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Thoraco-abdominal duplications in children: Two case reports

INTRODUCTION: Thoraco-abdominal duplication is rare congenital malformations of the notochord that occurs in only 2% of cases of alimentary tract duplications. We report two rare cases of thoraco-abdominal duplication, emphasizing the value of radiological assessment and discussing the place of diag...

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Autores principales: Thamri, Fatma, Sahli, Sondes, Houidi, Senda, Aziza, Bochra, Jouini, Riadh
Formato: Online Artículo Texto
Lenguaje:English
Publicado: Elsevier 2021
Materias:
Acceso en línea:https://www.ncbi.nlm.nih.gov/pmc/articles/PMC8665331/
https://www.ncbi.nlm.nih.gov/pubmed/34890978
http://dx.doi.org/10.1016/j.ijscr.2021.106651
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author Thamri, Fatma
Sahli, Sondes
Houidi, Senda
Aziza, Bochra
Jouini, Riadh
author_facet Thamri, Fatma
Sahli, Sondes
Houidi, Senda
Aziza, Bochra
Jouini, Riadh
author_sort Thamri, Fatma
collection PubMed
description INTRODUCTION: Thoraco-abdominal duplication is rare congenital malformations of the notochord that occurs in only 2% of cases of alimentary tract duplications. We report two rare cases of thoraco-abdominal duplication, emphasizing the value of radiological assessment and discussing the place of diagnostic and therapeutic laparoscopy. PRESENTATION OF CASE: It was a 12-year-old girl and an 8-month-old boy, admitted for epigastralgia and dysphagia with respiratory distress respectively. Imaging was in favor of pancreatic duplication with intra-thoracic extension for the first patient and gastro-esophageal duplication for the second. A mass excision was done laparoscopically for the first and by a thoracotomy for the second. The aftermath of the surgery was simple in both cases. CLINICAL DISCUSSION: Thoraco-abdominal duplications are rare congenital malformations that account for only 2% of cases of gastrointestinal duplications. Their diagnosis is difficult since the revealing symptomatology is not common. The treatment is only surgical is facilitated by the laparoscopy which has a diagnostic and therapeutic interest. CONCLUSION: Our case reports focused on the difficulty of the diagnosis that is done by imaging and is confirmed by surgery with anatomopathological examination of the excised mass. Diagnostic and therapeutic minimally invasive approach should be used whenever possible.
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spelling pubmed-86653312021-12-15 Thoraco-abdominal duplications in children: Two case reports Thamri, Fatma Sahli, Sondes Houidi, Senda Aziza, Bochra Jouini, Riadh Int J Surg Case Rep Case Report INTRODUCTION: Thoraco-abdominal duplication is rare congenital malformations of the notochord that occurs in only 2% of cases of alimentary tract duplications. We report two rare cases of thoraco-abdominal duplication, emphasizing the value of radiological assessment and discussing the place of diagnostic and therapeutic laparoscopy. PRESENTATION OF CASE: It was a 12-year-old girl and an 8-month-old boy, admitted for epigastralgia and dysphagia with respiratory distress respectively. Imaging was in favor of pancreatic duplication with intra-thoracic extension for the first patient and gastro-esophageal duplication for the second. A mass excision was done laparoscopically for the first and by a thoracotomy for the second. The aftermath of the surgery was simple in both cases. CLINICAL DISCUSSION: Thoraco-abdominal duplications are rare congenital malformations that account for only 2% of cases of gastrointestinal duplications. Their diagnosis is difficult since the revealing symptomatology is not common. The treatment is only surgical is facilitated by the laparoscopy which has a diagnostic and therapeutic interest. CONCLUSION: Our case reports focused on the difficulty of the diagnosis that is done by imaging and is confirmed by surgery with anatomopathological examination of the excised mass. Diagnostic and therapeutic minimally invasive approach should be used whenever possible. Elsevier 2021-12-04 /pmc/articles/PMC8665331/ /pubmed/34890978 http://dx.doi.org/10.1016/j.ijscr.2021.106651 Text en © 2021 The Authors. Published by Elsevier Ltd on behalf of IJS Publishing Group Ltd. https://creativecommons.org/licenses/by-nc-nd/4.0/This is an open access article under the CC BY-NC-ND license (http://creativecommons.org/licenses/by-nc-nd/4.0/).
spellingShingle Case Report
Thamri, Fatma
Sahli, Sondes
Houidi, Senda
Aziza, Bochra
Jouini, Riadh
Thoraco-abdominal duplications in children: Two case reports
title Thoraco-abdominal duplications in children: Two case reports
title_full Thoraco-abdominal duplications in children: Two case reports
title_fullStr Thoraco-abdominal duplications in children: Two case reports
title_full_unstemmed Thoraco-abdominal duplications in children: Two case reports
title_short Thoraco-abdominal duplications in children: Two case reports
title_sort thoraco-abdominal duplications in children: two case reports
topic Case Report
url https://www.ncbi.nlm.nih.gov/pmc/articles/PMC8665331/
https://www.ncbi.nlm.nih.gov/pubmed/34890978
http://dx.doi.org/10.1016/j.ijscr.2021.106651
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