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Hollow Visceral Myopathy, a Rare Gastrointestinal Disorder: A Case Report and Short Review
Hollow visceral myopathy (HVM) is described as impaired intestinal function and motility in the absence of mechanical obstruction. In this case report, we describe a unique case of an 18-year-old female who presented to the hospital with complaints of persistent nausea, vomiting, inability to tolera...
Autores principales: | , , , , , |
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Formato: | Online Artículo Texto |
Lenguaje: | English |
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SAGE Publications
2021
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Materias: | |
Acceso en línea: | https://www.ncbi.nlm.nih.gov/pmc/articles/PMC8361550/ https://www.ncbi.nlm.nih.gov/pubmed/34378443 http://dx.doi.org/10.1177/23247096211034303 |
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author | Dahiya, Dushyant Singh Batth, Arshdeep Batth, Jaspreet Wani, Farah Singh, Jagmeet Kichloo, Asim |
author_facet | Dahiya, Dushyant Singh Batth, Arshdeep Batth, Jaspreet Wani, Farah Singh, Jagmeet Kichloo, Asim |
author_sort | Dahiya, Dushyant Singh |
collection | PubMed |
description | Hollow visceral myopathy (HVM) is described as impaired intestinal function and motility in the absence of mechanical obstruction. In this case report, we describe a unique case of an 18-year-old female who presented to the hospital with complaints of persistent nausea, vomiting, inability to tolerate oral feeds, and substantial weight loss for 2 months. After appropriate investigations, a diagnosis of gastroparesis was established. The patient was started on metoclopramide, which led to significant symptomatic improvement, and she was eventually discharged home. One month after discharge, she presented to the hospital with symptoms similar to her initial presentation. After further laboratory and radiological investigation, she was diagnosed with severe gastroparesis and chronic intestinal pseudo-obstruction. Over the next month, the patient was given an extensive trial of multiple prokinetic agents such as mirtazapine, ondansetron, pyridostigmine, octreotide, and promethazine, but she failed to show clinical improvement. Due to failure of medical therapy, a nasojejunal feeding tube was placed for enteral nutrition. However, the patient reported worsening of her symptoms despite slow feeding rates; hence, a decision was made to start the patient on total parenteral nutrition and transfer her to a larger tertiary center for higher level of care. At the tertiary hospital, the patient was continued on total parenteral nutrition and underwent extensive evaluation. Ultimately, she was diagnosed with HVM after a laparoscopic full-thickness intestinal biopsy showed histopathological evidence of the disease. She underwent isolated small intestine transplant, which led to significant improvement of her symptoms and was eventually discharged home. The patient continues to be symptom-free and follows up with Gastroenterology and Transplant Surgery regularly. This case report highlights a rare clinical condition, HVM, as a potential diagnosis in patients with clinical features of intestinal obstruction without mechanical obstruction. |
format | Online Article Text |
id | pubmed-8361550 |
institution | National Center for Biotechnology Information |
language | English |
publishDate | 2021 |
publisher | SAGE Publications |
record_format | MEDLINE/PubMed |
spelling | pubmed-83615502021-08-14 Hollow Visceral Myopathy, a Rare Gastrointestinal Disorder: A Case Report and Short Review Dahiya, Dushyant Singh Batth, Arshdeep Batth, Jaspreet Wani, Farah Singh, Jagmeet Kichloo, Asim J Investig Med High Impact Case Rep Case Report Hollow visceral myopathy (HVM) is described as impaired intestinal function and motility in the absence of mechanical obstruction. In this case report, we describe a unique case of an 18-year-old female who presented to the hospital with complaints of persistent nausea, vomiting, inability to tolerate oral feeds, and substantial weight loss for 2 months. After appropriate investigations, a diagnosis of gastroparesis was established. The patient was started on metoclopramide, which led to significant symptomatic improvement, and she was eventually discharged home. One month after discharge, she presented to the hospital with symptoms similar to her initial presentation. After further laboratory and radiological investigation, she was diagnosed with severe gastroparesis and chronic intestinal pseudo-obstruction. Over the next month, the patient was given an extensive trial of multiple prokinetic agents such as mirtazapine, ondansetron, pyridostigmine, octreotide, and promethazine, but she failed to show clinical improvement. Due to failure of medical therapy, a nasojejunal feeding tube was placed for enteral nutrition. However, the patient reported worsening of her symptoms despite slow feeding rates; hence, a decision was made to start the patient on total parenteral nutrition and transfer her to a larger tertiary center for higher level of care. At the tertiary hospital, the patient was continued on total parenteral nutrition and underwent extensive evaluation. Ultimately, she was diagnosed with HVM after a laparoscopic full-thickness intestinal biopsy showed histopathological evidence of the disease. She underwent isolated small intestine transplant, which led to significant improvement of her symptoms and was eventually discharged home. The patient continues to be symptom-free and follows up with Gastroenterology and Transplant Surgery regularly. This case report highlights a rare clinical condition, HVM, as a potential diagnosis in patients with clinical features of intestinal obstruction without mechanical obstruction. SAGE Publications 2021-08-11 /pmc/articles/PMC8361550/ /pubmed/34378443 http://dx.doi.org/10.1177/23247096211034303 Text en © 2021 American Federation for Medical Research https://creativecommons.org/licenses/by-nc/4.0/This article is distributed under the terms of the Creative Commons Attribution-NonCommercial 4.0 License (https://creativecommons.org/licenses/by-nc/4.0/) which permits non-commercial use, reproduction and distribution of the work without further permission provided the original work is attributed as specified on the SAGE and Open Access page (https://us.sagepub.com/en-us/nam/open-access-at-sage). |
spellingShingle | Case Report Dahiya, Dushyant Singh Batth, Arshdeep Batth, Jaspreet Wani, Farah Singh, Jagmeet Kichloo, Asim Hollow Visceral Myopathy, a Rare Gastrointestinal Disorder: A Case Report and Short Review |
title | Hollow Visceral Myopathy, a Rare Gastrointestinal Disorder: A Case Report and Short Review |
title_full | Hollow Visceral Myopathy, a Rare Gastrointestinal Disorder: A Case Report and Short Review |
title_fullStr | Hollow Visceral Myopathy, a Rare Gastrointestinal Disorder: A Case Report and Short Review |
title_full_unstemmed | Hollow Visceral Myopathy, a Rare Gastrointestinal Disorder: A Case Report and Short Review |
title_short | Hollow Visceral Myopathy, a Rare Gastrointestinal Disorder: A Case Report and Short Review |
title_sort | hollow visceral myopathy, a rare gastrointestinal disorder: a case report and short review |
topic | Case Report |
url | https://www.ncbi.nlm.nih.gov/pmc/articles/PMC8361550/ https://www.ncbi.nlm.nih.gov/pubmed/34378443 http://dx.doi.org/10.1177/23247096211034303 |
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