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Coffin-Lowry Syndrome Induced by RPS6KA3 Gene Variation in China: A Case Report in Twins
Background and objectives: Coffin-Lowry Syndrome (CLS), a rare neurodegenerative disorder, is mainly diagnosed based on clinical manifestations and molecular analyses. In total, about 20 cases of CLS have been reported in China. Here, we report two cases of CLS in identical twin brothers and examine...
Autores principales: | , , |
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Formato: | Online Artículo Texto |
Lenguaje: | English |
Publicado: |
MDPI
2022
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Materias: | |
Acceso en línea: | https://www.ncbi.nlm.nih.gov/pmc/articles/PMC9320784/ https://www.ncbi.nlm.nih.gov/pubmed/35888677 http://dx.doi.org/10.3390/medicina58070958 |
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author | Jin, Huiying Li, Haifeng Qiang, Shu |
author_facet | Jin, Huiying Li, Haifeng Qiang, Shu |
author_sort | Jin, Huiying |
collection | PubMed |
description | Background and objectives: Coffin-Lowry Syndrome (CLS), a rare neurodegenerative disorder, is mainly diagnosed based on clinical manifestations and molecular analyses. In total, about 20 cases of CLS have been reported in China. Here, we report two cases of CLS in identical twin brothers and examine their potential causative mutations. Methods: The Trio mode was used in this analysis, i.e., DNA from the proband and his parents was sequenced. Furthermore, DNA from the proband’s twin brother was used for confirmation. Results: A hemizygous variation was detected in the 11th exon of the RPS6KA3 gene, c.898C>T (p.R300*) of the proband, and the same site variation was detected in his identical twin brother; however, the mutation was not detected in his parents. Conclusions: The RPS6KA3 gene mutation c.898C>T (p.R300*) is the causative factor of familial CLS. The variant detected was reported for the first time in the Chinese population. Additionally, by analyzing the previous literature, we were able to summarize the phenotypic and genetic characteristics of GLS in China. |
format | Online Article Text |
id | pubmed-9320784 |
institution | National Center for Biotechnology Information |
language | English |
publishDate | 2022 |
publisher | MDPI |
record_format | MEDLINE/PubMed |
spelling | pubmed-93207842022-07-27 Coffin-Lowry Syndrome Induced by RPS6KA3 Gene Variation in China: A Case Report in Twins Jin, Huiying Li, Haifeng Qiang, Shu Medicina (Kaunas) Case Report Background and objectives: Coffin-Lowry Syndrome (CLS), a rare neurodegenerative disorder, is mainly diagnosed based on clinical manifestations and molecular analyses. In total, about 20 cases of CLS have been reported in China. Here, we report two cases of CLS in identical twin brothers and examine their potential causative mutations. Methods: The Trio mode was used in this analysis, i.e., DNA from the proband and his parents was sequenced. Furthermore, DNA from the proband’s twin brother was used for confirmation. Results: A hemizygous variation was detected in the 11th exon of the RPS6KA3 gene, c.898C>T (p.R300*) of the proband, and the same site variation was detected in his identical twin brother; however, the mutation was not detected in his parents. Conclusions: The RPS6KA3 gene mutation c.898C>T (p.R300*) is the causative factor of familial CLS. The variant detected was reported for the first time in the Chinese population. Additionally, by analyzing the previous literature, we were able to summarize the phenotypic and genetic characteristics of GLS in China. MDPI 2022-07-20 /pmc/articles/PMC9320784/ /pubmed/35888677 http://dx.doi.org/10.3390/medicina58070958 Text en © 2022 by the authors. https://creativecommons.org/licenses/by/4.0/Licensee MDPI, Basel, Switzerland. This article is an open access article distributed under the terms and conditions of the Creative Commons Attribution (CC BY) license (https://creativecommons.org/licenses/by/4.0/). |
spellingShingle | Case Report Jin, Huiying Li, Haifeng Qiang, Shu Coffin-Lowry Syndrome Induced by RPS6KA3 Gene Variation in China: A Case Report in Twins |
title | Coffin-Lowry Syndrome Induced by RPS6KA3 Gene Variation in China: A Case Report in Twins |
title_full | Coffin-Lowry Syndrome Induced by RPS6KA3 Gene Variation in China: A Case Report in Twins |
title_fullStr | Coffin-Lowry Syndrome Induced by RPS6KA3 Gene Variation in China: A Case Report in Twins |
title_full_unstemmed | Coffin-Lowry Syndrome Induced by RPS6KA3 Gene Variation in China: A Case Report in Twins |
title_short | Coffin-Lowry Syndrome Induced by RPS6KA3 Gene Variation in China: A Case Report in Twins |
title_sort | coffin-lowry syndrome induced by rps6ka3 gene variation in china: a case report in twins |
topic | Case Report |
url | https://www.ncbi.nlm.nih.gov/pmc/articles/PMC9320784/ https://www.ncbi.nlm.nih.gov/pubmed/35888677 http://dx.doi.org/10.3390/medicina58070958 |
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