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Renal Damage in Recurrent Atypical Hemolytic Uremic Syndrome Associated with C3 p.Ile1157Thr Gene Mutation
Patients with atypical hemolytic uremic syndrome (aHUS) associated with a C3 p.Ile1157Thr mutation show a relatively high renal survival and low mortality rates, but renal histopathological findings after recurrence have been rarely reported. A 30-year-old man with a C3 p.Ile1157Thr mutation experie...
Autores principales: | , , , , , , , |
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Formato: | Online Artículo Texto |
Lenguaje: | English |
Publicado: |
The Japanese Society of Internal Medicine
2020
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Materias: | |
Acceso en línea: | https://www.ncbi.nlm.nih.gov/pmc/articles/PMC8024950/ https://www.ncbi.nlm.nih.gov/pubmed/33087669 http://dx.doi.org/10.2169/internalmedicine.5716-20 |
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author | Okabe, Masahiro Kobayashi, Arisa Marumoto, Hirokazu Koike, Kentaro Yamamoto, Izumi Kawamura, Tetsuya Tsuboi, Nobuo Yokoo, Takashi |
author_facet | Okabe, Masahiro Kobayashi, Arisa Marumoto, Hirokazu Koike, Kentaro Yamamoto, Izumi Kawamura, Tetsuya Tsuboi, Nobuo Yokoo, Takashi |
author_sort | Okabe, Masahiro |
collection | PubMed |
description | Patients with atypical hemolytic uremic syndrome (aHUS) associated with a C3 p.Ile1157Thr mutation show a relatively high renal survival and low mortality rates, but renal histopathological findings after recurrence have been rarely reported. A 30-year-old man with a C3 p.Ile1157Thr mutation experienced a third recurrence of thrombotic microangiopathies with neurological and gastrointestinal disorders. A renal biopsy performed during the recovery phase of acute kidney injury revealed collapsed glomeruli and arteriolar vacuolization. Approximately 10% of glomeruli were globally sclerotic, despite the absence of arterio-/arteriolo-sclerosis. These findings suggest substantial progression of irreversible injuries in multiple organs, including kidneys, which occurs in aHUS patients with repeated thrombotic microangiopathies. |
format | Online Article Text |
id | pubmed-8024950 |
institution | National Center for Biotechnology Information |
language | English |
publishDate | 2020 |
publisher | The Japanese Society of Internal Medicine |
record_format | MEDLINE/PubMed |
spelling | pubmed-80249502021-04-15 Renal Damage in Recurrent Atypical Hemolytic Uremic Syndrome Associated with C3 p.Ile1157Thr Gene Mutation Okabe, Masahiro Kobayashi, Arisa Marumoto, Hirokazu Koike, Kentaro Yamamoto, Izumi Kawamura, Tetsuya Tsuboi, Nobuo Yokoo, Takashi Intern Med Case Report Patients with atypical hemolytic uremic syndrome (aHUS) associated with a C3 p.Ile1157Thr mutation show a relatively high renal survival and low mortality rates, but renal histopathological findings after recurrence have been rarely reported. A 30-year-old man with a C3 p.Ile1157Thr mutation experienced a third recurrence of thrombotic microangiopathies with neurological and gastrointestinal disorders. A renal biopsy performed during the recovery phase of acute kidney injury revealed collapsed glomeruli and arteriolar vacuolization. Approximately 10% of glomeruli were globally sclerotic, despite the absence of arterio-/arteriolo-sclerosis. These findings suggest substantial progression of irreversible injuries in multiple organs, including kidneys, which occurs in aHUS patients with repeated thrombotic microangiopathies. The Japanese Society of Internal Medicine 2020-10-21 2021-03-15 /pmc/articles/PMC8024950/ /pubmed/33087669 http://dx.doi.org/10.2169/internalmedicine.5716-20 Text en Copyright © 2021 by The Japanese Society of Internal Medicine https://creativecommons.org/licenses/by-nc-nd/4.0/ The Internal Medicine is an Open Access journal distributed under the Creative Commons Attribution-NonCommercial-NoDerivatives 4.0 International License. To view the details of this license, please visit (https://creativecommons.org/licenses/by-nc-nd/4.0/). |
spellingShingle | Case Report Okabe, Masahiro Kobayashi, Arisa Marumoto, Hirokazu Koike, Kentaro Yamamoto, Izumi Kawamura, Tetsuya Tsuboi, Nobuo Yokoo, Takashi Renal Damage in Recurrent Atypical Hemolytic Uremic Syndrome Associated with C3 p.Ile1157Thr Gene Mutation |
title | Renal Damage in Recurrent Atypical Hemolytic Uremic Syndrome Associated with C3 p.Ile1157Thr Gene Mutation |
title_full | Renal Damage in Recurrent Atypical Hemolytic Uremic Syndrome Associated with C3 p.Ile1157Thr Gene Mutation |
title_fullStr | Renal Damage in Recurrent Atypical Hemolytic Uremic Syndrome Associated with C3 p.Ile1157Thr Gene Mutation |
title_full_unstemmed | Renal Damage in Recurrent Atypical Hemolytic Uremic Syndrome Associated with C3 p.Ile1157Thr Gene Mutation |
title_short | Renal Damage in Recurrent Atypical Hemolytic Uremic Syndrome Associated with C3 p.Ile1157Thr Gene Mutation |
title_sort | renal damage in recurrent atypical hemolytic uremic syndrome associated with c3 p.ile1157thr gene mutation |
topic | Case Report |
url | https://www.ncbi.nlm.nih.gov/pmc/articles/PMC8024950/ https://www.ncbi.nlm.nih.gov/pubmed/33087669 http://dx.doi.org/10.2169/internalmedicine.5716-20 |
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