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Seromucinous hamartoma of ethmoid sinus in pediatric patient (case report)

INTRODUCTION AND IMPORTANCE: Seromucinous hamartoma is a rare benign glandular proliferation arising from the respiratory epithelium, which was originally described by Baillie and Batsakis in 1974. Since this time, case reports started to be published on SH, as a middle aged and elderly disease, her...

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Autores principales: Alokby, Ghassan, Alayed, Rawan S., Al Fayez, Jude B.
Formato: Online Artículo Texto
Lenguaje:English
Publicado: Elsevier 2021
Materias:
Acceso en línea:https://www.ncbi.nlm.nih.gov/pmc/articles/PMC8113836/
https://www.ncbi.nlm.nih.gov/pubmed/33957404
http://dx.doi.org/10.1016/j.ijscr.2021.105915
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author Alokby, Ghassan
Alayed, Rawan S.
Al Fayez, Jude B.
author_facet Alokby, Ghassan
Alayed, Rawan S.
Al Fayez, Jude B.
author_sort Alokby, Ghassan
collection PubMed
description INTRODUCTION AND IMPORTANCE: Seromucinous hamartoma is a rare benign glandular proliferation arising from the respiratory epithelium, which was originally described by Baillie and Batsakis in 1974. Since this time, case reports started to be published on SH, as a middle aged and elderly disease, here we report a case of a pediatric patient who found to have SH. PRESENTATION OF THE CASE: 2-year-old girl, brought by her parent with a complain of a mass at the right medial canthal area for one year. CLINICAL DISCUSSION: As this pediatric patient presented with long standing history of right medial canthal area, we made out differential diagnosis list, with keeping congenital midline nasal masses such as nasal glioma, dermoid, and encephalocele at the top of our differentials, followed by inflammatory disease and lacreimal system disease. After bedside clinical assessment and imaging, patient underwent endoscopic sinus surgery for surgical excision, histopathology analysis came as Seromucinous hamartoma. Postoperative course was unremarkable, patient is disease- free for 18 months, till her most recent follow up. With no additional treatment or recurrence. CONCLUSION: This case report indicates that seromucinous hamartoma should always be considered in the differential diagnosis of pediatric sinonasal disease. According to the literature review we did; this is the first case reported in such an age group.
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spelling pubmed-81138362021-05-18 Seromucinous hamartoma of ethmoid sinus in pediatric patient (case report) Alokby, Ghassan Alayed, Rawan S. Al Fayez, Jude B. Int J Surg Case Rep Case Report INTRODUCTION AND IMPORTANCE: Seromucinous hamartoma is a rare benign glandular proliferation arising from the respiratory epithelium, which was originally described by Baillie and Batsakis in 1974. Since this time, case reports started to be published on SH, as a middle aged and elderly disease, here we report a case of a pediatric patient who found to have SH. PRESENTATION OF THE CASE: 2-year-old girl, brought by her parent with a complain of a mass at the right medial canthal area for one year. CLINICAL DISCUSSION: As this pediatric patient presented with long standing history of right medial canthal area, we made out differential diagnosis list, with keeping congenital midline nasal masses such as nasal glioma, dermoid, and encephalocele at the top of our differentials, followed by inflammatory disease and lacreimal system disease. After bedside clinical assessment and imaging, patient underwent endoscopic sinus surgery for surgical excision, histopathology analysis came as Seromucinous hamartoma. Postoperative course was unremarkable, patient is disease- free for 18 months, till her most recent follow up. With no additional treatment or recurrence. CONCLUSION: This case report indicates that seromucinous hamartoma should always be considered in the differential diagnosis of pediatric sinonasal disease. According to the literature review we did; this is the first case reported in such an age group. Elsevier 2021-04-27 /pmc/articles/PMC8113836/ /pubmed/33957404 http://dx.doi.org/10.1016/j.ijscr.2021.105915 Text en © 2021 The Authors https://creativecommons.org/licenses/by-nc-nd/4.0/This is an open access article under the CC BY-NC-ND license (http://creativecommons.org/licenses/by-nc-nd/4.0/).
spellingShingle Case Report
Alokby, Ghassan
Alayed, Rawan S.
Al Fayez, Jude B.
Seromucinous hamartoma of ethmoid sinus in pediatric patient (case report)
title Seromucinous hamartoma of ethmoid sinus in pediatric patient (case report)
title_full Seromucinous hamartoma of ethmoid sinus in pediatric patient (case report)
title_fullStr Seromucinous hamartoma of ethmoid sinus in pediatric patient (case report)
title_full_unstemmed Seromucinous hamartoma of ethmoid sinus in pediatric patient (case report)
title_short Seromucinous hamartoma of ethmoid sinus in pediatric patient (case report)
title_sort seromucinous hamartoma of ethmoid sinus in pediatric patient (case report)
topic Case Report
url https://www.ncbi.nlm.nih.gov/pmc/articles/PMC8113836/
https://www.ncbi.nlm.nih.gov/pubmed/33957404
http://dx.doi.org/10.1016/j.ijscr.2021.105915
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