Cargando…

Case Report: SATB2-Associated Syndrome Overlapping With Clinical Mitochondrial Disease Presentation: Report of Two Cases

SATB2-associated syndrome (SAS) is an autosomal dominant neurogenetic multisystemic disorder. We describe two individuals with global developmental delay and hypotonia who underwent an extensive evaluation to rule out an underlying mitochondrial disorder before their eventual diagnosis of SAS. Altho...

Descripción completa

Detalles Bibliográficos
Autores principales: Zarate, Yuri A., Vernon, Hilary J., Bosanko, Katherine A., Ramani, Praveen K., Gokden, Murat, Writzl, Karin, Meznaric, Marija, Vipotnik Vesnaver, Tina, Ramakrishnaiah, Raghu, Osredkar, Damjan
Formato: Online Artículo Texto
Lenguaje:English
Publicado: Frontiers Media S.A. 2021
Materias:
Acceso en línea:https://www.ncbi.nlm.nih.gov/pmc/articles/PMC8257052/
https://www.ncbi.nlm.nih.gov/pubmed/34234817
http://dx.doi.org/10.3389/fgene.2021.692087
_version_ 1783718224937877504
author Zarate, Yuri A.
Vernon, Hilary J.
Bosanko, Katherine A.
Ramani, Praveen K.
Gokden, Murat
Writzl, Karin
Meznaric, Marija
Vipotnik Vesnaver, Tina
Ramakrishnaiah, Raghu
Osredkar, Damjan
author_facet Zarate, Yuri A.
Vernon, Hilary J.
Bosanko, Katherine A.
Ramani, Praveen K.
Gokden, Murat
Writzl, Karin
Meznaric, Marija
Vipotnik Vesnaver, Tina
Ramakrishnaiah, Raghu
Osredkar, Damjan
author_sort Zarate, Yuri A.
collection PubMed
description SATB2-associated syndrome (SAS) is an autosomal dominant neurogenetic multisystemic disorder. We describe two individuals with global developmental delay and hypotonia who underwent an extensive evaluation to rule out an underlying mitochondrial disorder before their eventual diagnosis of SAS. Although the strict application of the clinical mitochondrial disease score only led to the designation of “possible” mitochondrial disorder for these two individuals, other documented abnormalities included nonspecific neuroimaging findings on magnetic resonance imaging and magnetic resonance spectroscopy, decreased complex I activity on muscle biopsy for patient 2, and variation in the size and relative proportion of types of muscle fibers in the muscle biopsies that were aligned with mitochondrial diseases. SAS should be in the differential diagnoses of mitochondrial disorders, and broad-spectrum diagnostic tests such as exome sequencing need to be considered early in the evaluation process of undiagnosed neurodevelopmental disorders.
format Online
Article
Text
id pubmed-8257052
institution National Center for Biotechnology Information
language English
publishDate 2021
publisher Frontiers Media S.A.
record_format MEDLINE/PubMed
spelling pubmed-82570522021-07-06 Case Report: SATB2-Associated Syndrome Overlapping With Clinical Mitochondrial Disease Presentation: Report of Two Cases Zarate, Yuri A. Vernon, Hilary J. Bosanko, Katherine A. Ramani, Praveen K. Gokden, Murat Writzl, Karin Meznaric, Marija Vipotnik Vesnaver, Tina Ramakrishnaiah, Raghu Osredkar, Damjan Front Genet Genetics SATB2-associated syndrome (SAS) is an autosomal dominant neurogenetic multisystemic disorder. We describe two individuals with global developmental delay and hypotonia who underwent an extensive evaluation to rule out an underlying mitochondrial disorder before their eventual diagnosis of SAS. Although the strict application of the clinical mitochondrial disease score only led to the designation of “possible” mitochondrial disorder for these two individuals, other documented abnormalities included nonspecific neuroimaging findings on magnetic resonance imaging and magnetic resonance spectroscopy, decreased complex I activity on muscle biopsy for patient 2, and variation in the size and relative proportion of types of muscle fibers in the muscle biopsies that were aligned with mitochondrial diseases. SAS should be in the differential diagnoses of mitochondrial disorders, and broad-spectrum diagnostic tests such as exome sequencing need to be considered early in the evaluation process of undiagnosed neurodevelopmental disorders. Frontiers Media S.A. 2021-06-21 /pmc/articles/PMC8257052/ /pubmed/34234817 http://dx.doi.org/10.3389/fgene.2021.692087 Text en Copyright © 2021 Zarate, Vernon, Bosanko, Ramani, Gokden, Writzl, Meznaric, Vipotnik Vesnaver, Ramakrishnaiah and Osredkar. https://creativecommons.org/licenses/by/4.0/This is an open-access article distributed under the terms of the Creative Commons Attribution License (CC BY). The use, distribution or reproduction in other forums is permitted, provided the original author(s) and the copyright owner(s) are credited and that the original publication in this journal is cited, in accordance with accepted academic practice. No use, distribution or reproduction is permitted which does not comply with these terms.
spellingShingle Genetics
Zarate, Yuri A.
Vernon, Hilary J.
Bosanko, Katherine A.
Ramani, Praveen K.
Gokden, Murat
Writzl, Karin
Meznaric, Marija
Vipotnik Vesnaver, Tina
Ramakrishnaiah, Raghu
Osredkar, Damjan
Case Report: SATB2-Associated Syndrome Overlapping With Clinical Mitochondrial Disease Presentation: Report of Two Cases
title Case Report: SATB2-Associated Syndrome Overlapping With Clinical Mitochondrial Disease Presentation: Report of Two Cases
title_full Case Report: SATB2-Associated Syndrome Overlapping With Clinical Mitochondrial Disease Presentation: Report of Two Cases
title_fullStr Case Report: SATB2-Associated Syndrome Overlapping With Clinical Mitochondrial Disease Presentation: Report of Two Cases
title_full_unstemmed Case Report: SATB2-Associated Syndrome Overlapping With Clinical Mitochondrial Disease Presentation: Report of Two Cases
title_short Case Report: SATB2-Associated Syndrome Overlapping With Clinical Mitochondrial Disease Presentation: Report of Two Cases
title_sort case report: satb2-associated syndrome overlapping with clinical mitochondrial disease presentation: report of two cases
topic Genetics
url https://www.ncbi.nlm.nih.gov/pmc/articles/PMC8257052/
https://www.ncbi.nlm.nih.gov/pubmed/34234817
http://dx.doi.org/10.3389/fgene.2021.692087
work_keys_str_mv AT zarateyuria casereportsatb2associatedsyndromeoverlappingwithclinicalmitochondrialdiseasepresentationreportoftwocases
AT vernonhilaryj casereportsatb2associatedsyndromeoverlappingwithclinicalmitochondrialdiseasepresentationreportoftwocases
AT bosankokatherinea casereportsatb2associatedsyndromeoverlappingwithclinicalmitochondrialdiseasepresentationreportoftwocases
AT ramanipraveenk casereportsatb2associatedsyndromeoverlappingwithclinicalmitochondrialdiseasepresentationreportoftwocases
AT gokdenmurat casereportsatb2associatedsyndromeoverlappingwithclinicalmitochondrialdiseasepresentationreportoftwocases
AT writzlkarin casereportsatb2associatedsyndromeoverlappingwithclinicalmitochondrialdiseasepresentationreportoftwocases
AT meznaricmarija casereportsatb2associatedsyndromeoverlappingwithclinicalmitochondrialdiseasepresentationreportoftwocases
AT vipotnikvesnavertina casereportsatb2associatedsyndromeoverlappingwithclinicalmitochondrialdiseasepresentationreportoftwocases
AT ramakrishnaiahraghu casereportsatb2associatedsyndromeoverlappingwithclinicalmitochondrialdiseasepresentationreportoftwocases
AT osredkardamjan casereportsatb2associatedsyndromeoverlappingwithclinicalmitochondrialdiseasepresentationreportoftwocases