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High-dimensional single-cell phenotyping reveals extensive haploinsufficiency

Haploinsufficiency, a dominant phenotype caused by a heterozygous loss-of-function mutation, has been rarely observed. However, high-dimensional single-cell phenotyping of yeast morphological characteristics revealed haploinsufficiency phenotypes for more than half of 1,112 essential genes under opt...

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Detalles Bibliográficos
Autores principales: Ohnuki, Shinsuke, Ohya, Yoshikazu
Formato: Online Artículo Texto
Lenguaje:English
Publicado: Public Library of Science 2018
Materias:
Acceso en línea:https://www.ncbi.nlm.nih.gov/pmc/articles/PMC5955526/
https://www.ncbi.nlm.nih.gov/pubmed/29768403
http://dx.doi.org/10.1371/journal.pbio.2005130
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author Ohnuki, Shinsuke
Ohya, Yoshikazu
author_facet Ohnuki, Shinsuke
Ohya, Yoshikazu
author_sort Ohnuki, Shinsuke
collection PubMed
description Haploinsufficiency, a dominant phenotype caused by a heterozygous loss-of-function mutation, has been rarely observed. However, high-dimensional single-cell phenotyping of yeast morphological characteristics revealed haploinsufficiency phenotypes for more than half of 1,112 essential genes under optimal growth conditions. Additionally, 40% of the essential genes with no obvious phenotype under optimal growth conditions displayed haploinsufficiency under severe growth conditions. Haploinsufficiency was detected more frequently in essential genes than in nonessential genes. Similar haploinsufficiency phenotypes were observed mostly in mutants with heterozygous deletion of functionally related genes, suggesting that haploinsufficiency phenotypes were caused by functional defects of the genes. A global view of the gene network was presented based on the similarities of the haploinsufficiency phenotypes. Our dataset contains rich information regarding essential gene functions, providing evidence that single-cell phenotyping is a powerful approach, even in the heterozygous condition, for analyzing complex biological systems.
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spelling pubmed-59555262018-05-25 High-dimensional single-cell phenotyping reveals extensive haploinsufficiency Ohnuki, Shinsuke Ohya, Yoshikazu PLoS Biol Methods and Resources Haploinsufficiency, a dominant phenotype caused by a heterozygous loss-of-function mutation, has been rarely observed. However, high-dimensional single-cell phenotyping of yeast morphological characteristics revealed haploinsufficiency phenotypes for more than half of 1,112 essential genes under optimal growth conditions. Additionally, 40% of the essential genes with no obvious phenotype under optimal growth conditions displayed haploinsufficiency under severe growth conditions. Haploinsufficiency was detected more frequently in essential genes than in nonessential genes. Similar haploinsufficiency phenotypes were observed mostly in mutants with heterozygous deletion of functionally related genes, suggesting that haploinsufficiency phenotypes were caused by functional defects of the genes. A global view of the gene network was presented based on the similarities of the haploinsufficiency phenotypes. Our dataset contains rich information regarding essential gene functions, providing evidence that single-cell phenotyping is a powerful approach, even in the heterozygous condition, for analyzing complex biological systems. Public Library of Science 2018-05-16 /pmc/articles/PMC5955526/ /pubmed/29768403 http://dx.doi.org/10.1371/journal.pbio.2005130 Text en © 2018 Ohnuki, Ohya http://creativecommons.org/licenses/by/4.0/ This is an open access article distributed under the terms of the Creative Commons Attribution License (http://creativecommons.org/licenses/by/4.0/) , which permits unrestricted use, distribution, and reproduction in any medium, provided the original author and source are credited.
spellingShingle Methods and Resources
Ohnuki, Shinsuke
Ohya, Yoshikazu
High-dimensional single-cell phenotyping reveals extensive haploinsufficiency
title High-dimensional single-cell phenotyping reveals extensive haploinsufficiency
title_full High-dimensional single-cell phenotyping reveals extensive haploinsufficiency
title_fullStr High-dimensional single-cell phenotyping reveals extensive haploinsufficiency
title_full_unstemmed High-dimensional single-cell phenotyping reveals extensive haploinsufficiency
title_short High-dimensional single-cell phenotyping reveals extensive haploinsufficiency
title_sort high-dimensional single-cell phenotyping reveals extensive haploinsufficiency
topic Methods and Resources
url https://www.ncbi.nlm.nih.gov/pmc/articles/PMC5955526/
https://www.ncbi.nlm.nih.gov/pubmed/29768403
http://dx.doi.org/10.1371/journal.pbio.2005130
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