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Placental defects lead to embryonic lethality in mice lacking the Formin and PCP proteins Daam1 and Daam2

The actin cytoskeleton plays a central role in establishing cell polarity and shape during embryonic morphogenesis. Daam1, a member of the Formin family of actin cytoskeleton regulators, is a Dvl2-binding protein that functions in the Wnt/Planar Cell Polarity (PCP) pathway. To examine the role of th...

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Autores principales: Nakaya, Masa-aki, Gudmundsson, Kristibjorn Orri, Komiya, Yuko, Keller, Jonathan R., Habas, Raymond, Yamaguchi, Terry P., Ajima, Rieko
Formato: Online Artículo Texto
Lenguaje:English
Publicado: Public Library of Science 2020
Materias:
Acceso en línea:https://www.ncbi.nlm.nih.gov/pmc/articles/PMC7192421/
https://www.ncbi.nlm.nih.gov/pubmed/32353019
http://dx.doi.org/10.1371/journal.pone.0232025
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author Nakaya, Masa-aki
Gudmundsson, Kristibjorn Orri
Komiya, Yuko
Keller, Jonathan R.
Habas, Raymond
Yamaguchi, Terry P.
Ajima, Rieko
author_facet Nakaya, Masa-aki
Gudmundsson, Kristibjorn Orri
Komiya, Yuko
Keller, Jonathan R.
Habas, Raymond
Yamaguchi, Terry P.
Ajima, Rieko
author_sort Nakaya, Masa-aki
collection PubMed
description The actin cytoskeleton plays a central role in establishing cell polarity and shape during embryonic morphogenesis. Daam1, a member of the Formin family of actin cytoskeleton regulators, is a Dvl2-binding protein that functions in the Wnt/Planar Cell Polarity (PCP) pathway. To examine the role of the Daam proteins in mammalian development, we generated Daam-deficient mice by gene targeting and found that Daam1, but not Daam2, is necessary for fetal survival. Embryonic development of Daam1 mutants was delayed most likely due to functional defects in the labyrinthine layer of the placenta. Examination of Daam2 and Daam1/2 double mutants revealed that Daam1 and Daam2 are functionally redundant during placental development. Of note, neural tube closure defects (NTD), which are observed in several mammalian PCP mutants, are not observed in Wnt5a or Daam1 single mutants, but arise in Daam1;Wnt5a double mutants. These findings demonstrate a unique function for Daam genes in placental development and are consistent with a role for Daam1 in the Wnt/PCP pathway in mammals.
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spelling pubmed-71924212020-05-11 Placental defects lead to embryonic lethality in mice lacking the Formin and PCP proteins Daam1 and Daam2 Nakaya, Masa-aki Gudmundsson, Kristibjorn Orri Komiya, Yuko Keller, Jonathan R. Habas, Raymond Yamaguchi, Terry P. Ajima, Rieko PLoS One Research Article The actin cytoskeleton plays a central role in establishing cell polarity and shape during embryonic morphogenesis. Daam1, a member of the Formin family of actin cytoskeleton regulators, is a Dvl2-binding protein that functions in the Wnt/Planar Cell Polarity (PCP) pathway. To examine the role of the Daam proteins in mammalian development, we generated Daam-deficient mice by gene targeting and found that Daam1, but not Daam2, is necessary for fetal survival. Embryonic development of Daam1 mutants was delayed most likely due to functional defects in the labyrinthine layer of the placenta. Examination of Daam2 and Daam1/2 double mutants revealed that Daam1 and Daam2 are functionally redundant during placental development. Of note, neural tube closure defects (NTD), which are observed in several mammalian PCP mutants, are not observed in Wnt5a or Daam1 single mutants, but arise in Daam1;Wnt5a double mutants. These findings demonstrate a unique function for Daam genes in placental development and are consistent with a role for Daam1 in the Wnt/PCP pathway in mammals. Public Library of Science 2020-04-30 /pmc/articles/PMC7192421/ /pubmed/32353019 http://dx.doi.org/10.1371/journal.pone.0232025 Text en https://creativecommons.org/publicdomain/zero/1.0/ This is an open access article, free of all copyright, and may be freely reproduced, distributed, transmitted, modified, built upon, or otherwise used by anyone for any lawful purpose. The work is made available under the Creative Commons CC0 (https://creativecommons.org/publicdomain/zero/1.0/) public domain dedication.
spellingShingle Research Article
Nakaya, Masa-aki
Gudmundsson, Kristibjorn Orri
Komiya, Yuko
Keller, Jonathan R.
Habas, Raymond
Yamaguchi, Terry P.
Ajima, Rieko
Placental defects lead to embryonic lethality in mice lacking the Formin and PCP proteins Daam1 and Daam2
title Placental defects lead to embryonic lethality in mice lacking the Formin and PCP proteins Daam1 and Daam2
title_full Placental defects lead to embryonic lethality in mice lacking the Formin and PCP proteins Daam1 and Daam2
title_fullStr Placental defects lead to embryonic lethality in mice lacking the Formin and PCP proteins Daam1 and Daam2
title_full_unstemmed Placental defects lead to embryonic lethality in mice lacking the Formin and PCP proteins Daam1 and Daam2
title_short Placental defects lead to embryonic lethality in mice lacking the Formin and PCP proteins Daam1 and Daam2
title_sort placental defects lead to embryonic lethality in mice lacking the formin and pcp proteins daam1 and daam2
topic Research Article
url https://www.ncbi.nlm.nih.gov/pmc/articles/PMC7192421/
https://www.ncbi.nlm.nih.gov/pubmed/32353019
http://dx.doi.org/10.1371/journal.pone.0232025
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