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Homozygous GRHPR C.494G>A mutation is deleterious that causes early onset of nephrolithiasis in West Bengal, India
Pediatric nephrolithiasis (NL) or Kidney stone disease (KSD) is an untethered topic in Asian population. In Western countries, the annual incidence of paediatric NL is around 6–10%. Here, we present data from West Bengal, India, on lower age (LA, 0–20 years) NL and its prevalence for the first time....
Autores principales: | , , , , , , , , , , , |
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Formato: | Online Artículo Texto |
Lenguaje: | English |
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Frontiers Media S.A.
2022
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Acceso en línea: | https://www.ncbi.nlm.nih.gov/pmc/articles/PMC9815608/ https://www.ncbi.nlm.nih.gov/pubmed/36619171 http://dx.doi.org/10.3389/fmolb.2022.1049620 |
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author | Chatterjee, Arindam Sarkar, Kunal Bank, Sarbashri Ghosh, Sudakshina Kumar Pal, Dilip Saraf, Siddharth Wakle, Dhansagar Roy, Bidyut Chakraborty, Santanu Bankura, Biswabandhu Chattopadhyay, Debprasad Das, Madhusudan |
author_facet | Chatterjee, Arindam Sarkar, Kunal Bank, Sarbashri Ghosh, Sudakshina Kumar Pal, Dilip Saraf, Siddharth Wakle, Dhansagar Roy, Bidyut Chakraborty, Santanu Bankura, Biswabandhu Chattopadhyay, Debprasad Das, Madhusudan |
author_sort | Chatterjee, Arindam |
collection | PubMed |
description | Pediatric nephrolithiasis (NL) or Kidney stone disease (KSD) is an untethered topic in Asian population. In Western countries, the annual incidence of paediatric NL is around 6–10%. Here, we present data from West Bengal, India, on lower age (LA, 0–20 years) NL and its prevalence for the first time. To discover the mutations associated with KSD, twenty-four (18 + 6) rare LA-NL patients were selected for Whole Exome Sequencing (WES) and Sanger sequencing, respectively. It was found that GRHPR c. 494G>A mutation (MZ826703) is predominant in our study cohort. This specific homozygous mutation is functionally studied for the first time directly from human peripheral mononuclear cell (PBMC) samples. Using expression study with biochemical activity and computational analysis we assumed that the mutation is pathogenic with loss of function. Moreover, three genes, AGXT, HOGA1 and GRHPR with Novel variants known to cause hyperoxaluria were found frequently in the study cohort. Our study analyses the genes and variations that cause LA-NL, as well as the molecular function of the GRHPR mutation, which may serve as a clinical marker in the population of West Bengal, Eastern India. |
format | Online Article Text |
id | pubmed-9815608 |
institution | National Center for Biotechnology Information |
language | English |
publishDate | 2022 |
publisher | Frontiers Media S.A. |
record_format | MEDLINE/PubMed |
spelling | pubmed-98156082023-01-06 Homozygous GRHPR C.494G>A mutation is deleterious that causes early onset of nephrolithiasis in West Bengal, India Chatterjee, Arindam Sarkar, Kunal Bank, Sarbashri Ghosh, Sudakshina Kumar Pal, Dilip Saraf, Siddharth Wakle, Dhansagar Roy, Bidyut Chakraborty, Santanu Bankura, Biswabandhu Chattopadhyay, Debprasad Das, Madhusudan Front Mol Biosci Molecular Biosciences Pediatric nephrolithiasis (NL) or Kidney stone disease (KSD) is an untethered topic in Asian population. In Western countries, the annual incidence of paediatric NL is around 6–10%. Here, we present data from West Bengal, India, on lower age (LA, 0–20 years) NL and its prevalence for the first time. To discover the mutations associated with KSD, twenty-four (18 + 6) rare LA-NL patients were selected for Whole Exome Sequencing (WES) and Sanger sequencing, respectively. It was found that GRHPR c. 494G>A mutation (MZ826703) is predominant in our study cohort. This specific homozygous mutation is functionally studied for the first time directly from human peripheral mononuclear cell (PBMC) samples. Using expression study with biochemical activity and computational analysis we assumed that the mutation is pathogenic with loss of function. Moreover, three genes, AGXT, HOGA1 and GRHPR with Novel variants known to cause hyperoxaluria were found frequently in the study cohort. Our study analyses the genes and variations that cause LA-NL, as well as the molecular function of the GRHPR mutation, which may serve as a clinical marker in the population of West Bengal, Eastern India. Frontiers Media S.A. 2022-12-22 /pmc/articles/PMC9815608/ /pubmed/36619171 http://dx.doi.org/10.3389/fmolb.2022.1049620 Text en Copyright © 2022 Chatterjee, Sarkar, Bank, Ghosh, Kumar Pal, Saraf, Wakle, Roy, Chakraborty, Bankura, Chattopadhyay and Das. https://creativecommons.org/licenses/by/4.0/This is an open-access article distributed under the terms of the Creative Commons Attribution License (CC BY). The use, distribution or reproduction in other forums is permitted, provided the original author(s) and the copyright owner(s) are credited and that the original publication in this journal is cited, in accordance with accepted academic practice. No use, distribution or reproduction is permitted which does not comply with these terms. |
spellingShingle | Molecular Biosciences Chatterjee, Arindam Sarkar, Kunal Bank, Sarbashri Ghosh, Sudakshina Kumar Pal, Dilip Saraf, Siddharth Wakle, Dhansagar Roy, Bidyut Chakraborty, Santanu Bankura, Biswabandhu Chattopadhyay, Debprasad Das, Madhusudan Homozygous GRHPR C.494G>A mutation is deleterious that causes early onset of nephrolithiasis in West Bengal, India |
title | Homozygous GRHPR C.494G>A mutation is deleterious that causes early onset of nephrolithiasis in West Bengal, India |
title_full | Homozygous GRHPR C.494G>A mutation is deleterious that causes early onset of nephrolithiasis in West Bengal, India |
title_fullStr | Homozygous GRHPR C.494G>A mutation is deleterious that causes early onset of nephrolithiasis in West Bengal, India |
title_full_unstemmed | Homozygous GRHPR C.494G>A mutation is deleterious that causes early onset of nephrolithiasis in West Bengal, India |
title_short | Homozygous GRHPR C.494G>A mutation is deleterious that causes early onset of nephrolithiasis in West Bengal, India |
title_sort | homozygous grhpr c.494g>a mutation is deleterious that causes early onset of nephrolithiasis in west bengal, india |
topic | Molecular Biosciences |
url | https://www.ncbi.nlm.nih.gov/pmc/articles/PMC9815608/ https://www.ncbi.nlm.nih.gov/pubmed/36619171 http://dx.doi.org/10.3389/fmolb.2022.1049620 |
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