Cargando…

Enamel Renal Syndrome: A Systematic Review

The enamel renal syndrome (ERS) is a rare autosomal recessive disease that is associated with mutations in the FAM20A gene. The syndrome is characterized by impaired amelogenesis of the hypoplastic type and nephrocalcinosis, presenting with presence of thin or absence of enamel, late dental eruption...

Descripción completa

Detalles Bibliográficos
Autores principales: Farias, Maria Luiza Morais, Ornela, Gabriela Oliveira, de Andrade, Rodrigo Soares, Martelli, Daniella Reis B., Dias, Verônica Oliveira, Júnior, Hercílio Martelli
Formato: Online Artículo Texto
Lenguaje:English
Publicado: Wolters Kluwer - Medknow 2021
Materias:
Acceso en línea:https://www.ncbi.nlm.nih.gov/pmc/articles/PMC8101666/
https://www.ncbi.nlm.nih.gov/pubmed/33994680
http://dx.doi.org/10.4103/ijn.IJN_27_19
_version_ 1783688990443962368
author Farias, Maria Luiza Morais
Ornela, Gabriela Oliveira
de Andrade, Rodrigo Soares
Martelli, Daniella Reis B.
Dias, Verônica Oliveira
Júnior, Hercílio Martelli
author_facet Farias, Maria Luiza Morais
Ornela, Gabriela Oliveira
de Andrade, Rodrigo Soares
Martelli, Daniella Reis B.
Dias, Verônica Oliveira
Júnior, Hercílio Martelli
author_sort Farias, Maria Luiza Morais
collection PubMed
description The enamel renal syndrome (ERS) is a rare autosomal recessive disease that is associated with mutations in the FAM20A gene. The syndrome is characterized by impaired amelogenesis of the hypoplastic type and nephrocalcinosis, presenting with presence of thin or absence of enamel, late dental eruption, intrapulpal calcifications, bilateral nephrocalcinosis, and normal plasma calcium level. The objective is to characterize ERS by systematically literature reviewing, highlighting the main findings of the syndrome to increase knowledge about this condition in the health professionals. The study is a systematic review of the scientific literature, whose research was developed in the PubMed database in March 2018. A total of 69 articles were found. Two authors analyzed their abstracts and selected, according to the language and main subject, 30 articles to write this study. A total of 69 patients were cited in the studies and their data were analysed. There was gender equivalence and the ages ranged from 1 to 64 years old. There is a clear hereditary relation of the syndrome, since there was consanguinity in 18 cases, indicating a percentage of 26.08% and family history in 30 cases (43.47%). Laboratory changes vary greatly from patient to patient and may even remain unchanged. The relationship between the syndrome and the mutation in the FAM20A gene can be proven from the data, since all patients with ERS screened by the mutation were positive. With the advancement of the ERS studies, some associations with the syndrome are suspected, such as the presence of gingival fibromatosis, hearing loss, and hypertrichosis. Thus, it is noticed that the syndrome does not show a predilection for gender or age and there is a strong hereditary character, marked by the consanguinity and family history of the patients. The association with the FAM20A gene is reinforced, since the mutation was identified in all patients analyzed.
format Online
Article
Text
id pubmed-8101666
institution National Center for Biotechnology Information
language English
publishDate 2021
publisher Wolters Kluwer - Medknow
record_format MEDLINE/PubMed
spelling pubmed-81016662021-05-13 Enamel Renal Syndrome: A Systematic Review Farias, Maria Luiza Morais Ornela, Gabriela Oliveira de Andrade, Rodrigo Soares Martelli, Daniella Reis B. Dias, Verônica Oliveira Júnior, Hercílio Martelli Indian J Nephrol Review Article The enamel renal syndrome (ERS) is a rare autosomal recessive disease that is associated with mutations in the FAM20A gene. The syndrome is characterized by impaired amelogenesis of the hypoplastic type and nephrocalcinosis, presenting with presence of thin or absence of enamel, late dental eruption, intrapulpal calcifications, bilateral nephrocalcinosis, and normal plasma calcium level. The objective is to characterize ERS by systematically literature reviewing, highlighting the main findings of the syndrome to increase knowledge about this condition in the health professionals. The study is a systematic review of the scientific literature, whose research was developed in the PubMed database in March 2018. A total of 69 articles were found. Two authors analyzed their abstracts and selected, according to the language and main subject, 30 articles to write this study. A total of 69 patients were cited in the studies and their data were analysed. There was gender equivalence and the ages ranged from 1 to 64 years old. There is a clear hereditary relation of the syndrome, since there was consanguinity in 18 cases, indicating a percentage of 26.08% and family history in 30 cases (43.47%). Laboratory changes vary greatly from patient to patient and may even remain unchanged. The relationship between the syndrome and the mutation in the FAM20A gene can be proven from the data, since all patients with ERS screened by the mutation were positive. With the advancement of the ERS studies, some associations with the syndrome are suspected, such as the presence of gingival fibromatosis, hearing loss, and hypertrichosis. Thus, it is noticed that the syndrome does not show a predilection for gender or age and there is a strong hereditary character, marked by the consanguinity and family history of the patients. The association with the FAM20A gene is reinforced, since the mutation was identified in all patients analyzed. Wolters Kluwer - Medknow 2021 2021-01-27 /pmc/articles/PMC8101666/ /pubmed/33994680 http://dx.doi.org/10.4103/ijn.IJN_27_19 Text en Copyright: © 2021 Indian Journal of Nephrology https://creativecommons.org/licenses/by-nc-sa/4.0/This is an open access journal, and articles are distributed under the terms of the Creative Commons Attribution-NonCommercial-ShareAlike 4.0 License, which allows others to remix, tweak, and build upon the work non-commercially, as long as appropriate credit is given and the new creations are licensed under the identical terms.
spellingShingle Review Article
Farias, Maria Luiza Morais
Ornela, Gabriela Oliveira
de Andrade, Rodrigo Soares
Martelli, Daniella Reis B.
Dias, Verônica Oliveira
Júnior, Hercílio Martelli
Enamel Renal Syndrome: A Systematic Review
title Enamel Renal Syndrome: A Systematic Review
title_full Enamel Renal Syndrome: A Systematic Review
title_fullStr Enamel Renal Syndrome: A Systematic Review
title_full_unstemmed Enamel Renal Syndrome: A Systematic Review
title_short Enamel Renal Syndrome: A Systematic Review
title_sort enamel renal syndrome: a systematic review
topic Review Article
url https://www.ncbi.nlm.nih.gov/pmc/articles/PMC8101666/
https://www.ncbi.nlm.nih.gov/pubmed/33994680
http://dx.doi.org/10.4103/ijn.IJN_27_19
work_keys_str_mv AT fariasmarialuizamorais enamelrenalsyndromeasystematicreview
AT ornelagabrielaoliveira enamelrenalsyndromeasystematicreview
AT deandraderodrigosoares enamelrenalsyndromeasystematicreview
AT martellidaniellareisb enamelrenalsyndromeasystematicreview
AT diasveronicaoliveira enamelrenalsyndromeasystematicreview
AT juniorherciliomartelli enamelrenalsyndromeasystematicreview