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Ruptured innominate artery pseudoaneurysm presenting as hoarseness in Behçet’s syndrome: a case report

BACKGROUND: Vascular involvement is an infrequent clinical manifestation of Behçet’s syndrome. Owing to the rarity of arterial involvement in Behçet’s syndrome, there is limited experience in managing this phenomenon. CASE PRESENTATION: Here, we report a 28-year-old Iranian man with a Behçet’s syndr...

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Autores principales: Johari, Hamed Ghoddusi, Moein, Seyed Arman, Shenavande, Saeedeh, Amirian, Armin, Nabavizadeh, Sara Sadat
Formato: Online Artículo Texto
Lenguaje:English
Publicado: BioMed Central 2022
Materias:
Acceso en línea:https://www.ncbi.nlm.nih.gov/pmc/articles/PMC9694818/
https://www.ncbi.nlm.nih.gov/pubmed/36424646
http://dx.doi.org/10.1186/s13256-022-03662-7
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author Johari, Hamed Ghoddusi
Moein, Seyed Arman
Shenavande, Saeedeh
Amirian, Armin
Nabavizadeh, Sara Sadat
author_facet Johari, Hamed Ghoddusi
Moein, Seyed Arman
Shenavande, Saeedeh
Amirian, Armin
Nabavizadeh, Sara Sadat
author_sort Johari, Hamed Ghoddusi
collection PubMed
description BACKGROUND: Vascular involvement is an infrequent clinical manifestation of Behçet’s syndrome. Owing to the rarity of arterial involvement in Behçet’s syndrome, there is limited experience in managing this phenomenon. CASE PRESENTATION: Here, we report a 28-year-old Iranian man with a Behçet’s syndrome background, who presented with shoulder pain and hoarseness. Chest computed tomography angiography was conducted with a suspicion of a vascular pathology causing pressure on the recurrent laryngeal nerves. The patient was diagnosed with a ruptured innominate artery pseudoaneurysm. An innominate artery to the right common carotid artery bypass was performed, and the pseudoaneurysm was excised and replaced with an expandable polytetrafluoroethylene graft. Eventually, the patient was discharged after an uneventful hospital course. CONCLUSION: It appears that we are still a long way from finding the optimal treatment for Behçet’s syndrome vascular involvement, and a combination of surgical and medicinal treatments is required.
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spelling pubmed-96948182022-11-26 Ruptured innominate artery pseudoaneurysm presenting as hoarseness in Behçet’s syndrome: a case report Johari, Hamed Ghoddusi Moein, Seyed Arman Shenavande, Saeedeh Amirian, Armin Nabavizadeh, Sara Sadat J Med Case Rep Case Report BACKGROUND: Vascular involvement is an infrequent clinical manifestation of Behçet’s syndrome. Owing to the rarity of arterial involvement in Behçet’s syndrome, there is limited experience in managing this phenomenon. CASE PRESENTATION: Here, we report a 28-year-old Iranian man with a Behçet’s syndrome background, who presented with shoulder pain and hoarseness. Chest computed tomography angiography was conducted with a suspicion of a vascular pathology causing pressure on the recurrent laryngeal nerves. The patient was diagnosed with a ruptured innominate artery pseudoaneurysm. An innominate artery to the right common carotid artery bypass was performed, and the pseudoaneurysm was excised and replaced with an expandable polytetrafluoroethylene graft. Eventually, the patient was discharged after an uneventful hospital course. CONCLUSION: It appears that we are still a long way from finding the optimal treatment for Behçet’s syndrome vascular involvement, and a combination of surgical and medicinal treatments is required. BioMed Central 2022-11-24 /pmc/articles/PMC9694818/ /pubmed/36424646 http://dx.doi.org/10.1186/s13256-022-03662-7 Text en © The Author(s) 2022 https://creativecommons.org/licenses/by/4.0/Open AccessThis article is licensed under a Creative Commons Attribution 4.0 International License, which permits use, sharing, adaptation, distribution and reproduction in any medium or format, as long as you give appropriate credit to the original author(s) and the source, provide a link to the Creative Commons licence, and indicate if changes were made. The images or other third party material in this article are included in the article's Creative Commons licence, unless indicated otherwise in a credit line to the material. If material is not included in the article's Creative Commons licence and your intended use is not permitted by statutory regulation or exceeds the permitted use, you will need to obtain permission directly from the copyright holder. To view a copy of this licence, visit http://creativecommons.org/licenses/by/4.0/ (https://creativecommons.org/licenses/by/4.0/) . The Creative Commons Public Domain Dedication waiver (http://creativecommons.org/publicdomain/zero/1.0/ (https://creativecommons.org/publicdomain/zero/1.0/) ) applies to the data made available in this article, unless otherwise stated in a credit line to the data.
spellingShingle Case Report
Johari, Hamed Ghoddusi
Moein, Seyed Arman
Shenavande, Saeedeh
Amirian, Armin
Nabavizadeh, Sara Sadat
Ruptured innominate artery pseudoaneurysm presenting as hoarseness in Behçet’s syndrome: a case report
title Ruptured innominate artery pseudoaneurysm presenting as hoarseness in Behçet’s syndrome: a case report
title_full Ruptured innominate artery pseudoaneurysm presenting as hoarseness in Behçet’s syndrome: a case report
title_fullStr Ruptured innominate artery pseudoaneurysm presenting as hoarseness in Behçet’s syndrome: a case report
title_full_unstemmed Ruptured innominate artery pseudoaneurysm presenting as hoarseness in Behçet’s syndrome: a case report
title_short Ruptured innominate artery pseudoaneurysm presenting as hoarseness in Behçet’s syndrome: a case report
title_sort ruptured innominate artery pseudoaneurysm presenting as hoarseness in behçet’s syndrome: a case report
topic Case Report
url https://www.ncbi.nlm.nih.gov/pmc/articles/PMC9694818/
https://www.ncbi.nlm.nih.gov/pubmed/36424646
http://dx.doi.org/10.1186/s13256-022-03662-7
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