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Vascular Ehlers-Danlos syndrome, an often unrecognized clinical entity: a case report of a novel mutation in the COL3A1 gene

Due to life-threatening complications, vascular Ehlers-Danlos syndrome (vEDS) is the most severe form of EDS. Because the syndrome is associated with a shortened life expectancy and variable clinical presentation, diagnosis confirmed by genetic testing is crucial to determining appropriate treatment...

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Autores principales: Huljev Frković, Sanda, Marija Slišković, Ana, Toivonen, Mia, Crkvenac Gregorek, Andrea, Šutalo, Ana, Vrkić Kirhmajer, Majda
Formato: Online Artículo Texto
Lenguaje:English
Publicado: Croatian Medical Schools 2022
Materias:
Acceso en línea:https://www.ncbi.nlm.nih.gov/pmc/articles/PMC9468738/
https://www.ncbi.nlm.nih.gov/pubmed/36046937
http://dx.doi.org/10.3325/cmj.2022.63.394
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author Huljev Frković, Sanda
Marija Slišković, Ana
Toivonen, Mia
Crkvenac Gregorek, Andrea
Šutalo, Ana
Vrkić Kirhmajer, Majda
author_facet Huljev Frković, Sanda
Marija Slišković, Ana
Toivonen, Mia
Crkvenac Gregorek, Andrea
Šutalo, Ana
Vrkić Kirhmajer, Majda
author_sort Huljev Frković, Sanda
collection PubMed
description Due to life-threatening complications, vascular Ehlers-Danlos syndrome (vEDS) is the most severe form of EDS. Because the syndrome is associated with a shortened life expectancy and variable clinical presentation, diagnosis confirmed by genetic testing is crucial to determining appropriate treatment. Despite some distinguishing features, this rare disease often goes unrecognized. Apart from surgical or endovascular treatment of serious vascular complications, medical treatment based on celiprolol helps reduce arterial complications. We report on a case of vEDS in a young man who suffered several episodes of severe vascular complications. The diagnosis of vEDS was established based on clinical manifestations and confirmed by genetic testing. A novel heterozygous pathogenic variant in the COL3A1 gene was found. To our knowledge, this is the first case of vEDS caused by this variant.
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spelling pubmed-94687382022-09-23 Vascular Ehlers-Danlos syndrome, an often unrecognized clinical entity: a case report of a novel mutation in the COL3A1 gene Huljev Frković, Sanda Marija Slišković, Ana Toivonen, Mia Crkvenac Gregorek, Andrea Šutalo, Ana Vrkić Kirhmajer, Majda Croat Med J Case Report Due to life-threatening complications, vascular Ehlers-Danlos syndrome (vEDS) is the most severe form of EDS. Because the syndrome is associated with a shortened life expectancy and variable clinical presentation, diagnosis confirmed by genetic testing is crucial to determining appropriate treatment. Despite some distinguishing features, this rare disease often goes unrecognized. Apart from surgical or endovascular treatment of serious vascular complications, medical treatment based on celiprolol helps reduce arterial complications. We report on a case of vEDS in a young man who suffered several episodes of severe vascular complications. The diagnosis of vEDS was established based on clinical manifestations and confirmed by genetic testing. A novel heterozygous pathogenic variant in the COL3A1 gene was found. To our knowledge, this is the first case of vEDS caused by this variant. Croatian Medical Schools 2022-08 /pmc/articles/PMC9468738/ /pubmed/36046937 http://dx.doi.org/10.3325/cmj.2022.63.394 Text en Copyright © 2022 by the Croatian Medical Journal. All rights reserved. https://creativecommons.org/licenses/by/2.5/This is an open access article distributed under the Creative Commons Attribution License, which permits unrestricted non-commercial use, distribution, and reproduction in any medium, provided the original work is properly cited.
spellingShingle Case Report
Huljev Frković, Sanda
Marija Slišković, Ana
Toivonen, Mia
Crkvenac Gregorek, Andrea
Šutalo, Ana
Vrkić Kirhmajer, Majda
Vascular Ehlers-Danlos syndrome, an often unrecognized clinical entity: a case report of a novel mutation in the COL3A1 gene
title Vascular Ehlers-Danlos syndrome, an often unrecognized clinical entity: a case report of a novel mutation in the COL3A1 gene
title_full Vascular Ehlers-Danlos syndrome, an often unrecognized clinical entity: a case report of a novel mutation in the COL3A1 gene
title_fullStr Vascular Ehlers-Danlos syndrome, an often unrecognized clinical entity: a case report of a novel mutation in the COL3A1 gene
title_full_unstemmed Vascular Ehlers-Danlos syndrome, an often unrecognized clinical entity: a case report of a novel mutation in the COL3A1 gene
title_short Vascular Ehlers-Danlos syndrome, an often unrecognized clinical entity: a case report of a novel mutation in the COL3A1 gene
title_sort vascular ehlers-danlos syndrome, an often unrecognized clinical entity: a case report of a novel mutation in the col3a1 gene
topic Case Report
url https://www.ncbi.nlm.nih.gov/pmc/articles/PMC9468738/
https://www.ncbi.nlm.nih.gov/pubmed/36046937
http://dx.doi.org/10.3325/cmj.2022.63.394
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