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Genome-wide association studies identify the role of caspase-9 in kidney disease
Genome-wide association studies (GWAS) have identified hundreds of genetic risk regions for kidney dysfunction [estimated glomerular filtration rate (eGFR)]; however, the causal genes, cell types, and pathways are poorly understood. Integration of GWAS and human kidney expression of quantitative tra...
Autores principales: | , , , , , , , , |
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Formato: | Online Artículo Texto |
Lenguaje: | English |
Publicado: |
American Association for the Advancement of Science
2021
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Materias: | |
Acceso en línea: | https://www.ncbi.nlm.nih.gov/pmc/articles/PMC8570608/ https://www.ncbi.nlm.nih.gov/pubmed/34739325 http://dx.doi.org/10.1126/sciadv.abi8051 |
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author | Doke, Tomohito Huang, Shizheng Qiu, Chengxiang Sheng, Xin Seasock, Matthew Liu, Hongbo Ma, Ziyuan Palmer, Matthew Susztak, Katalin |
author_facet | Doke, Tomohito Huang, Shizheng Qiu, Chengxiang Sheng, Xin Seasock, Matthew Liu, Hongbo Ma, Ziyuan Palmer, Matthew Susztak, Katalin |
author_sort | Doke, Tomohito |
collection | PubMed |
description | Genome-wide association studies (GWAS) have identified hundreds of genetic risk regions for kidney dysfunction [estimated glomerular filtration rate (eGFR)]; however, the causal genes, cell types, and pathways are poorly understood. Integration of GWAS and human kidney expression of quantitative trait analysis using Bayesian colocations, transcriptome-wide association studies, and summary-based Mendelian randomization studies prioritized caspase-9 (CASP9) as a kidney disease risk gene. Human kidney single-cell epigenetic and immunostaining studies indicated kidney tubule cells as a disease-causing cell type. Mice with genetic deletion or pharmacological inhibition of CASP9 showed lower apoptosis while having improved mitophagy, resulting in dampened activation of cytosolic nucleotide sensing pathways (cGAS-STING), reduction of inflammation, and protection from acute kidney disease or renal fibrosis. In summary, here, we prioritized CASP9 as an eGFR GWAS target gene and demonstrated the causal role of CASP9 in kidney disease development via improving mitophagy and lowering inflammation and apoptosis. |
format | Online Article Text |
id | pubmed-8570608 |
institution | National Center for Biotechnology Information |
language | English |
publishDate | 2021 |
publisher | American Association for the Advancement of Science |
record_format | MEDLINE/PubMed |
spelling | pubmed-85706082021-11-17 Genome-wide association studies identify the role of caspase-9 in kidney disease Doke, Tomohito Huang, Shizheng Qiu, Chengxiang Sheng, Xin Seasock, Matthew Liu, Hongbo Ma, Ziyuan Palmer, Matthew Susztak, Katalin Sci Adv Biomedicine and Life Sciences Genome-wide association studies (GWAS) have identified hundreds of genetic risk regions for kidney dysfunction [estimated glomerular filtration rate (eGFR)]; however, the causal genes, cell types, and pathways are poorly understood. Integration of GWAS and human kidney expression of quantitative trait analysis using Bayesian colocations, transcriptome-wide association studies, and summary-based Mendelian randomization studies prioritized caspase-9 (CASP9) as a kidney disease risk gene. Human kidney single-cell epigenetic and immunostaining studies indicated kidney tubule cells as a disease-causing cell type. Mice with genetic deletion or pharmacological inhibition of CASP9 showed lower apoptosis while having improved mitophagy, resulting in dampened activation of cytosolic nucleotide sensing pathways (cGAS-STING), reduction of inflammation, and protection from acute kidney disease or renal fibrosis. In summary, here, we prioritized CASP9 as an eGFR GWAS target gene and demonstrated the causal role of CASP9 in kidney disease development via improving mitophagy and lowering inflammation and apoptosis. American Association for the Advancement of Science 2021-11-05 /pmc/articles/PMC8570608/ /pubmed/34739325 http://dx.doi.org/10.1126/sciadv.abi8051 Text en Copyright © 2021 The Authors, some rights reserved; exclusive licensee American Association for the Advancement of Science. No claim to original U.S. Government Works. Distributed under a Creative Commons Attribution License 4.0 (CC BY). https://creativecommons.org/licenses/by/4.0/This is an open-access article distributed under the terms of the Creative Commons Attribution license (https://creativecommons.org/licenses/by/4.0/) , which permits unrestricted use, distribution, and reproduction in any medium, provided the original work is properly cited. |
spellingShingle | Biomedicine and Life Sciences Doke, Tomohito Huang, Shizheng Qiu, Chengxiang Sheng, Xin Seasock, Matthew Liu, Hongbo Ma, Ziyuan Palmer, Matthew Susztak, Katalin Genome-wide association studies identify the role of caspase-9 in kidney disease |
title | Genome-wide association studies identify the role of caspase-9 in kidney disease |
title_full | Genome-wide association studies identify the role of caspase-9 in kidney disease |
title_fullStr | Genome-wide association studies identify the role of caspase-9 in kidney disease |
title_full_unstemmed | Genome-wide association studies identify the role of caspase-9 in kidney disease |
title_short | Genome-wide association studies identify the role of caspase-9 in kidney disease |
title_sort | genome-wide association studies identify the role of caspase-9 in kidney disease |
topic | Biomedicine and Life Sciences |
url | https://www.ncbi.nlm.nih.gov/pmc/articles/PMC8570608/ https://www.ncbi.nlm.nih.gov/pubmed/34739325 http://dx.doi.org/10.1126/sciadv.abi8051 |
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