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Extremely Rare Case of Cavernous Haemangioma of Submandibular Gland

INTRODUCTION: Haemangioma or hemangioendothelioma is amongst the commonest developmental, vascular lesions of infancy and childhood. Hemangioendothelioma of the salivary glands, however, is extremely rare. Due to their rarity, they may be misdiagnosed as lymphangiomas or other cystic lesions found m...

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Autores principales: Kalra, Rishita, Rizvi, Sama, Pathak, Vivek Kumar, Nayak, Pradeepti
Formato: Online Artículo Texto
Lenguaje:English
Publicado: Mashhad University of Medical Sciences 2022
Materias:
Acceso en línea:https://www.ncbi.nlm.nih.gov/pmc/articles/PMC9709394/
https://www.ncbi.nlm.nih.gov/pubmed/36474490
http://dx.doi.org/10.22038/IJORL.2022.64705.3221
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author Kalra, Rishita
Rizvi, Sama
Pathak, Vivek Kumar
Nayak, Pradeepti
author_facet Kalra, Rishita
Rizvi, Sama
Pathak, Vivek Kumar
Nayak, Pradeepti
author_sort Kalra, Rishita
collection PubMed
description INTRODUCTION: Haemangioma or hemangioendothelioma is amongst the commonest developmental, vascular lesions of infancy and childhood. Hemangioendothelioma of the salivary glands, however, is extremely rare. Due to their rarity, they may be misdiagnosed as lymphangiomas or other cystic lesions found more commonly in the region. This may lead to surgical complications including torrential hemorrhage that may have dire consequences for the patient. CASE REPORT: Herein we present the case of a nine-year-old male with a cavernous haemangioma involving the left submandibular gland which was diagnosed on-table due to inconclusive pre-operative radiological and pathological diagnosis. Fortunately, due to meticulous dissection and care the lesion was excised in toto without any significant blood loss. CONCLUSIONS: Haemangioma of the submandibular gland is so uncommon that often it isn't even considered a differential diagnosis for cystic swellings and lesions in this region. Mistaken diagnoses preoperatively may prove disastrous for the patient. Excision of haemangiomas requires planning for hemostasis and blood loss if it occurs. Even minor iatrogenic manipulation of vascular lesions may completely obscure the field due to bleeding, making dissection and recognition of anatomical landmarks very difficult. This is especially dangerous in the submandibular region due to the proximity of various vital vascular and neural elements. A differential of haemangioma should therefore always be considered by surgeons and radiologists alike for lesions with suspicious or indeterminate features, in this region.
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spelling pubmed-97093942022-12-05 Extremely Rare Case of Cavernous Haemangioma of Submandibular Gland Kalra, Rishita Rizvi, Sama Pathak, Vivek Kumar Nayak, Pradeepti Iran J Otorhinolaryngol Case Report INTRODUCTION: Haemangioma or hemangioendothelioma is amongst the commonest developmental, vascular lesions of infancy and childhood. Hemangioendothelioma of the salivary glands, however, is extremely rare. Due to their rarity, they may be misdiagnosed as lymphangiomas or other cystic lesions found more commonly in the region. This may lead to surgical complications including torrential hemorrhage that may have dire consequences for the patient. CASE REPORT: Herein we present the case of a nine-year-old male with a cavernous haemangioma involving the left submandibular gland which was diagnosed on-table due to inconclusive pre-operative radiological and pathological diagnosis. Fortunately, due to meticulous dissection and care the lesion was excised in toto without any significant blood loss. CONCLUSIONS: Haemangioma of the submandibular gland is so uncommon that often it isn't even considered a differential diagnosis for cystic swellings and lesions in this region. Mistaken diagnoses preoperatively may prove disastrous for the patient. Excision of haemangiomas requires planning for hemostasis and blood loss if it occurs. Even minor iatrogenic manipulation of vascular lesions may completely obscure the field due to bleeding, making dissection and recognition of anatomical landmarks very difficult. This is especially dangerous in the submandibular region due to the proximity of various vital vascular and neural elements. A differential of haemangioma should therefore always be considered by surgeons and radiologists alike for lesions with suspicious or indeterminate features, in this region. Mashhad University of Medical Sciences 2022-11 /pmc/articles/PMC9709394/ /pubmed/36474490 http://dx.doi.org/10.22038/IJORL.2022.64705.3221 Text en https://creativecommons.org/licenses/by/3.0/This is an Open Access article distributed under the terms of the Creative Commons Attribution License, (http://creativecommons.org/licenses/by/3.0/ (https://creativecommons.org/licenses/by/3.0/) ) which permits unrestricted use, distribution, and reproduction in any medium, provided the original work is properly cited.
spellingShingle Case Report
Kalra, Rishita
Rizvi, Sama
Pathak, Vivek Kumar
Nayak, Pradeepti
Extremely Rare Case of Cavernous Haemangioma of Submandibular Gland
title Extremely Rare Case of Cavernous Haemangioma of Submandibular Gland
title_full Extremely Rare Case of Cavernous Haemangioma of Submandibular Gland
title_fullStr Extremely Rare Case of Cavernous Haemangioma of Submandibular Gland
title_full_unstemmed Extremely Rare Case of Cavernous Haemangioma of Submandibular Gland
title_short Extremely Rare Case of Cavernous Haemangioma of Submandibular Gland
title_sort extremely rare case of cavernous haemangioma of submandibular gland
topic Case Report
url https://www.ncbi.nlm.nih.gov/pmc/articles/PMC9709394/
https://www.ncbi.nlm.nih.gov/pubmed/36474490
http://dx.doi.org/10.22038/IJORL.2022.64705.3221
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