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Whole Exome Sequencing Facilitated the Identification of a Mosaic Small Supernumerary Marker Chromosome (sSMC)

Small supernumerary marker chromosomes (sSMCs) are a group of rare chromosomal anomalies, which pose challenges in the clinical practice of prenatal diagnosis and genetic counseling. This study enrolled an extended family with an underage male patient displaying infantile seizures, intellectual disa...

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Detalles Bibliográficos
Autores principales: Xing, Huan-xia, Li, Peng-bin, Cui, Li-min, Jiang, Jian-ye, Hu, Ning-ning, Zhang, Xiao-bin
Formato: Online Artículo Texto
Lenguaje:English
Publicado: Hindawi 2021
Materias:
Acceso en línea:https://www.ncbi.nlm.nih.gov/pmc/articles/PMC8272673/
https://www.ncbi.nlm.nih.gov/pubmed/34307659
http://dx.doi.org/10.1155/2021/6258527
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author Xing, Huan-xia
Li, Peng-bin
Cui, Li-min
Jiang, Jian-ye
Hu, Ning-ning
Zhang, Xiao-bin
author_facet Xing, Huan-xia
Li, Peng-bin
Cui, Li-min
Jiang, Jian-ye
Hu, Ning-ning
Zhang, Xiao-bin
author_sort Xing, Huan-xia
collection PubMed
description Small supernumerary marker chromosomes (sSMCs) are a group of rare chromosomal anomalies, which pose challenges in the clinical practice of prenatal diagnosis and genetic counseling. This study enrolled an extended family with an underage male patient displaying infantile seizures, intellectual disability, and retarded speech and psychomotor function. A series of multiplatform genetic detections was conducted to explore the diagnostic variation. Whole exome sequencing (WES) and chromosomal microarray analysis (CMA) indicated a mosaic sSMC derived from the pericentromeric region of chromosome 8 in the patient, which was confirmed using cytogenetic methods. The proband and his mother, who carried this mosaic variant, exhibited strong phenotypic variability. We also ruled out the pathogenicity of a KDM5C variant by extended validation. Our results emphasized the capacity of WES to detect mosaic SMCs and the importance of mosaic ratios in the appearance and severity of symptomatic phenotypes.
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spelling pubmed-82726732021-07-22 Whole Exome Sequencing Facilitated the Identification of a Mosaic Small Supernumerary Marker Chromosome (sSMC) Xing, Huan-xia Li, Peng-bin Cui, Li-min Jiang, Jian-ye Hu, Ning-ning Zhang, Xiao-bin Biomed Res Int Research Article Small supernumerary marker chromosomes (sSMCs) are a group of rare chromosomal anomalies, which pose challenges in the clinical practice of prenatal diagnosis and genetic counseling. This study enrolled an extended family with an underage male patient displaying infantile seizures, intellectual disability, and retarded speech and psychomotor function. A series of multiplatform genetic detections was conducted to explore the diagnostic variation. Whole exome sequencing (WES) and chromosomal microarray analysis (CMA) indicated a mosaic sSMC derived from the pericentromeric region of chromosome 8 in the patient, which was confirmed using cytogenetic methods. The proband and his mother, who carried this mosaic variant, exhibited strong phenotypic variability. We also ruled out the pathogenicity of a KDM5C variant by extended validation. Our results emphasized the capacity of WES to detect mosaic SMCs and the importance of mosaic ratios in the appearance and severity of symptomatic phenotypes. Hindawi 2021-07-02 /pmc/articles/PMC8272673/ /pubmed/34307659 http://dx.doi.org/10.1155/2021/6258527 Text en Copyright © 2021 Huan-xia Xing et al. https://creativecommons.org/licenses/by/4.0/This is an open access article distributed under the Creative Commons Attribution License, which permits unrestricted use, distribution, and reproduction in any medium, provided the original work is properly cited.
spellingShingle Research Article
Xing, Huan-xia
Li, Peng-bin
Cui, Li-min
Jiang, Jian-ye
Hu, Ning-ning
Zhang, Xiao-bin
Whole Exome Sequencing Facilitated the Identification of a Mosaic Small Supernumerary Marker Chromosome (sSMC)
title Whole Exome Sequencing Facilitated the Identification of a Mosaic Small Supernumerary Marker Chromosome (sSMC)
title_full Whole Exome Sequencing Facilitated the Identification of a Mosaic Small Supernumerary Marker Chromosome (sSMC)
title_fullStr Whole Exome Sequencing Facilitated the Identification of a Mosaic Small Supernumerary Marker Chromosome (sSMC)
title_full_unstemmed Whole Exome Sequencing Facilitated the Identification of a Mosaic Small Supernumerary Marker Chromosome (sSMC)
title_short Whole Exome Sequencing Facilitated the Identification of a Mosaic Small Supernumerary Marker Chromosome (sSMC)
title_sort whole exome sequencing facilitated the identification of a mosaic small supernumerary marker chromosome (ssmc)
topic Research Article
url https://www.ncbi.nlm.nih.gov/pmc/articles/PMC8272673/
https://www.ncbi.nlm.nih.gov/pubmed/34307659
http://dx.doi.org/10.1155/2021/6258527
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