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O'Donnel-Luria-Rodan Syndrome: New gene variant identified in Romania (A case report)
O'Donnel-Luria-Rodan (ODLURO) syndrome is a neurodevelopmental disorder with autosomal dominant inheritance. It appears more frequently in males during the first decade of life and is associated with developmental delay, low intelligence quotient, autism spectrum disorder-like behavior, epileps...
Autores principales: | , , , , , |
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Formato: | Online Artículo Texto |
Lenguaje: | English |
Publicado: |
D.A. Spandidos
2022
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Materias: | |
Acceso en línea: | https://www.ncbi.nlm.nih.gov/pmc/articles/PMC9016787/ https://www.ncbi.nlm.nih.gov/pubmed/35481221 http://dx.doi.org/10.3892/etm.2022.11294 |
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author | Cătană, Andreea Kutasi, Enikő Cuzmici-Barabaș, Zina Militaru, Diana Iordănescu, Irina Militaru, Mariela Sanda |
author_facet | Cătană, Andreea Kutasi, Enikő Cuzmici-Barabaș, Zina Militaru, Diana Iordănescu, Irina Militaru, Mariela Sanda |
author_sort | Cătană, Andreea |
collection | PubMed |
description | O'Donnel-Luria-Rodan (ODLURO) syndrome is a neurodevelopmental disorder with autosomal dominant inheritance. It appears more frequently in males during the first decade of life and is associated with developmental delay, low intelligence quotient, autism spectrum disorder-like behavior, epilepsy, speech delay, aggression, facial and skeletal deformities, gastrointestinal symptoms and hypotonia. Although few cases have been documented, it appears that the phenotype spectrum may vary, especially between the two biological sexes. The present study reported a case of a 5-year-old male patient who was diagnosed with ODLURO at the age of 4 years using whole-exome sequencing. Molecular analysis identified a new mutation in the lysine methyltransferase 2E (inactive) (KMT2E) gene, which was classified as a variant with unknown significance. The father, who presented with non-specific and undiagnosed psychiatric manifestations, presented the same KMT2E variant. The case described in the present study is not only interesting because there are <40 cases described in the literature, but also because a new inherited mutation in the KMT2E gene, present in both father and son, that resulted in different phenotypic manifestations was identified. |
format | Online Article Text |
id | pubmed-9016787 |
institution | National Center for Biotechnology Information |
language | English |
publishDate | 2022 |
publisher | D.A. Spandidos |
record_format | MEDLINE/PubMed |
spelling | pubmed-90167872022-04-26 O'Donnel-Luria-Rodan Syndrome: New gene variant identified in Romania (A case report) Cătană, Andreea Kutasi, Enikő Cuzmici-Barabaș, Zina Militaru, Diana Iordănescu, Irina Militaru, Mariela Sanda Exp Ther Med Case Report O'Donnel-Luria-Rodan (ODLURO) syndrome is a neurodevelopmental disorder with autosomal dominant inheritance. It appears more frequently in males during the first decade of life and is associated with developmental delay, low intelligence quotient, autism spectrum disorder-like behavior, epilepsy, speech delay, aggression, facial and skeletal deformities, gastrointestinal symptoms and hypotonia. Although few cases have been documented, it appears that the phenotype spectrum may vary, especially between the two biological sexes. The present study reported a case of a 5-year-old male patient who was diagnosed with ODLURO at the age of 4 years using whole-exome sequencing. Molecular analysis identified a new mutation in the lysine methyltransferase 2E (inactive) (KMT2E) gene, which was classified as a variant with unknown significance. The father, who presented with non-specific and undiagnosed psychiatric manifestations, presented the same KMT2E variant. The case described in the present study is not only interesting because there are <40 cases described in the literature, but also because a new inherited mutation in the KMT2E gene, present in both father and son, that resulted in different phenotypic manifestations was identified. D.A. Spandidos 2022-05 2022-04-04 /pmc/articles/PMC9016787/ /pubmed/35481221 http://dx.doi.org/10.3892/etm.2022.11294 Text en Copyright: © Cătană et al. https://creativecommons.org/licenses/by-nc-nd/4.0/This is an open access article distributed under the terms of the Creative Commons Attribution-NonCommercial-NoDerivs License (https://creativecommons.org/licenses/by-nc-nd/4.0/) , which permits use and distribution in any medium, provided the original work is properly cited, the use is non-commercial and no modifications or adaptations are made. |
spellingShingle | Case Report Cătană, Andreea Kutasi, Enikő Cuzmici-Barabaș, Zina Militaru, Diana Iordănescu, Irina Militaru, Mariela Sanda O'Donnel-Luria-Rodan Syndrome: New gene variant identified in Romania (A case report) |
title | O'Donnel-Luria-Rodan Syndrome: New gene variant identified in Romania (A case report) |
title_full | O'Donnel-Luria-Rodan Syndrome: New gene variant identified in Romania (A case report) |
title_fullStr | O'Donnel-Luria-Rodan Syndrome: New gene variant identified in Romania (A case report) |
title_full_unstemmed | O'Donnel-Luria-Rodan Syndrome: New gene variant identified in Romania (A case report) |
title_short | O'Donnel-Luria-Rodan Syndrome: New gene variant identified in Romania (A case report) |
title_sort | o'donnel-luria-rodan syndrome: new gene variant identified in romania (a case report) |
topic | Case Report |
url | https://www.ncbi.nlm.nih.gov/pmc/articles/PMC9016787/ https://www.ncbi.nlm.nih.gov/pubmed/35481221 http://dx.doi.org/10.3892/etm.2022.11294 |
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