Cargando…

CRISPR Detection and Research on Screening Mutant Gene TTN of Moyamoya Disease Family Based on Whole Exome Sequencing

Moyamoya disease (MMD) has a high incidence in Asian populations and demonstrates some degree of familial clustering. Whole-exome sequencing (WES) is useful in establishing key related genes in familial genetic diseases but is time-consuming and costly. Therefore, exploring a new method will be more...

Descripción completa

Detalles Bibliográficos
Autores principales: Xiao, Yilei, Liu, Weidong, Hao, Jiheng, Jiang, Qunlong, Wang, Xingbang, Yu, Donghu, Zhang, Liyong, Dong, Zhaogang, Wang, Jiyue
Formato: Online Artículo Texto
Lenguaje:English
Publicado: Frontiers Media S.A. 2022
Materias:
Acceso en línea:https://www.ncbi.nlm.nih.gov/pmc/articles/PMC8959584/
https://www.ncbi.nlm.nih.gov/pubmed/35355511
http://dx.doi.org/10.3389/fmolb.2022.846579
_version_ 1784677189122260992
author Xiao, Yilei
Liu, Weidong
Hao, Jiheng
Jiang, Qunlong
Wang, Xingbang
Yu, Donghu
Zhang, Liyong
Dong, Zhaogang
Wang, Jiyue
author_facet Xiao, Yilei
Liu, Weidong
Hao, Jiheng
Jiang, Qunlong
Wang, Xingbang
Yu, Donghu
Zhang, Liyong
Dong, Zhaogang
Wang, Jiyue
author_sort Xiao, Yilei
collection PubMed
description Moyamoya disease (MMD) has a high incidence in Asian populations and demonstrates some degree of familial clustering. Whole-exome sequencing (WES) is useful in establishing key related genes in familial genetic diseases but is time-consuming and costly. Therefore, exploring a new method will be more effective for the diagnosis of MMD. We identified familial cohorts showing MMD susceptibility and performed WES on 5 affected individuals to identify susceptibility loci, which identified point mutation sites in the titin (TTN) gene (rs771533925, rs559712998 and rs72677250). Moreover, TTN mutations were not found in a cohort of 50 sporadic MMD cases. We also analyzed mutation frequencies and used bioinformatic predictions to reveal mutation harmfulness, functions and probabilities of disease correlation, the results showed that rs771533925 and rs72677250 were likely harmful mutations with GO analyses indicating the involvement of TTN in a variety of biological processes related to MMD etiology. CRISPR-Cas12a assays designed to detect TTN mutations provided results consistent with WES analysis, which was further confirmed by Sanger sequencing. This study recognized TTN as a new familial gene marker for moyamoya disease and moreover, demonstrated that CRISPR-Cas12a has the advantages of rapid detection, low cost and simple operation, and has broad prospects in the practical application of rapid detection of MMD mutation sites.
format Online
Article
Text
id pubmed-8959584
institution National Center for Biotechnology Information
language English
publishDate 2022
publisher Frontiers Media S.A.
record_format MEDLINE/PubMed
spelling pubmed-89595842022-03-29 CRISPR Detection and Research on Screening Mutant Gene TTN of Moyamoya Disease Family Based on Whole Exome Sequencing Xiao, Yilei Liu, Weidong Hao, Jiheng Jiang, Qunlong Wang, Xingbang Yu, Donghu Zhang, Liyong Dong, Zhaogang Wang, Jiyue Front Mol Biosci Molecular Biosciences Moyamoya disease (MMD) has a high incidence in Asian populations and demonstrates some degree of familial clustering. Whole-exome sequencing (WES) is useful in establishing key related genes in familial genetic diseases but is time-consuming and costly. Therefore, exploring a new method will be more effective for the diagnosis of MMD. We identified familial cohorts showing MMD susceptibility and performed WES on 5 affected individuals to identify susceptibility loci, which identified point mutation sites in the titin (TTN) gene (rs771533925, rs559712998 and rs72677250). Moreover, TTN mutations were not found in a cohort of 50 sporadic MMD cases. We also analyzed mutation frequencies and used bioinformatic predictions to reveal mutation harmfulness, functions and probabilities of disease correlation, the results showed that rs771533925 and rs72677250 were likely harmful mutations with GO analyses indicating the involvement of TTN in a variety of biological processes related to MMD etiology. CRISPR-Cas12a assays designed to detect TTN mutations provided results consistent with WES analysis, which was further confirmed by Sanger sequencing. This study recognized TTN as a new familial gene marker for moyamoya disease and moreover, demonstrated that CRISPR-Cas12a has the advantages of rapid detection, low cost and simple operation, and has broad prospects in the practical application of rapid detection of MMD mutation sites. Frontiers Media S.A. 2022-03-09 /pmc/articles/PMC8959584/ /pubmed/35355511 http://dx.doi.org/10.3389/fmolb.2022.846579 Text en Copyright © 2022 Xiao, Liu, Hao, Jiang, Wang, Yu, Zhang, Dong and Wang. https://creativecommons.org/licenses/by/4.0/This is an open-access article distributed under the terms of the Creative Commons Attribution License (CC BY). The use, distribution or reproduction in other forums is permitted, provided the original author(s) and the copyright owner(s) are credited and that the original publication in this journal is cited, in accordance with accepted academic practice. No use, distribution or reproduction is permitted which does not comply with these terms.
spellingShingle Molecular Biosciences
Xiao, Yilei
Liu, Weidong
Hao, Jiheng
Jiang, Qunlong
Wang, Xingbang
Yu, Donghu
Zhang, Liyong
Dong, Zhaogang
Wang, Jiyue
CRISPR Detection and Research on Screening Mutant Gene TTN of Moyamoya Disease Family Based on Whole Exome Sequencing
title CRISPR Detection and Research on Screening Mutant Gene TTN of Moyamoya Disease Family Based on Whole Exome Sequencing
title_full CRISPR Detection and Research on Screening Mutant Gene TTN of Moyamoya Disease Family Based on Whole Exome Sequencing
title_fullStr CRISPR Detection and Research on Screening Mutant Gene TTN of Moyamoya Disease Family Based on Whole Exome Sequencing
title_full_unstemmed CRISPR Detection and Research on Screening Mutant Gene TTN of Moyamoya Disease Family Based on Whole Exome Sequencing
title_short CRISPR Detection and Research on Screening Mutant Gene TTN of Moyamoya Disease Family Based on Whole Exome Sequencing
title_sort crispr detection and research on screening mutant gene ttn of moyamoya disease family based on whole exome sequencing
topic Molecular Biosciences
url https://www.ncbi.nlm.nih.gov/pmc/articles/PMC8959584/
https://www.ncbi.nlm.nih.gov/pubmed/35355511
http://dx.doi.org/10.3389/fmolb.2022.846579
work_keys_str_mv AT xiaoyilei crisprdetectionandresearchonscreeningmutantgenettnofmoyamoyadiseasefamilybasedonwholeexomesequencing
AT liuweidong crisprdetectionandresearchonscreeningmutantgenettnofmoyamoyadiseasefamilybasedonwholeexomesequencing
AT haojiheng crisprdetectionandresearchonscreeningmutantgenettnofmoyamoyadiseasefamilybasedonwholeexomesequencing
AT jiangqunlong crisprdetectionandresearchonscreeningmutantgenettnofmoyamoyadiseasefamilybasedonwholeexomesequencing
AT wangxingbang crisprdetectionandresearchonscreeningmutantgenettnofmoyamoyadiseasefamilybasedonwholeexomesequencing
AT yudonghu crisprdetectionandresearchonscreeningmutantgenettnofmoyamoyadiseasefamilybasedonwholeexomesequencing
AT zhangliyong crisprdetectionandresearchonscreeningmutantgenettnofmoyamoyadiseasefamilybasedonwholeexomesequencing
AT dongzhaogang crisprdetectionandresearchonscreeningmutantgenettnofmoyamoyadiseasefamilybasedonwholeexomesequencing
AT wangjiyue crisprdetectionandresearchonscreeningmutantgenettnofmoyamoyadiseasefamilybasedonwholeexomesequencing