Marumoto, Hirokazu
Koike, Kentaro
Yamamoto, Izumi
Kawamura, Tetsuya
Tsuboi, Nobuo
Yokoo, Takashi
Renal Damage in Recurrent Atypical Hemolytic Uremic Syndrome Associated with C3 p.Ile1157Thr Gene Mutation
title Renal Damage in Recurrent Atypical Hemolytic Uremic Syndrome Associated with C3 p.Ile1157Thr Gene Mutation
title_full Renal Damage in Recurrent Atypical Hemolytic Uremic Syndrome Associated with C3 p.Ile1157Thr Gene Mutation
title_fullStr Renal Damage in Recurrent Atypical Hemolytic Uremic Syndrome Associated with C3 p.Ile1157Thr Gene Mutation
title_full_unstemmed Renal Damage in Recurrent Atypical Hemolytic Uremic Syndrome Associated with C3 p.Ile1157Thr Gene Mutation
title_short Renal Damage in Recurrent Atypical Hemolytic Uremic Syndrome Associated with C3 p.Ile1157Thr Gene Mutation
title_sort renal damage in recurrent atypical hemolytic uremic syndrome associated with c3 p.ile1157thr gene mutation
topic Case Report
url https://www.ncbi.nlm.nih.gov/pmc/articles/PMC8024950/
https://www.ncbi.nlm.nih.gov/pubmed/33087669
http://dx.doi.org/10.2169/internalmedicine.5716-20
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