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Epilepsy and Hearing Loss in a Patient with a Rare Heterozygous Variant in the CACNA1H Gene

The calcium voltage-gated channel subunit alpha 1 H (CACNA1H) is a gene present in eukaryotic cells located on chromosome 16 that encodes the T-type calcium channels, which are important for calcium influx and depolarization of cells. Pathogenic variants in CACNA1H cause autosomal dominant susceptib...

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Autores principales: Algahtani, Hussein A., Shirah, Bader H., Samman, Ahmed, Alhazmi, Abdulellah
Formato: Online Artículo Texto
Lenguaje:English
Publicado: Korean Epilepsy Society 2022
Materias:
Acceso en línea:https://www.ncbi.nlm.nih.gov/pmc/articles/PMC9289382/
https://www.ncbi.nlm.nih.gov/pubmed/35910327
http://dx.doi.org/10.14581/jer.22006
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author Algahtani, Hussein A.
Shirah, Bader H.
Samman, Ahmed
Alhazmi, Abdulellah
author_facet Algahtani, Hussein A.
Shirah, Bader H.
Samman, Ahmed
Alhazmi, Abdulellah
author_sort Algahtani, Hussein A.
collection PubMed
description The calcium voltage-gated channel subunit alpha 1 H (CACNA1H) is a gene present in eukaryotic cells located on chromosome 16 that encodes the T-type calcium channels, which are important for calcium influx and depolarization of cells. Pathogenic variants in CACNA1H cause autosomal dominant susceptibility to idiopathic generalized epilepsy 6 (OMIM: 611942), which is a broad term that encompasses several common seizure phenotypes. In this article, we reported a Saudi female with a heterozygous variant in the CACNA1H gene (OMIM: 607904) who had epilepsy and hearing loss. This is the first case to report the association of epilepsy and hearing loss with a variant in CACNA1H. We believe that variant may be the reason for developing both epilepsy and sensorineural hearing loss. Further studies are needed to identify the role of CACNA1H in the physiology of the ear to allow for a better understanding of the effects of mutations. In children who present with early childhood hearing loss, genetic studies in highly selected cases including those with a strong family history of hearing loss and epilepsy may help detect a CACNA1H variant early and help with the early screening and diagnosis of other associated disorders including subclinical epilepsy.
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spelling pubmed-92893822022-07-29 Epilepsy and Hearing Loss in a Patient with a Rare Heterozygous Variant in the CACNA1H Gene Algahtani, Hussein A. Shirah, Bader H. Samman, Ahmed Alhazmi, Abdulellah J Epilepsy Res Case Report The calcium voltage-gated channel subunit alpha 1 H (CACNA1H) is a gene present in eukaryotic cells located on chromosome 16 that encodes the T-type calcium channels, which are important for calcium influx and depolarization of cells. Pathogenic variants in CACNA1H cause autosomal dominant susceptibility to idiopathic generalized epilepsy 6 (OMIM: 611942), which is a broad term that encompasses several common seizure phenotypes. In this article, we reported a Saudi female with a heterozygous variant in the CACNA1H gene (OMIM: 607904) who had epilepsy and hearing loss. This is the first case to report the association of epilepsy and hearing loss with a variant in CACNA1H. We believe that variant may be the reason for developing both epilepsy and sensorineural hearing loss. Further studies are needed to identify the role of CACNA1H in the physiology of the ear to allow for a better understanding of the effects of mutations. In children who present with early childhood hearing loss, genetic studies in highly selected cases including those with a strong family history of hearing loss and epilepsy may help detect a CACNA1H variant early and help with the early screening and diagnosis of other associated disorders including subclinical epilepsy. Korean Epilepsy Society 2022-06-30 /pmc/articles/PMC9289382/ /pubmed/35910327 http://dx.doi.org/10.14581/jer.22006 Text en Copyright © 2022 Korean Epilepsy Society https://creativecommons.org/licenses/by-nc/3.0/This is an Open Access article distributed under the terms of the Creative Commons Attribution Non-Commercial License (http://creativecommons.org/licenses/by-nc/3.0/ (https://creativecommons.org/licenses/by-nc/3.0/) ) which permits unrestricted non-commercial use, distribution, and reproduction in any medium, provided the original work is properly cited.
spellingShingle Case Report
Algahtani, Hussein A.
Shirah, Bader H.
Samman, Ahmed
Alhazmi, Abdulellah
Epilepsy and Hearing Loss in a Patient with a Rare Heterozygous Variant in the CACNA1H Gene
title Epilepsy and Hearing Loss in a Patient with a Rare Heterozygous Variant in the CACNA1H Gene
title_full Epilepsy and Hearing Loss in a Patient with a Rare Heterozygous Variant in the CACNA1H Gene
title_fullStr Epilepsy and Hearing Loss in a Patient with a Rare Heterozygous Variant in the CACNA1H Gene
title_full_unstemmed Epilepsy and Hearing Loss in a Patient with a Rare Heterozygous Variant in the CACNA1H Gene
title_short Epilepsy and Hearing Loss in a Patient with a Rare Heterozygous Variant in the CACNA1H Gene
title_sort epilepsy and hearing loss in a patient with a rare heterozygous variant in the cacna1h gene
topic Case Report
url https://www.ncbi.nlm.nih.gov/pmc/articles/PMC9289382/
https://www.ncbi.nlm.nih.gov/pubmed/35910327
http://dx.doi.org/10.14581/jer.22006
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