Cargando…
Gene Spectrum and Clinical Traits of Nine Patients With Oocyte Maturation Arrest
Background: Oocyte maturation arrest is a disease that produces immature oocytes and cannot be mature after culturing in vitro, which leads to female primary infertility. We aimed to summarize nine representative patients in our center to retrospectively analyze the genetic variants and clinical cha...
Autores principales: | , , , , , , , |
---|---|
Formato: | Online Artículo Texto |
Lenguaje: | English |
Publicado: |
Frontiers Media S.A.
2022
|
Materias: | |
Acceso en línea: | https://www.ncbi.nlm.nih.gov/pmc/articles/PMC8819080/ https://www.ncbi.nlm.nih.gov/pubmed/35140748 http://dx.doi.org/10.3389/fgene.2022.772143 |
_version_ | 1784645976304123904 |
---|---|
author | Huo, Mingzhu Zhang, Yile Shi, Senlin Shi, Hao Liu, Yidong Zhang, Lingyun Wang, Yanchi Niu, Wenbin |
author_facet | Huo, Mingzhu Zhang, Yile Shi, Senlin Shi, Hao Liu, Yidong Zhang, Lingyun Wang, Yanchi Niu, Wenbin |
author_sort | Huo, Mingzhu |
collection | PubMed |
description | Background: Oocyte maturation arrest is a disease that produces immature oocytes and cannot be mature after culturing in vitro, which leads to female primary infertility. We aimed to summarize nine representative patients in our center to retrospectively analyze the genetic variants and clinical characteristics of oocyte maturation arrest. Methods: This study examined and analyzed nine families with oocyte maturation arrest. Whole-exome sequencing (WES) of the probands was performed to detect the pathogenic variants. Sanger sequencing verified the WES findings in patients and available parents. ExAC database was used to search the variant frequency. The variants were assessed by pathogenicity and conservational property prediction analysis and according to the American College of Medical Genetics and Genomics (ACMG). Phenotypes of oocytes were evaluated by a light microscopy, and the phenotype-genotype correlation was also evaluated. Results: Nine pathogenic variants in five genes were detected in nine patients, of which three were novel variants, including PATL2 [c.1374A > G (p. Ile458Met)] and [1289-1291del TCC (p. Leu430del)] and ZP2 [c.1543C > T (p. Pro515Ser)]. Nine variants were predicted to be pathogenic, resulting in different types of oocyte maturation arrest and clinical phenotypes. Conclusion: Three novel pathogenic variants were identified, enabling the expansion of the gene variant spectrum. The related pathogenic mutations of the PATL2, TUBB8, and ZP1∼3 genes were highly suggestive of being causative of oocyte maturation arrest. |
format | Online Article Text |
id | pubmed-8819080 |
institution | National Center for Biotechnology Information |
language | English |
publishDate | 2022 |
publisher | Frontiers Media S.A. |
record_format | MEDLINE/PubMed |
spelling | pubmed-88190802022-02-08 Gene Spectrum and Clinical Traits of Nine Patients With Oocyte Maturation Arrest Huo, Mingzhu Zhang, Yile Shi, Senlin Shi, Hao Liu, Yidong Zhang, Lingyun Wang, Yanchi Niu, Wenbin Front Genet Genetics Background: Oocyte maturation arrest is a disease that produces immature oocytes and cannot be mature after culturing in vitro, which leads to female primary infertility. We aimed to summarize nine representative patients in our center to retrospectively analyze the genetic variants and clinical characteristics of oocyte maturation arrest. Methods: This study examined and analyzed nine families with oocyte maturation arrest. Whole-exome sequencing (WES) of the probands was performed to detect the pathogenic variants. Sanger sequencing verified the WES findings in patients and available parents. ExAC database was used to search the variant frequency. The variants were assessed by pathogenicity and conservational property prediction analysis and according to the American College of Medical Genetics and Genomics (ACMG). Phenotypes of oocytes were evaluated by a light microscopy, and the phenotype-genotype correlation was also evaluated. Results: Nine pathogenic variants in five genes were detected in nine patients, of which three were novel variants, including PATL2 [c.1374A > G (p. Ile458Met)] and [1289-1291del TCC (p. Leu430del)] and ZP2 [c.1543C > T (p. Pro515Ser)]. Nine variants were predicted to be pathogenic, resulting in different types of oocyte maturation arrest and clinical phenotypes. Conclusion: Three novel pathogenic variants were identified, enabling the expansion of the gene variant spectrum. The related pathogenic mutations of the PATL2, TUBB8, and ZP1∼3 genes were highly suggestive of being causative of oocyte maturation arrest. Frontiers Media S.A. 2022-01-24 /pmc/articles/PMC8819080/ /pubmed/35140748 http://dx.doi.org/10.3389/fgene.2022.772143 Text en Copyright © 2022 Huo, Zhang, Shi, Shi, Liu, Zhang, Wang and Niu. https://creativecommons.org/licenses/by/4.0/This is an open-access article distributed under the terms of the Creative Commons Attribution License (CC BY). The use, distribution or reproduction in other forums is permitted, provided the original author(s) and the copyright owner(s) are credited and that the original publication in this journal is cited, in accordance with accepted academic practice. No use, distribution or reproduction is permitted which does not comply with these terms. |
spellingShingle | Genetics Huo, Mingzhu Zhang, Yile Shi, Senlin Shi, Hao Liu, Yidong Zhang, Lingyun Wang, Yanchi Niu, Wenbin Gene Spectrum and Clinical Traits of Nine Patients With Oocyte Maturation Arrest |
title | Gene Spectrum and Clinical Traits of Nine Patients With Oocyte Maturation Arrest |
title_full | Gene Spectrum and Clinical Traits of Nine Patients With Oocyte Maturation Arrest |
title_fullStr | Gene Spectrum and Clinical Traits of Nine Patients With Oocyte Maturation Arrest |
title_full_unstemmed | Gene Spectrum and Clinical Traits of Nine Patients With Oocyte Maturation Arrest |
title_short | Gene Spectrum and Clinical Traits of Nine Patients With Oocyte Maturation Arrest |
title_sort | gene spectrum and clinical traits of nine patients with oocyte maturation arrest |
topic | Genetics |
url | https://www.ncbi.nlm.nih.gov/pmc/articles/PMC8819080/ https://www.ncbi.nlm.nih.gov/pubmed/35140748 http://dx.doi.org/10.3389/fgene.2022.772143 |
work_keys_str_mv | AT huomingzhu genespectrumandclinicaltraitsofninepatientswithoocytematurationarrest AT zhangyile genespectrumandclinicaltraitsofninepatientswithoocytematurationarrest AT shisenlin genespectrumandclinicaltraitsofninepatientswithoocytematurationarrest AT shihao genespectrumandclinicaltraitsofninepatientswithoocytematurationarrest AT liuyidong genespectrumandclinicaltraitsofninepatientswithoocytematurationarrest AT zhanglingyun genespectrumandclinicaltraitsofninepatientswithoocytematurationarrest AT wangyanchi genespectrumandclinicaltraitsofninepatientswithoocytematurationarrest AT niuwenbin genespectrumandclinicaltraitsofninepatientswithoocytematurationarrest |