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Mitochondrial 3243A > G mutation confers pro-atherogenic and pro-inflammatory properties in MELAS iPS derived endothelial cells

Mitochondrial encephalomyopathy, lactic acidosis, and stroke-like episodes (MELAS) syndrome is a mitochondrial disorder that is commonly caused by the m.3243A > G mutation in the MT-TL1 gene encoding for mitochondrial tRNA(Leu(UUR)). While clinical studies reported cerebral infarcts, atherosclero...

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Autores principales: Pek, Nicole Min Qian, Phua, Qian Hua, Ho, Beatrice Xuan, Pang, Jeremy Kah Sheng, Hor, Jin-Hui, An, Omer, Yang, Henry He, Yu, Yang, Fan, Yong, Ng, Shi-Yan, Soh, Boon-Seng
Formato: Online Artículo Texto
Lenguaje:English
Publicado: Nature Publishing Group UK 2019
Materias:
Acceso en línea:https://www.ncbi.nlm.nih.gov/pmc/articles/PMC6805858/
https://www.ncbi.nlm.nih.gov/pubmed/31641105
http://dx.doi.org/10.1038/s41419-019-2036-9
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author Pek, Nicole Min Qian
Phua, Qian Hua
Ho, Beatrice Xuan
Pang, Jeremy Kah Sheng
Hor, Jin-Hui
An, Omer
Yang, Henry He
Yu, Yang
Fan, Yong
Ng, Shi-Yan
Soh, Boon-Seng
author_facet Pek, Nicole Min Qian
Phua, Qian Hua
Ho, Beatrice Xuan
Pang, Jeremy Kah Sheng
Hor, Jin-Hui
An, Omer
Yang, Henry He
Yu, Yang
Fan, Yong
Ng, Shi-Yan
Soh, Boon-Seng
author_sort Pek, Nicole Min Qian
collection PubMed
description Mitochondrial encephalomyopathy, lactic acidosis, and stroke-like episodes (MELAS) syndrome is a mitochondrial disorder that is commonly caused by the m.3243A > G mutation in the MT-TL1 gene encoding for mitochondrial tRNA(Leu(UUR)). While clinical studies reported cerebral infarcts, atherosclerotic lesions, and altered vasculature and stroke-like episodes (SLE) in MELAS patients, it remains unclear how this mutation causes the onset and subsequent progression of the disease. Here, we report that in addition to endothelial dysfunction, diseased endothelial cells (ECs) were found to be pro-atherogenic and pro-inflammation due to high levels of ROS and Ox-LDLs, and high basal expressions of VCAM-1, in particular isoform b, respectively. Consistently, more monocytes were found to adhere to MELAS ECs as compared to the isogenic control, suggesting the presence of an atherosclerosis-like pathology in MELAS. Notably, these disease phenotypes in endothelial cells can be effectively reversed by anti-oxidant treatment suggesting that the lowering of ROS is critical for treating patients with MELAS syndrome.
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spelling pubmed-68058582019-10-24 Mitochondrial 3243A > G mutation confers pro-atherogenic and pro-inflammatory properties in MELAS iPS derived endothelial cells Pek, Nicole Min Qian Phua, Qian Hua Ho, Beatrice Xuan Pang, Jeremy Kah Sheng Hor, Jin-Hui An, Omer Yang, Henry He Yu, Yang Fan, Yong Ng, Shi-Yan Soh, Boon-Seng Cell Death Dis Article Mitochondrial encephalomyopathy, lactic acidosis, and stroke-like episodes (MELAS) syndrome is a mitochondrial disorder that is commonly caused by the m.3243A > G mutation in the MT-TL1 gene encoding for mitochondrial tRNA(Leu(UUR)). While clinical studies reported cerebral infarcts, atherosclerotic lesions, and altered vasculature and stroke-like episodes (SLE) in MELAS patients, it remains unclear how this mutation causes the onset and subsequent progression of the disease. Here, we report that in addition to endothelial dysfunction, diseased endothelial cells (ECs) were found to be pro-atherogenic and pro-inflammation due to high levels of ROS and Ox-LDLs, and high basal expressions of VCAM-1, in particular isoform b, respectively. Consistently, more monocytes were found to adhere to MELAS ECs as compared to the isogenic control, suggesting the presence of an atherosclerosis-like pathology in MELAS. Notably, these disease phenotypes in endothelial cells can be effectively reversed by anti-oxidant treatment suggesting that the lowering of ROS is critical for treating patients with MELAS syndrome. Nature Publishing Group UK 2019-10-22 /pmc/articles/PMC6805858/ /pubmed/31641105 http://dx.doi.org/10.1038/s41419-019-2036-9 Text en © The Author(s) 2019 Open Access This article is licensed under a Creative Commons Attribution 4.0 International License, which permits use, sharing, adaptation, distribution and reproduction in any medium or format, as long as you give appropriate credit to the original author(s) and the source, provide a link to the Creative Commons license, and indicate if changes were made. The images or other third party material in this article are included in the article’s Creative Commons license, unless indicated otherwise in a credit line to the material. If material is not included in the article’s Creative Commons license and your intended use is not permitted by statutory regulation or exceeds the permitted use, you will need to obtain permission directly from the copyright holder. To view a copy of this license, visit http://creativecommons.org/licenses/by/4.0/.
spellingShingle Article
Pek, Nicole Min Qian
Phua, Qian Hua
Ho, Beatrice Xuan
Pang, Jeremy Kah Sheng
Hor, Jin-Hui
An, Omer
Yang, Henry He
Yu, Yang
Fan, Yong
Ng, Shi-Yan
Soh, Boon-Seng
Mitochondrial 3243A > G mutation confers pro-atherogenic and pro-inflammatory properties in MELAS iPS derived endothelial cells
title Mitochondrial 3243A > G mutation confers pro-atherogenic and pro-inflammatory properties in MELAS iPS derived endothelial cells
title_full Mitochondrial 3243A > G mutation confers pro-atherogenic and pro-inflammatory properties in MELAS iPS derived endothelial cells
title_fullStr Mitochondrial 3243A > G mutation confers pro-atherogenic and pro-inflammatory properties in MELAS iPS derived endothelial cells
title_full_unstemmed Mitochondrial 3243A > G mutation confers pro-atherogenic and pro-inflammatory properties in MELAS iPS derived endothelial cells
title_short Mitochondrial 3243A > G mutation confers pro-atherogenic and pro-inflammatory properties in MELAS iPS derived endothelial cells
title_sort mitochondrial 3243a > g mutation confers pro-atherogenic and pro-inflammatory properties in melas ips derived endothelial cells
topic Article
url https://www.ncbi.nlm.nih.gov/pmc/articles/PMC6805858/
https://www.ncbi.nlm.nih.gov/pubmed/31641105
http://dx.doi.org/10.1038/s41419-019-2036-9
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