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Rare Disease Registries Are Key to Evidence-Based Personalized Medicine: Highlighting the European Experience

Rare diseases, such as inherited metabolic diseases, have been identified as a health priority within the European Union more than 20 years ago and have become an integral part of EU health programs and European Reference Networks. Having the potential to pool data, to achieve sufficient sample size...

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Autores principales: Kölker, Stefan, Gleich, Florian, Mütze, Ulrike, Opladen, Thomas
Formato: Online Artículo Texto
Lenguaje:English
Publicado: Frontiers Media S.A. 2022
Materias:
Acceso en línea:https://www.ncbi.nlm.nih.gov/pmc/articles/PMC8934440/
https://www.ncbi.nlm.nih.gov/pubmed/35317224
http://dx.doi.org/10.3389/fendo.2022.832063
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author Kölker, Stefan
Gleich, Florian
Mütze, Ulrike
Opladen, Thomas
author_facet Kölker, Stefan
Gleich, Florian
Mütze, Ulrike
Opladen, Thomas
author_sort Kölker, Stefan
collection PubMed
description Rare diseases, such as inherited metabolic diseases, have been identified as a health priority within the European Union more than 20 years ago and have become an integral part of EU health programs and European Reference Networks. Having the potential to pool data, to achieve sufficient sample size, to overcome the knowledge gap on rare diseases and to foster epidemiological and clinical research, patient registries are recognized as key instruments to evidence-based medicine for individuals with rare diseases. Patient registries can be used for multiple purposes, such as (1) describing the natural history and phenotypic diversity of rare diseases, (2) improving case definition and indication to treat, (3) identifying strategies for risk stratification and early prediction of disease severity (4), evaluating the impact of preventive, diagnostic, and therapeutic strategies on individual health, health economics, and the society, and (5) informing guideline development and policy makers. In contrast to clinical trials, patient registries aim to gather real-world evidence and to achieve generalizable results based on patient cohorts with a broad phenotypic spectrum. In order to develop a consistent and sustained framework for rare disease registries, uniform core principles have been formulated and have been formalized through the European Rare Disease Registration Infrastructure. Adherence to these core principles and compliance with the European general data protection regulations ensures that data collected and stored in patient registries can be exchanged and pooled in a protected environment. To illustrate the benefits and limitations of patient registries on rare disease research this review focuses on inherited metabolic diseases.
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spelling pubmed-89344402022-03-21 Rare Disease Registries Are Key to Evidence-Based Personalized Medicine: Highlighting the European Experience Kölker, Stefan Gleich, Florian Mütze, Ulrike Opladen, Thomas Front Endocrinol (Lausanne) Endocrinology Rare diseases, such as inherited metabolic diseases, have been identified as a health priority within the European Union more than 20 years ago and have become an integral part of EU health programs and European Reference Networks. Having the potential to pool data, to achieve sufficient sample size, to overcome the knowledge gap on rare diseases and to foster epidemiological and clinical research, patient registries are recognized as key instruments to evidence-based medicine for individuals with rare diseases. Patient registries can be used for multiple purposes, such as (1) describing the natural history and phenotypic diversity of rare diseases, (2) improving case definition and indication to treat, (3) identifying strategies for risk stratification and early prediction of disease severity (4), evaluating the impact of preventive, diagnostic, and therapeutic strategies on individual health, health economics, and the society, and (5) informing guideline development and policy makers. In contrast to clinical trials, patient registries aim to gather real-world evidence and to achieve generalizable results based on patient cohorts with a broad phenotypic spectrum. In order to develop a consistent and sustained framework for rare disease registries, uniform core principles have been formulated and have been formalized through the European Rare Disease Registration Infrastructure. Adherence to these core principles and compliance with the European general data protection regulations ensures that data collected and stored in patient registries can be exchanged and pooled in a protected environment. To illustrate the benefits and limitations of patient registries on rare disease research this review focuses on inherited metabolic diseases. Frontiers Media S.A. 2022-03-04 /pmc/articles/PMC8934440/ /pubmed/35317224 http://dx.doi.org/10.3389/fendo.2022.832063 Text en Copyright © 2022 Kölker, Gleich, Mütze and Opladen https://creativecommons.org/licenses/by/4.0/This is an open-access article distributed under the terms of the Creative Commons Attribution License (CC BY). The use, distribution or reproduction in other forums is permitted, provided the original author(s) and the copyright owner(s) are credited and that the original publication in this journal is cited, in accordance with accepted academic practice. No use, distribution or reproduction is permitted which does not comply with these terms.
spellingShingle Endocrinology
Kölker, Stefan
Gleich, Florian
Mütze, Ulrike
Opladen, Thomas
Rare Disease Registries Are Key to Evidence-Based Personalized Medicine: Highlighting the European Experience
title Rare Disease Registries Are Key to Evidence-Based Personalized Medicine: Highlighting the European Experience
title_full Rare Disease Registries Are Key to Evidence-Based Personalized Medicine: Highlighting the European Experience
title_fullStr Rare Disease Registries Are Key to Evidence-Based Personalized Medicine: Highlighting the European Experience
title_full_unstemmed Rare Disease Registries Are Key to Evidence-Based Personalized Medicine: Highlighting the European Experience
title_short Rare Disease Registries Are Key to Evidence-Based Personalized Medicine: Highlighting the European Experience
title_sort rare disease registries are key to evidence-based personalized medicine: highlighting the european experience
topic Endocrinology
url https://www.ncbi.nlm.nih.gov/pmc/articles/PMC8934440/
https://www.ncbi.nlm.nih.gov/pubmed/35317224
http://dx.doi.org/10.3389/fendo.2022.832063
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