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Muscle MRI as a Useful Biomarker in Hereditary Transthyretin Amyloidosis: A Pilot Study

Hereditary transthyretin amyloidosis (ATTRv, v for variant) is a severe and heterogeneous multisystem condition with a prevalent peripheral nervous system impairment, due to mutations in the transthyretin gene. Considering the introduction of different disease-modifying therapies in the last few yea...

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Autores principales: Primiano, Guido, Verdolotti, Tommaso, D’Apolito, Gabriella, Di Paolantonio, Andrea, Guglielmino, Valeria, Romano, Angela, Lucioli, Gabriele, Luigetti, Marco, Servidei, Serenella
Formato: Online Artículo Texto
Lenguaje:English
Publicado: MDPI 2021
Materias:
Acceso en línea:https://www.ncbi.nlm.nih.gov/pmc/articles/PMC8623476/
https://www.ncbi.nlm.nih.gov/pubmed/34828392
http://dx.doi.org/10.3390/genes12111786
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author Primiano, Guido
Verdolotti, Tommaso
D’Apolito, Gabriella
Di Paolantonio, Andrea
Guglielmino, Valeria
Romano, Angela
Lucioli, Gabriele
Luigetti, Marco
Servidei, Serenella
author_facet Primiano, Guido
Verdolotti, Tommaso
D’Apolito, Gabriella
Di Paolantonio, Andrea
Guglielmino, Valeria
Romano, Angela
Lucioli, Gabriele
Luigetti, Marco
Servidei, Serenella
author_sort Primiano, Guido
collection PubMed
description Hereditary transthyretin amyloidosis (ATTRv, v for variant) is a severe and heterogeneous multisystem condition with a prevalent peripheral nervous system impairment, due to mutations in the transthyretin gene. Considering the introduction of different disease-modifying therapies in the last few years, a need of reliable biomarkers is emerging. In this study, we evaluated muscle MRI in a cohort of ATTRv patients in order to establish if the severity of muscle involvement correlated with disease severity. Linear regression analysis showed a significant positive correlation between the total fatty infiltration score and NIS, NIS-LL, and Norfolk, and an inverse correlation with Sudoscan registered from feet. In conclusion, we demonstrated the role of muscle MRI in ATTRv as possible disease biomarker, both for diagnostic purposes and for assessing the severity of the disease.
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spelling pubmed-86234762021-11-27 Muscle MRI as a Useful Biomarker in Hereditary Transthyretin Amyloidosis: A Pilot Study Primiano, Guido Verdolotti, Tommaso D’Apolito, Gabriella Di Paolantonio, Andrea Guglielmino, Valeria Romano, Angela Lucioli, Gabriele Luigetti, Marco Servidei, Serenella Genes (Basel) Article Hereditary transthyretin amyloidosis (ATTRv, v for variant) is a severe and heterogeneous multisystem condition with a prevalent peripheral nervous system impairment, due to mutations in the transthyretin gene. Considering the introduction of different disease-modifying therapies in the last few years, a need of reliable biomarkers is emerging. In this study, we evaluated muscle MRI in a cohort of ATTRv patients in order to establish if the severity of muscle involvement correlated with disease severity. Linear regression analysis showed a significant positive correlation between the total fatty infiltration score and NIS, NIS-LL, and Norfolk, and an inverse correlation with Sudoscan registered from feet. In conclusion, we demonstrated the role of muscle MRI in ATTRv as possible disease biomarker, both for diagnostic purposes and for assessing the severity of the disease. MDPI 2021-11-11 /pmc/articles/PMC8623476/ /pubmed/34828392 http://dx.doi.org/10.3390/genes12111786 Text en © 2021 by the authors. https://creativecommons.org/licenses/by/4.0/Licensee MDPI, Basel, Switzerland. This article is an open access article distributed under the terms and conditions of the Creative Commons Attribution (CC BY) license (https://creativecommons.org/licenses/by/4.0/).
spellingShingle Article
Primiano, Guido
Verdolotti, Tommaso
D’Apolito, Gabriella
Di Paolantonio, Andrea
Guglielmino, Valeria
Romano, Angela
Lucioli, Gabriele
Luigetti, Marco
Servidei, Serenella
Muscle MRI as a Useful Biomarker in Hereditary Transthyretin Amyloidosis: A Pilot Study
title Muscle MRI as a Useful Biomarker in Hereditary Transthyretin Amyloidosis: A Pilot Study
title_full Muscle MRI as a Useful Biomarker in Hereditary Transthyretin Amyloidosis: A Pilot Study
title_fullStr Muscle MRI as a Useful Biomarker in Hereditary Transthyretin Amyloidosis: A Pilot Study
title_full_unstemmed Muscle MRI as a Useful Biomarker in Hereditary Transthyretin Amyloidosis: A Pilot Study
title_short Muscle MRI as a Useful Biomarker in Hereditary Transthyretin Amyloidosis: A Pilot Study
title_sort muscle mri as a useful biomarker in hereditary transthyretin amyloidosis: a pilot study
topic Article
url https://www.ncbi.nlm.nih.gov/pmc/articles/PMC8623476/
https://www.ncbi.nlm.nih.gov/pubmed/34828392
http://dx.doi.org/10.3390/genes12111786
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