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ALS Associated Mutations in Matrin 3 Alter Protein-Protein Interactions and Impede mRNA Nuclear Export

Mutations in Matrin 3 have recently been linked to ALS, though the mechanism that induces disease in these patients is unknown. To define the protein interactome of wild-type and ALS-linked MATR3 mutations, we performed immunoprecipitation followed by mass spectrometry using NSC-34 cells expressing...

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Autores principales: Boehringer, Ashley, Garcia-Mansfield, Krystine, Singh, Gurkaran, Bakkar, Nadine, Pirrotte, Patrick, Bowser, Robert
Formato: Online Artículo Texto
Lenguaje:English
Publicado: Nature Publishing Group UK 2017
Materias:
Acceso en línea:https://www.ncbi.nlm.nih.gov/pmc/articles/PMC5674072/
https://www.ncbi.nlm.nih.gov/pubmed/29109432
http://dx.doi.org/10.1038/s41598-017-14924-6
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author Boehringer, Ashley
Garcia-Mansfield, Krystine
Singh, Gurkaran
Bakkar, Nadine
Pirrotte, Patrick
Bowser, Robert
author_facet Boehringer, Ashley
Garcia-Mansfield, Krystine
Singh, Gurkaran
Bakkar, Nadine
Pirrotte, Patrick
Bowser, Robert
author_sort Boehringer, Ashley
collection PubMed
description Mutations in Matrin 3 have recently been linked to ALS, though the mechanism that induces disease in these patients is unknown. To define the protein interactome of wild-type and ALS-linked MATR3 mutations, we performed immunoprecipitation followed by mass spectrometry using NSC-34 cells expressing human wild-type or mutant Matrin 3. Gene ontology analysis identified a novel role for Matrin 3 in mRNA transport centered on proteins in the TRanscription and EXport (TREX) complex, known to function in mRNA biogenesis and nuclear export. ALS-linked mutations in Matrin 3 led to its re-distribution within the nucleus, decreased co-localization with endogenous Matrin 3 and increased co-localization with specific TREX components. Expression of disease-causing Matrin 3 mutations led to nuclear mRNA export defects of both global mRNA and more specifically the mRNA of TDP-43 and FUS. Our findings identify a potential pathogenic mechanism attributable to MATR3 mutations and further link cellular transport defects to ALS.
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spelling pubmed-56740722017-11-15 ALS Associated Mutations in Matrin 3 Alter Protein-Protein Interactions and Impede mRNA Nuclear Export Boehringer, Ashley Garcia-Mansfield, Krystine Singh, Gurkaran Bakkar, Nadine Pirrotte, Patrick Bowser, Robert Sci Rep Article Mutations in Matrin 3 have recently been linked to ALS, though the mechanism that induces disease in these patients is unknown. To define the protein interactome of wild-type and ALS-linked MATR3 mutations, we performed immunoprecipitation followed by mass spectrometry using NSC-34 cells expressing human wild-type or mutant Matrin 3. Gene ontology analysis identified a novel role for Matrin 3 in mRNA transport centered on proteins in the TRanscription and EXport (TREX) complex, known to function in mRNA biogenesis and nuclear export. ALS-linked mutations in Matrin 3 led to its re-distribution within the nucleus, decreased co-localization with endogenous Matrin 3 and increased co-localization with specific TREX components. Expression of disease-causing Matrin 3 mutations led to nuclear mRNA export defects of both global mRNA and more specifically the mRNA of TDP-43 and FUS. Our findings identify a potential pathogenic mechanism attributable to MATR3 mutations and further link cellular transport defects to ALS. Nature Publishing Group UK 2017-11-06 /pmc/articles/PMC5674072/ /pubmed/29109432 http://dx.doi.org/10.1038/s41598-017-14924-6 Text en © The Author(s) 2017 Open Access This article is licensed under a Creative Commons Attribution 4.0 International License, which permits use, sharing, adaptation, distribution and reproduction in any medium or format, as long as you give appropriate credit to the original author(s) and the source, provide a link to the Creative Commons license, and indicate if changes were made. The images or other third party material in this article are included in the article’s Creative Commons license, unless indicated otherwise in a credit line to the material. If material is not included in the article’s Creative Commons license and your intended use is not permitted by statutory regulation or exceeds the permitted use, you will need to obtain permission directly from the copyright holder. To view a copy of this license, visit http://creativecommons.org/licenses/by/4.0/.
spellingShingle Article
Boehringer, Ashley
Garcia-Mansfield, Krystine
Singh, Gurkaran
Bakkar, Nadine
Pirrotte, Patrick
Bowser, Robert
ALS Associated Mutations in Matrin 3 Alter Protein-Protein Interactions and Impede mRNA Nuclear Export
title ALS Associated Mutations in Matrin 3 Alter Protein-Protein Interactions and Impede mRNA Nuclear Export
title_full ALS Associated Mutations in Matrin 3 Alter Protein-Protein Interactions and Impede mRNA Nuclear Export
title_fullStr ALS Associated Mutations in Matrin 3 Alter Protein-Protein Interactions and Impede mRNA Nuclear Export
title_full_unstemmed ALS Associated Mutations in Matrin 3 Alter Protein-Protein Interactions and Impede mRNA Nuclear Export
title_short ALS Associated Mutations in Matrin 3 Alter Protein-Protein Interactions and Impede mRNA Nuclear Export
title_sort als associated mutations in matrin 3 alter protein-protein interactions and impede mrna nuclear export
topic Article
url https://www.ncbi.nlm.nih.gov/pmc/articles/PMC5674072/
https://www.ncbi.nlm.nih.gov/pubmed/29109432
http://dx.doi.org/10.1038/s41598-017-14924-6
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