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Adult-onset woakes' syndrome: Report of two cases

INTRODUCTION: Woakes' syndrome is a rare condition commonly defined as recurrent sinonasal polyposis with consecutive destruction of the nasal pyramid. Till now, only a few cases have been reported in the literature. The purpose of this paper is to present the features of woakes' syndrome...

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Autores principales: Chennoufi, Ilham, Bendiouri, Reda, Lachkar, Azeddine, Drissia, Belfadil, Abdenbi Tsen, Adil, Elayoubi, Fahd, Ghailan, Rachid
Formato: Online Artículo Texto
Lenguaje:English
Publicado: Elsevier 2021
Materias:
Acceso en línea:https://www.ncbi.nlm.nih.gov/pmc/articles/PMC8377525/
https://www.ncbi.nlm.nih.gov/pubmed/34457252
http://dx.doi.org/10.1016/j.amsu.2021.102695
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author Chennoufi, Ilham
Bendiouri, Reda
Lachkar, Azeddine
Drissia, Belfadil
Abdenbi Tsen, Adil
Elayoubi, Fahd
Ghailan, Rachid
author_facet Chennoufi, Ilham
Bendiouri, Reda
Lachkar, Azeddine
Drissia, Belfadil
Abdenbi Tsen, Adil
Elayoubi, Fahd
Ghailan, Rachid
author_sort Chennoufi, Ilham
collection PubMed
description INTRODUCTION: Woakes' syndrome is a rare condition commonly defined as recurrent sinonasal polyposis with consecutive destruction of the nasal pyramid. Till now, only a few cases have been reported in the literature. The purpose of this paper is to present the features of woakes' syndrome through two new clinical cases, adding some valuable insight to the recently reported cases. CASE REPORT: We report a series of two consecutive adults male and female patients, aged 55 and 58 years, with Samter's triad, who presented recurrent nasal polyposis and progressive broadening of the nasal dorsum. Facial CT showed in both patients the same radiologic pattern of nasal and paranasal cavities obliteration with nasal bone deformation. Both patients underwent functional endoscopic sinus surgery and correction of the bony nasal vault deformity without osteotomies. At 3 months follow-up, the nasal air passage remained free and aesthetic outcomes were observed. DISCUSSION: having been described over 130 years ago, the etiology of woakes' syndrome remains unclear. Treatment includes topical treatment and sinonasal surgery. Surgical treatment of the nasal dorsum deformity is rarely addressed. CONCLUSION: These observations suggest that the external nose deformity may be successfully corrected by digital compression, in combination with endoscopic sinus surgery.
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spelling pubmed-83775252021-08-26 Adult-onset woakes' syndrome: Report of two cases Chennoufi, Ilham Bendiouri, Reda Lachkar, Azeddine Drissia, Belfadil Abdenbi Tsen, Adil Elayoubi, Fahd Ghailan, Rachid Ann Med Surg (Lond) Case Report INTRODUCTION: Woakes' syndrome is a rare condition commonly defined as recurrent sinonasal polyposis with consecutive destruction of the nasal pyramid. Till now, only a few cases have been reported in the literature. The purpose of this paper is to present the features of woakes' syndrome through two new clinical cases, adding some valuable insight to the recently reported cases. CASE REPORT: We report a series of two consecutive adults male and female patients, aged 55 and 58 years, with Samter's triad, who presented recurrent nasal polyposis and progressive broadening of the nasal dorsum. Facial CT showed in both patients the same radiologic pattern of nasal and paranasal cavities obliteration with nasal bone deformation. Both patients underwent functional endoscopic sinus surgery and correction of the bony nasal vault deformity without osteotomies. At 3 months follow-up, the nasal air passage remained free and aesthetic outcomes were observed. DISCUSSION: having been described over 130 years ago, the etiology of woakes' syndrome remains unclear. Treatment includes topical treatment and sinonasal surgery. Surgical treatment of the nasal dorsum deformity is rarely addressed. CONCLUSION: These observations suggest that the external nose deformity may be successfully corrected by digital compression, in combination with endoscopic sinus surgery. Elsevier 2021-08-09 /pmc/articles/PMC8377525/ /pubmed/34457252 http://dx.doi.org/10.1016/j.amsu.2021.102695 Text en © 2021 The Authors https://creativecommons.org/licenses/by-nc-nd/4.0/This is an open access article under the CC BY-NC-ND license (http://creativecommons.org/licenses/by-nc-nd/4.0/).
spellingShingle Case Report
Chennoufi, Ilham
Bendiouri, Reda
Lachkar, Azeddine
Drissia, Belfadil
Abdenbi Tsen, Adil
Elayoubi, Fahd
Ghailan, Rachid
Adult-onset woakes' syndrome: Report of two cases
title Adult-onset woakes' syndrome: Report of two cases
title_full Adult-onset woakes' syndrome: Report of two cases
title_fullStr Adult-onset woakes' syndrome: Report of two cases
title_full_unstemmed Adult-onset woakes' syndrome: Report of two cases
title_short Adult-onset woakes' syndrome: Report of two cases
title_sort adult-onset woakes' syndrome: report of two cases
topic Case Report
url https://www.ncbi.nlm.nih.gov/pmc/articles/PMC8377525/
https://www.ncbi.nlm.nih.gov/pubmed/34457252
http://dx.doi.org/10.1016/j.amsu.2021.102695
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