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A Mosaic Mutation in the LAMA2 Gene in a Case of Merosin-deficient Congenital Muscular Dystrophy

Merosine deficient congenital muscular dystrophy is one of the most common forms of congenital muscular dystrophy. This disease is caused by a primary deficiency or a functionally inactive form of the protein merosin in muscle tissue. The type of inheritance of this disease is autosomal recessive. D...

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Autores principales: Chausova, P. A., Ryzhkova, O. P., Rudenskaya, G. E., Chernykh, V. B., Shchagina, O. A., Polyakov, A. V.
Formato: Online Artículo Texto
Lenguaje:English
Publicado: Frontiers Media S.A. 2021
Materias:
Acceso en línea:https://www.ncbi.nlm.nih.gov/pmc/articles/PMC8586452/
https://www.ncbi.nlm.nih.gov/pubmed/34777456
http://dx.doi.org/10.3389/fgene.2021.686800
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author Chausova, P. A.
Ryzhkova, O. P.
Rudenskaya, G. E.
Chernykh, V. B.
Shchagina, O. A.
Polyakov, A. V.
author_facet Chausova, P. A.
Ryzhkova, O. P.
Rudenskaya, G. E.
Chernykh, V. B.
Shchagina, O. A.
Polyakov, A. V.
author_sort Chausova, P. A.
collection PubMed
description Merosine deficient congenital muscular dystrophy is one of the most common forms of congenital muscular dystrophy. This disease is caused by a primary deficiency or a functionally inactive form of the protein merosin in muscle tissue. The type of inheritance of this disease is autosomal recessive. De novo variants with this type of inheritance are rare, and it is quite possible that the de novo variant may hide a mosaic form in the parent of an affected child. We present a birth family with two affected children who inherited a previously undescribed pathogenic variant c.1755del from their mother and a previously described pathogenic variant c.9253C > T in the LAMA2 gene from their mosaic father. LAMA2 gene mutation analysis was performed by mass parallel sequencing and direct sequencing of genomic DNAs.
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spelling pubmed-85864522021-11-13 A Mosaic Mutation in the LAMA2 Gene in a Case of Merosin-deficient Congenital Muscular Dystrophy Chausova, P. A. Ryzhkova, O. P. Rudenskaya, G. E. Chernykh, V. B. Shchagina, O. A. Polyakov, A. V. Front Genet Genetics Merosine deficient congenital muscular dystrophy is one of the most common forms of congenital muscular dystrophy. This disease is caused by a primary deficiency or a functionally inactive form of the protein merosin in muscle tissue. The type of inheritance of this disease is autosomal recessive. De novo variants with this type of inheritance are rare, and it is quite possible that the de novo variant may hide a mosaic form in the parent of an affected child. We present a birth family with two affected children who inherited a previously undescribed pathogenic variant c.1755del from their mother and a previously described pathogenic variant c.9253C > T in the LAMA2 gene from their mosaic father. LAMA2 gene mutation analysis was performed by mass parallel sequencing and direct sequencing of genomic DNAs. Frontiers Media S.A. 2021-10-29 /pmc/articles/PMC8586452/ /pubmed/34777456 http://dx.doi.org/10.3389/fgene.2021.686800 Text en Copyright © 2021 Chausova, Ryzhkova, Rudenskaya, Chernykh, Shchagina and Polyakov. https://creativecommons.org/licenses/by/4.0/This is an open-access article distributed under the terms of the Creative Commons Attribution License (CC BY). The use, distribution or reproduction in other forums is permitted, provided the original author(s) and the copyright owner(s) are credited and that the original publication in this journal is cited, in accordance with accepted academic practice. No use, distribution or reproduction is permitted which does not comply with these terms.
spellingShingle Genetics
Chausova, P. A.
Ryzhkova, O. P.
Rudenskaya, G. E.
Chernykh, V. B.
Shchagina, O. A.
Polyakov, A. V.
A Mosaic Mutation in the LAMA2 Gene in a Case of Merosin-deficient Congenital Muscular Dystrophy
title A Mosaic Mutation in the LAMA2 Gene in a Case of Merosin-deficient Congenital Muscular Dystrophy
title_full A Mosaic Mutation in the LAMA2 Gene in a Case of Merosin-deficient Congenital Muscular Dystrophy
title_fullStr A Mosaic Mutation in the LAMA2 Gene in a Case of Merosin-deficient Congenital Muscular Dystrophy
title_full_unstemmed A Mosaic Mutation in the LAMA2 Gene in a Case of Merosin-deficient Congenital Muscular Dystrophy
title_short A Mosaic Mutation in the LAMA2 Gene in a Case of Merosin-deficient Congenital Muscular Dystrophy
title_sort mosaic mutation in the lama2 gene in a case of merosin-deficient congenital muscular dystrophy
topic Genetics
url https://www.ncbi.nlm.nih.gov/pmc/articles/PMC8586452/
https://www.ncbi.nlm.nih.gov/pubmed/34777456
http://dx.doi.org/10.3389/fgene.2021.686800
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