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The Management of Asymptomatic Congenital Pulmonary Airway Malformation: Results of a European Delphi Survey
Consensus on the optimal management of asymptomatic congenital pulmonary airway malformation (CPAM) is lacking, and comparison between studies remains difficult due to a large variety in outcome measures. We aimed to define a core outcome set (COS) for pediatric patients with an asymptomatic CPAM. A...
Autores principales: | , , , , , , , , , , , , , , , , , , , , , , , , , , , , , , , , , , , , |
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Formato: | Online Artículo Texto |
Lenguaje: | English |
Publicado: |
MDPI
2022
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Materias: | |
Acceso en línea: | https://www.ncbi.nlm.nih.gov/pmc/articles/PMC9406306/ https://www.ncbi.nlm.nih.gov/pubmed/36010044 http://dx.doi.org/10.3390/children9081153 |
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author | Kersten, Casper M. Hermelijn, Sergei M. Mullassery, Dhanya Muthialu, Nagarajan Cobanoglu, Nazan Gartner, Silvia Bagolan, Pietro Mesas Burgos, Carmen Sgrò, Alberto Heyman, Stijn Till, Holger Suominen, Janne Schurink, Maarten Desender, Liesbeth Losty, Paul Steyaert, Henri Terheggen-Lagro, Suzanne Metzelder, Martin Bonnard, Arnaud Sfeir, Rony Singh, Michael Yardley, Iain Rikkers-Mutsaerts, Noor R. V. M. van der Ent, Cornelis K. Qvist, Niels Cox, Des W. Peters, Robert Bannier, Michiel A. G. E. Wessel, Lucas Proesmans, Marijke Stanton, Michael Hannon, Edward Zampoli, Marco Morini, Francesco Tiddens, Harm A. W. M. Wijnen, René M. H. Schnater, Johannes M. |
author_facet | Kersten, Casper M. Hermelijn, Sergei M. Mullassery, Dhanya Muthialu, Nagarajan Cobanoglu, Nazan Gartner, Silvia Bagolan, Pietro Mesas Burgos, Carmen Sgrò, Alberto Heyman, Stijn Till, Holger Suominen, Janne Schurink, Maarten Desender, Liesbeth Losty, Paul Steyaert, Henri Terheggen-Lagro, Suzanne Metzelder, Martin Bonnard, Arnaud Sfeir, Rony Singh, Michael Yardley, Iain Rikkers-Mutsaerts, Noor R. V. M. van der Ent, Cornelis K. Qvist, Niels Cox, Des W. Peters, Robert Bannier, Michiel A. G. E. Wessel, Lucas Proesmans, Marijke Stanton, Michael Hannon, Edward Zampoli, Marco Morini, Francesco Tiddens, Harm A. W. M. Wijnen, René M. H. Schnater, Johannes M. |
author_sort | Kersten, Casper M. |
collection | PubMed |
description | Consensus on the optimal management of asymptomatic congenital pulmonary airway malformation (CPAM) is lacking, and comparison between studies remains difficult due to a large variety in outcome measures. We aimed to define a core outcome set (COS) for pediatric patients with an asymptomatic CPAM. An online, three-round Delphi survey was conducted in two stakeholder groups of specialized caregivers (surgeons and non-surgeons) in various European centers. Proposed outcome parameters were scored according to level of importance, and the final COS was established through consensus. A total of 55 participants (33 surgeons, 22 non-surgeons) from 28 centers in 13 European countries completed the three rounds and rated 43 outcome parameters. The final COS comprises seven outcome parameters: respiratory insufficiency, surgical complications, mass effect/mediastinal shift (at three time-points) and multifocal disease (at two time-points). The seven outcome parameters included in the final COS reflect the diversity in priorities among this large group of European participants. However, we recommend the incorporation of these outcome parameters in the design of future studies, as they describe measurable and validated outcomes as well as the accepted age at measurement. |
format | Online Article Text |
id | pubmed-9406306 |
institution | National Center for Biotechnology Information |
language | English |
publishDate | 2022 |
publisher | MDPI |
record_format | MEDLINE/PubMed |
spelling | pubmed-94063062022-08-26 The Management of Asymptomatic Congenital Pulmonary Airway Malformation: Results of a European Delphi Survey Kersten, Casper M. Hermelijn, Sergei M. Mullassery, Dhanya Muthialu, Nagarajan Cobanoglu, Nazan Gartner, Silvia Bagolan, Pietro Mesas Burgos, Carmen Sgrò, Alberto Heyman, Stijn Till, Holger Suominen, Janne Schurink, Maarten Desender, Liesbeth Losty, Paul Steyaert, Henri Terheggen-Lagro, Suzanne Metzelder, Martin Bonnard, Arnaud Sfeir, Rony Singh, Michael Yardley, Iain Rikkers-Mutsaerts, Noor R. V. M. van der Ent, Cornelis K. Qvist, Niels Cox, Des W. Peters, Robert Bannier, Michiel A. G. E. Wessel, Lucas Proesmans, Marijke Stanton, Michael Hannon, Edward Zampoli, Marco Morini, Francesco Tiddens, Harm A. W. M. Wijnen, René M. H. Schnater, Johannes M. Children (Basel) Article Consensus on the optimal management of asymptomatic congenital pulmonary airway malformation (CPAM) is lacking, and comparison between studies remains difficult due to a large variety in outcome measures. We aimed to define a core outcome set (COS) for pediatric patients with an asymptomatic CPAM. An online, three-round Delphi survey was conducted in two stakeholder groups of specialized caregivers (surgeons and non-surgeons) in various European centers. Proposed outcome parameters were scored according to level of importance, and the final COS was established through consensus. A total of 55 participants (33 surgeons, 22 non-surgeons) from 28 centers in 13 European countries completed the three rounds and rated 43 outcome parameters. The final COS comprises seven outcome parameters: respiratory insufficiency, surgical complications, mass effect/mediastinal shift (at three time-points) and multifocal disease (at two time-points). The seven outcome parameters included in the final COS reflect the diversity in priorities among this large group of European participants. However, we recommend the incorporation of these outcome parameters in the design of future studies, as they describe measurable and validated outcomes as well as the accepted age at measurement. MDPI 2022-07-30 /pmc/articles/PMC9406306/ /pubmed/36010044 http://dx.doi.org/10.3390/children9081153 Text en © 2022 by the authors. https://creativecommons.org/licenses/by/4.0/Licensee MDPI, Basel, Switzerland. This article is an open access article distributed under the terms and conditions of the Creative Commons Attribution (CC BY) license (https://creativecommons.org/licenses/by/4.0/). |
spellingShingle | Article Kersten, Casper M. Hermelijn, Sergei M. Mullassery, Dhanya Muthialu, Nagarajan Cobanoglu, Nazan Gartner, Silvia Bagolan, Pietro Mesas Burgos, Carmen Sgrò, Alberto Heyman, Stijn Till, Holger Suominen, Janne Schurink, Maarten Desender, Liesbeth Losty, Paul Steyaert, Henri Terheggen-Lagro, Suzanne Metzelder, Martin Bonnard, Arnaud Sfeir, Rony Singh, Michael Yardley, Iain Rikkers-Mutsaerts, Noor R. V. M. van der Ent, Cornelis K. Qvist, Niels Cox, Des W. Peters, Robert Bannier, Michiel A. G. E. Wessel, Lucas Proesmans, Marijke Stanton, Michael Hannon, Edward Zampoli, Marco Morini, Francesco Tiddens, Harm A. W. M. Wijnen, René M. H. Schnater, Johannes M. The Management of Asymptomatic Congenital Pulmonary Airway Malformation: Results of a European Delphi Survey |
title | The Management of Asymptomatic Congenital Pulmonary Airway Malformation: Results of a European Delphi Survey |
title_full | The Management of Asymptomatic Congenital Pulmonary Airway Malformation: Results of a European Delphi Survey |
title_fullStr | The Management of Asymptomatic Congenital Pulmonary Airway Malformation: Results of a European Delphi Survey |
title_full_unstemmed | The Management of Asymptomatic Congenital Pulmonary Airway Malformation: Results of a European Delphi Survey |
title_short | The Management of Asymptomatic Congenital Pulmonary Airway Malformation: Results of a European Delphi Survey |
title_sort | management of asymptomatic congenital pulmonary airway malformation: results of a european delphi survey |
topic | Article |
url | https://www.ncbi.nlm.nih.gov/pmc/articles/PMC9406306/ https://www.ncbi.nlm.nih.gov/pubmed/36010044 http://dx.doi.org/10.3390/children9081153 |
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