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Genetic inactivation of RIP1 kinase activity in rats protects against ischemic brain injury
RIP1 kinase-mediated inflammatory and cell death pathways have been implicated in the pathology of acute and chronic disorders of the nervous system. Here, we describe a novel animal model of RIP1 kinase deficiency, generated by knock-in of the kinase-inactivating RIP1(D138N) mutation in rats. Homoz...
Autores principales: | , , , , , , , , , , , , , , |
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Formato: | Online Artículo Texto |
Lenguaje: | English |
Publicado: |
Nature Publishing Group UK
2021
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Materias: | |
Acceso en línea: | https://www.ncbi.nlm.nih.gov/pmc/articles/PMC8026634/ https://www.ncbi.nlm.nih.gov/pubmed/33828080 http://dx.doi.org/10.1038/s41419-021-03651-6 |
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author | Stark, Kimberly Goncharov, Tatiana Varfolomeev, Eugene Xie, Luke Ngu, Hai Peng, Ivan Anderson, Keith R. Verschueren, Erik Choi, Meena Kirkpatrick, Donald S. Easton, Amy Webster, Joshua D. McKenzie, Brent S. Vucic, Domagoj Bingol, Baris |
author_facet | Stark, Kimberly Goncharov, Tatiana Varfolomeev, Eugene Xie, Luke Ngu, Hai Peng, Ivan Anderson, Keith R. Verschueren, Erik Choi, Meena Kirkpatrick, Donald S. Easton, Amy Webster, Joshua D. McKenzie, Brent S. Vucic, Domagoj Bingol, Baris |
author_sort | Stark, Kimberly |
collection | PubMed |
description | RIP1 kinase-mediated inflammatory and cell death pathways have been implicated in the pathology of acute and chronic disorders of the nervous system. Here, we describe a novel animal model of RIP1 kinase deficiency, generated by knock-in of the kinase-inactivating RIP1(D138N) mutation in rats. Homozygous RIP1 kinase-dead (KD) rats had normal development, reproduction and did not show any gross phenotypes at baseline. However, cells derived from RIP1 KD rats displayed resistance to necroptotic cell death. In addition, RIP1 KD rats were resistant to TNF-induced systemic shock. We studied the utility of RIP1 KD rats for neurological disorders by testing the efficacy of the genetic inactivation in the transient middle cerebral artery occlusion/reperfusion model of brain injury. RIP1 KD rats were protected in this model in a battery of behavioral, imaging, and histopathological endpoints. In addition, RIP1 KD rats had reduced inflammation and accumulation of neuronal injury biomarkers. Unbiased proteomics in the plasma identified additional changes that were ameliorated by RIP1 genetic inactivation. Together these data highlight the utility of the RIP1 KD rats for target validation and biomarker studies for neurological disorders. |
format | Online Article Text |
id | pubmed-8026634 |
institution | National Center for Biotechnology Information |
language | English |
publishDate | 2021 |
publisher | Nature Publishing Group UK |
record_format | MEDLINE/PubMed |
spelling | pubmed-80266342021-04-21 Genetic inactivation of RIP1 kinase activity in rats protects against ischemic brain injury Stark, Kimberly Goncharov, Tatiana Varfolomeev, Eugene Xie, Luke Ngu, Hai Peng, Ivan Anderson, Keith R. Verschueren, Erik Choi, Meena Kirkpatrick, Donald S. Easton, Amy Webster, Joshua D. McKenzie, Brent S. Vucic, Domagoj Bingol, Baris Cell Death Dis Article RIP1 kinase-mediated inflammatory and cell death pathways have been implicated in the pathology of acute and chronic disorders of the nervous system. Here, we describe a novel animal model of RIP1 kinase deficiency, generated by knock-in of the kinase-inactivating RIP1(D138N) mutation in rats. Homozygous RIP1 kinase-dead (KD) rats had normal development, reproduction and did not show any gross phenotypes at baseline. However, cells derived from RIP1 KD rats displayed resistance to necroptotic cell death. In addition, RIP1 KD rats were resistant to TNF-induced systemic shock. We studied the utility of RIP1 KD rats for neurological disorders by testing the efficacy of the genetic inactivation in the transient middle cerebral artery occlusion/reperfusion model of brain injury. RIP1 KD rats were protected in this model in a battery of behavioral, imaging, and histopathological endpoints. In addition, RIP1 KD rats had reduced inflammation and accumulation of neuronal injury biomarkers. Unbiased proteomics in the plasma identified additional changes that were ameliorated by RIP1 genetic inactivation. Together these data highlight the utility of the RIP1 KD rats for target validation and biomarker studies for neurological disorders. Nature Publishing Group UK 2021-04-07 /pmc/articles/PMC8026634/ /pubmed/33828080 http://dx.doi.org/10.1038/s41419-021-03651-6 Text en © The Author(s) 2021 Open Access This article is licensed under a Creative Commons Attribution 4.0 International License, which permits use, sharing, adaptation, distribution and reproduction in any medium or format, as long as you give appropriate credit to the original author(s) and the source, provide a link to the Creative Commons license, and indicate if changes were made. The images or other third party material in this article are included in the article’s Creative Commons license, unless indicated otherwise in a credit line to the material. If material is not included in the article’s Creative Commons license and your intended use is not permitted by statutory regulation or exceeds the permitted use, you will need to obtain permission directly from the copyright holder. To view a copy of this license, visit http://creativecommons.org/licenses/by/4.0/. |
spellingShingle | Article Stark, Kimberly Goncharov, Tatiana Varfolomeev, Eugene Xie, Luke Ngu, Hai Peng, Ivan Anderson, Keith R. Verschueren, Erik Choi, Meena Kirkpatrick, Donald S. Easton, Amy Webster, Joshua D. McKenzie, Brent S. Vucic, Domagoj Bingol, Baris Genetic inactivation of RIP1 kinase activity in rats protects against ischemic brain injury |
title | Genetic inactivation of RIP1 kinase activity in rats protects against ischemic brain injury |
title_full | Genetic inactivation of RIP1 kinase activity in rats protects against ischemic brain injury |
title_fullStr | Genetic inactivation of RIP1 kinase activity in rats protects against ischemic brain injury |
title_full_unstemmed | Genetic inactivation of RIP1 kinase activity in rats protects against ischemic brain injury |
title_short | Genetic inactivation of RIP1 kinase activity in rats protects against ischemic brain injury |
title_sort | genetic inactivation of rip1 kinase activity in rats protects against ischemic brain injury |
topic | Article |
url | https://www.ncbi.nlm.nih.gov/pmc/articles/PMC8026634/ https://www.ncbi.nlm.nih.gov/pubmed/33828080 http://dx.doi.org/10.1038/s41419-021-03651-6 |
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