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Case Report: SATB2-Associated Syndrome Overlapping With Clinical Mitochondrial Disease Presentation: Report of Two Cases
SATB2-associated syndrome (SAS) is an autosomal dominant neurogenetic multisystemic disorder. We describe two individuals with global developmental delay and hypotonia who underwent an extensive evaluation to rule out an underlying mitochondrial disorder before their eventual diagnosis of SAS. Altho...
Autores principales: | , , , , , , , , , |
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Formato: | Online Artículo Texto |
Lenguaje: | English |
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Frontiers Media S.A.
2021
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Materias: | |
Acceso en línea: | https://www.ncbi.nlm.nih.gov/pmc/articles/PMC8257052/ https://www.ncbi.nlm.nih.gov/pubmed/34234817 http://dx.doi.org/10.3389/fgene.2021.692087 |
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author | Zarate, Yuri A. Vernon, Hilary J. Bosanko, Katherine A. Ramani, Praveen K. Gokden, Murat Writzl, Karin Meznaric, Marija Vipotnik Vesnaver, Tina Ramakrishnaiah, Raghu Osredkar, Damjan |
author_facet | Zarate, Yuri A. Vernon, Hilary J. Bosanko, Katherine A. Ramani, Praveen K. Gokden, Murat Writzl, Karin Meznaric, Marija Vipotnik Vesnaver, Tina Ramakrishnaiah, Raghu Osredkar, Damjan |
author_sort | Zarate, Yuri A. |
collection | PubMed |
description | SATB2-associated syndrome (SAS) is an autosomal dominant neurogenetic multisystemic disorder. We describe two individuals with global developmental delay and hypotonia who underwent an extensive evaluation to rule out an underlying mitochondrial disorder before their eventual diagnosis of SAS. Although the strict application of the clinical mitochondrial disease score only led to the designation of “possible” mitochondrial disorder for these two individuals, other documented abnormalities included nonspecific neuroimaging findings on magnetic resonance imaging and magnetic resonance spectroscopy, decreased complex I activity on muscle biopsy for patient 2, and variation in the size and relative proportion of types of muscle fibers in the muscle biopsies that were aligned with mitochondrial diseases. SAS should be in the differential diagnoses of mitochondrial disorders, and broad-spectrum diagnostic tests such as exome sequencing need to be considered early in the evaluation process of undiagnosed neurodevelopmental disorders. |
format | Online Article Text |
id | pubmed-8257052 |
institution | National Center for Biotechnology Information |
language | English |
publishDate | 2021 |
publisher | Frontiers Media S.A. |
record_format | MEDLINE/PubMed |
spelling | pubmed-82570522021-07-06 Case Report: SATB2-Associated Syndrome Overlapping With Clinical Mitochondrial Disease Presentation: Report of Two Cases Zarate, Yuri A. Vernon, Hilary J. Bosanko, Katherine A. Ramani, Praveen K. Gokden, Murat Writzl, Karin Meznaric, Marija Vipotnik Vesnaver, Tina Ramakrishnaiah, Raghu Osredkar, Damjan Front Genet Genetics SATB2-associated syndrome (SAS) is an autosomal dominant neurogenetic multisystemic disorder. We describe two individuals with global developmental delay and hypotonia who underwent an extensive evaluation to rule out an underlying mitochondrial disorder before their eventual diagnosis of SAS. Although the strict application of the clinical mitochondrial disease score only led to the designation of “possible” mitochondrial disorder for these two individuals, other documented abnormalities included nonspecific neuroimaging findings on magnetic resonance imaging and magnetic resonance spectroscopy, decreased complex I activity on muscle biopsy for patient 2, and variation in the size and relative proportion of types of muscle fibers in the muscle biopsies that were aligned with mitochondrial diseases. SAS should be in the differential diagnoses of mitochondrial disorders, and broad-spectrum diagnostic tests such as exome sequencing need to be considered early in the evaluation process of undiagnosed neurodevelopmental disorders. Frontiers Media S.A. 2021-06-21 /pmc/articles/PMC8257052/ /pubmed/34234817 http://dx.doi.org/10.3389/fgene.2021.692087 Text en Copyright © 2021 Zarate, Vernon, Bosanko, Ramani, Gokden, Writzl, Meznaric, Vipotnik Vesnaver, Ramakrishnaiah and Osredkar. https://creativecommons.org/licenses/by/4.0/This is an open-access article distributed under the terms of the Creative Commons Attribution License (CC BY). The use, distribution or reproduction in other forums is permitted, provided the original author(s) and the copyright owner(s) are credited and that the original publication in this journal is cited, in accordance with accepted academic practice. No use, distribution or reproduction is permitted which does not comply with these terms. |
spellingShingle | Genetics Zarate, Yuri A. Vernon, Hilary J. Bosanko, Katherine A. Ramani, Praveen K. Gokden, Murat Writzl, Karin Meznaric, Marija Vipotnik Vesnaver, Tina Ramakrishnaiah, Raghu Osredkar, Damjan Case Report: SATB2-Associated Syndrome Overlapping With Clinical Mitochondrial Disease Presentation: Report of Two Cases |
title | Case Report: SATB2-Associated Syndrome Overlapping With Clinical Mitochondrial Disease Presentation: Report of Two Cases |
title_full | Case Report: SATB2-Associated Syndrome Overlapping With Clinical Mitochondrial Disease Presentation: Report of Two Cases |
title_fullStr | Case Report: SATB2-Associated Syndrome Overlapping With Clinical Mitochondrial Disease Presentation: Report of Two Cases |
title_full_unstemmed | Case Report: SATB2-Associated Syndrome Overlapping With Clinical Mitochondrial Disease Presentation: Report of Two Cases |
title_short | Case Report: SATB2-Associated Syndrome Overlapping With Clinical Mitochondrial Disease Presentation: Report of Two Cases |
title_sort | case report: satb2-associated syndrome overlapping with clinical mitochondrial disease presentation: report of two cases |
topic | Genetics |
url | https://www.ncbi.nlm.nih.gov/pmc/articles/PMC8257052/ https://www.ncbi.nlm.nih.gov/pubmed/34234817 http://dx.doi.org/10.3389/fgene.2021.692087 |
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